Molecular basis of non-deletional HPFH in Thailand and identification of two novel mutations at the binding sites of CCAAT and GATA-1 transcription factors.


Journal

Scientific reports
ISSN: 2045-2322
Titre abrégé: Sci Rep
Pays: England
ID NLM: 101563288

Informations de publication

Date de publication:
24 07 2023
Historique:
received: 20 10 2022
accepted: 20 07 2023
medline: 26 7 2023
pubmed: 25 7 2023
entrez: 24 7 2023
Statut: epublish

Résumé

High Hb F determinants are genetic defects associated with increased expression of hemoglobin F in adult life, classified as deletional and non-deletional forms. We report the first description of non-deletional hereditary persistence of fetal hemoglobin (HFPH) in Thailand. Study was done on 388 subjects suspected of non-deletional HPFH with elevated Hb F expression. Mutations in the

Identifiants

pubmed: 37488161
doi: 10.1038/s41598-023-39173-8
pii: 10.1038/s41598-023-39173-8
pmc: PMC10366219
doi:

Substances chimiques

GATA Transcription Factors 0
gamma-Globins 0
Transcription Factors 0
Fetal Hemoglobin 9034-63-3

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

11926

Informations de copyright

© 2023. The Author(s).

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Auteurs

Kritsada Singha (K)

Centre for Research and Development of Medical Diagnostic Laboratories, Faculty of Associated Medical Sciences, Khon Kaen University, Khon Kaen, 40002, Thailand.
Faculty of Medicine, Mahasarakham University, Kantharawichai, Mahasarakham, Thailand.

Anupong Pansuwan (A)

Centre for Research and Development of Medical Diagnostic Laboratories, Faculty of Associated Medical Sciences, Khon Kaen University, Khon Kaen, 40002, Thailand.

Mattanee Chewasateanchai (M)

Regional Health Promotion Center 7, Ministry of Public Health, Khon Kaen, Thailand.

Goonnapa Fucharoen (G)

Centre for Research and Development of Medical Diagnostic Laboratories, Faculty of Associated Medical Sciences, Khon Kaen University, Khon Kaen, 40002, Thailand.

Supan Fucharoen (S)

Centre for Research and Development of Medical Diagnostic Laboratories, Faculty of Associated Medical Sciences, Khon Kaen University, Khon Kaen, 40002, Thailand. supan@kku.ac.th.

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Classifications MeSH