Overlapping drug-induced vasculitis, ANCA-associated vasculitis, and lupus nephritis caused by low-dose hydralazine.


Journal

International journal of rheumatic diseases
ISSN: 1756-185X
Titre abrégé: Int J Rheum Dis
Pays: England
ID NLM: 101474930

Informations de publication

Date de publication:
Nov 2023
Historique:
received: 21 04 2023
accepted: 16 06 2023
medline: 2 11 2023
pubmed: 15 7 2023
entrez: 15 7 2023
Statut: ppublish

Résumé

We present a case of drug-induced vasculitis secondary to low-dose hydralazine with overlapping features of antineutrophil cytoplasmic antibody-associated vasculitis and drug-induced lupus nephritis. A 52-year-old Hispanic woman with a medical history of resistant hypertension treated with hydralazine 10 mg twice daily for 1 year presented with generalized weakness, dizziness, nausea, vomiting, and gross hematuria. There was fever, tachycardia, leukocytosis, lactic acidosis, hyperkalemia, renal failure, and anemia. Chest computed tomography and bronchoscopy revealed a left lower lobe infiltrate and diffuse alveolar hemorrhage. Serologic testing was positive for anti-double-stranded DNA, anti-Smith, lupus anticoagulant, anti-histone, anti-cardiolipin IgM antibodies, and antineutrophil cytoplasmic antibodies (myeloperoxidase and proteinase 3). A kidney biopsy revealed crescentic glomerulonephritis with an overlapping finding of membranous nephropathy. Broad-spectrum antibiotics, immunosuppressants, corticosteroids, and plasmapheresis were initiated. The patient survived but required continuous hemodialysis. Although a few cases of simultaneous antibody-associated vasculitis and drug-induced lupus nephritis secondary to hydralazine use have been reported, this case is singular. Similar findings were previously reported with doses of 50-100 mg two to three times daily over 1-5 years. In our patient, a dose of only 10 mg twice daily for a year caused a severe disease presentation. This brings to light the combination of different vasculitides that can coexist and the potentially life-threatening adverse effects of low-dose hydralazine that should be kept in mind.

Identifiants

pubmed: 37452463
doi: 10.1111/1756-185X.14809
doi:

Substances chimiques

Hydralazine 26NAK24LS8
Antibodies, Antineutrophil Cytoplasmic 0

Types de publication

Case Reports

Langues

eng

Sous-ensembles de citation

IM

Pagination

2272-2277

Informations de copyright

© 2023 Asia Pacific League of Associations for Rheumatology and John Wiley & Sons Australia, Ltd.

Références

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Auteurs

M Bhatnagar (M)

Sunrise Health GME Consortium, Mountain View Hospital, Las Vegas, Nevada, USA.

A Agaronov (A)

College of Osteopathic Medicine, Touro University Nevada, Henderson, Nevada, USA.

E Sarkisyan (E)

College of Osteopathic Medicine, Touro University Nevada, Henderson, Nevada, USA.

I Sotoudeh Deilamy (I)

Sunrise Health GME Consortium, Mountain View Hospital, Las Vegas, Nevada, USA.

D Pepito (D)

Sunrise Health GME Consortium, Mountain View Hospital, Las Vegas, Nevada, USA.

H Akhondi (H)

Valley Health System, Las Vegas, Nevada, USA.

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