Heterogeneity of weight gain after initiation of Elexacaftor/Tezacaftor/Ivacaftor in people with cystic fibrosis.


Journal

Respiratory research
ISSN: 1465-993X
Titre abrégé: Respir Res
Pays: England
ID NLM: 101090633

Informations de publication

Date de publication:
17 Jun 2023
Historique:
received: 04 10 2022
accepted: 13 05 2023
medline: 19 6 2023
pubmed: 18 6 2023
entrez: 17 6 2023
Statut: epublish

Résumé

The introduction of the novel therapy, Elexacaftor/Tezacaftor/Ivacaftor (ETI) has been effective in improving weight gain in both clinical trials and real-world studies. However, the magnitude of this effect appears to be heterogeneous across patient subgroups. This study aims to identify potential determinants of heterogeneity in weight gain following 6-month ETI therapy. We conducted a multicenter, prospective cohort study enrolling 92 adults with CF at two major CF centers in Italy with follow-up visit at one month and six months from ETI initiation. The treatment's effect on weight changes was evaluated using mixed effect regression models that included subject-specific random intercepts and fixed effects for potential predictors of treatment response, time and a predictor-by-time interaction term. The mean weight gain at six months from the start of treatment was 4.6 kg (95% CI: 2.3-6.9) for the 10 patients with underweight, 3.2 kg (95% CI: 2.3-4.0) for the 72 patients with normal weight, and 0.7 kg (95% CI: -1.6-3.0) for the 10 patients with overweight. After six months of ETI treatment, 8 (80%) of the patients with underweight transitioned to the normal weight category, while 11 (15.3%) of the normal-weight patients became overweight. The major determinants of heterogeneity in weight gain were the baseline BMI and the presence of at least one CFTR residual function mutation, explaining 13% and 8% of the variability, respectively. Our results indicate that ETI is highly effective in improving weight gain in underweight subjects with CF. However, our data also suggests the need for close monitoring of excess weight gain to prevent potential cardiometabolic complications.

Sections du résumé

BACKGROUND BACKGROUND
The introduction of the novel therapy, Elexacaftor/Tezacaftor/Ivacaftor (ETI) has been effective in improving weight gain in both clinical trials and real-world studies. However, the magnitude of this effect appears to be heterogeneous across patient subgroups. This study aims to identify potential determinants of heterogeneity in weight gain following 6-month ETI therapy.
METHODS METHODS
We conducted a multicenter, prospective cohort study enrolling 92 adults with CF at two major CF centers in Italy with follow-up visit at one month and six months from ETI initiation. The treatment's effect on weight changes was evaluated using mixed effect regression models that included subject-specific random intercepts and fixed effects for potential predictors of treatment response, time and a predictor-by-time interaction term.
RESULTS RESULTS
The mean weight gain at six months from the start of treatment was 4.6 kg (95% CI: 2.3-6.9) for the 10 patients with underweight, 3.2 kg (95% CI: 2.3-4.0) for the 72 patients with normal weight, and 0.7 kg (95% CI: -1.6-3.0) for the 10 patients with overweight. After six months of ETI treatment, 8 (80%) of the patients with underweight transitioned to the normal weight category, while 11 (15.3%) of the normal-weight patients became overweight. The major determinants of heterogeneity in weight gain were the baseline BMI and the presence of at least one CFTR residual function mutation, explaining 13% and 8% of the variability, respectively.
CONCLUSIONS CONCLUSIONS
Our results indicate that ETI is highly effective in improving weight gain in underweight subjects with CF. However, our data also suggests the need for close monitoring of excess weight gain to prevent potential cardiometabolic complications.

Identifiants

pubmed: 37330504
doi: 10.1186/s12931-023-02451-0
pii: 10.1186/s12931-023-02451-0
pmc: PMC10276411
doi:

Substances chimiques

elexacaftor RRN67GMB0V
ivacaftor 1Y740ILL1Z
tezacaftor 0
Cystic Fibrosis Transmembrane Conductance Regulator 126880-72-6

Types de publication

Multicenter Study Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

164

Informations de copyright

© 2023. The Author(s).

Références

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Auteurs

Andrea Gramegna (A)

Department of Pathophysiology and Transplantation, University of Milan, Milan, Italy. andrea.gramegna@unimi.it.
Internal Medicine Department, Respiratory Unit and Cystic Fibrosis Adult Center, Fondazione IRCCS Ca' Granda Ospedale Maggiore Policlinico, Milan, 20122, Italy. andrea.gramegna@unimi.it.

Fabio Majo (F)

Cystic Fibrosis Unit, Bambino Gesù Children's Hospital, IRCCS, Rome, Italy.

Gianfranco Alicandro (G)

Department of Pathophysiology and Transplantation, University of Milan, Milan, Italy.

Gloria Leonardi (G)

Department of Pathophysiology and Transplantation, University of Milan, Milan, Italy.
Internal Medicine Department, Respiratory Unit and Cystic Fibrosis Adult Center, Fondazione IRCCS Ca' Granda Ospedale Maggiore Policlinico, Milan, 20122, Italy.

Luca Cristiani (L)

Cystic Fibrosis Unit, Bambino Gesù Children's Hospital, IRCCS, Rome, Italy.

Francesco Amati (F)

Department of Biomedical Sciences, Humanitas University, Pieve Emanuele, MI, Italy.
Respiratory Unit, IRCCS Humanitas Research Hospital, Rozzano, MI, Italy.

Martina Contarini (M)

Internal Medicine Department, Respiratory Unit and Cystic Fibrosis Adult Center, Fondazione IRCCS Ca' Granda Ospedale Maggiore Policlinico, Milan, 20122, Italy.

Stefano Aliberti (S)

Department of Biomedical Sciences, Humanitas University, Pieve Emanuele, MI, Italy.
Respiratory Unit, IRCCS Humanitas Research Hospital, Rozzano, MI, Italy.

Alessandro Giovanni Fiocchi (AG)

Cystic Fibrosis Unit, Bambino Gesù Children's Hospital, IRCCS, Rome, Italy.

Francesco Blasi (F)

Department of Pathophysiology and Transplantation, University of Milan, Milan, Italy.
Internal Medicine Department, Respiratory Unit and Cystic Fibrosis Adult Center, Fondazione IRCCS Ca' Granda Ospedale Maggiore Policlinico, Milan, 20122, Italy.

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