Delayed Sublingual Edema Following Neonatal Mandibular Distraction Osteogenesis.
Journal
The Journal of craniofacial surgery
ISSN: 1536-3732
Titre abrégé: J Craniofac Surg
Pays: United States
ID NLM: 9010410
Informations de publication
Date de publication:
01 Sep 2023
01 Sep 2023
Historique:
received:
14
11
2022
accepted:
28
05
2023
medline:
31
8
2023
pubmed:
27
7
2023
entrez:
27
7
2023
Statut:
ppublish
Résumé
The authors aim to report a rare sequela following neonatal mandibular distraction osteogenesis (MDO) involving delayed onset sublingual swelling. They performed a retrospective chart review of 3 patients who presented with delayed onset sublingual edema following neonatal MDO. The 3 patients presented at 2, 4, and 12 months following MDO for micrognathia secondary to Robin sequence with intermittent sublingual swelling associated with sialorrhea and feeding difficulties. There was no associated recent illness, fevers, or purulent drainage. All 3 children underwent magnetic resonance imaging which demonstrated asymmetric sublingual gland edema. The edema was located on the left sublingual gland in 2 children and was bilateral in the third. The symptoms continue to recur 25.5±3.3 months (range, 22.3-28.9) postoperatively and all are being managed conservatively. Chronic delayed onset intermittent sublingual edema is a possible long-term complication following neonatal MDO and further studies should explore the incidence and management of this finding.
Identifiants
pubmed: 37497798
doi: 10.1097/SCS.0000000000009554
pii: 00001665-202309000-00097
doi:
Types de publication
Journal Article
Langues
eng
Pagination
e612-e614Informations de copyright
Copyright © 2023 by Mutaz B. Habal, MD.
Déclaration de conflit d'intérêts
The authors declare no conflicts of interest.
Références
Hsieh ST, Woo AS. Pierre Robin sequence. Clin Plast Surg 2019;46:249–259
Morrison KA, Collares MV, Flores RL. Robin sequence: neonatal mandibular distraction. Clin Plast Surg 2021;48:363–373
Khansa I, Hall C, Madhoun LL, et al. Airway and feeding outcomes of mandibular distraction, tongue-lip adhesion, and conservative management in Pierre Robin sequence: a prospective study. Plast Reconstr Surg 2017;139:975e–983e
Master DL, Hanson PR, Gosain AK. Complications of mandibular distraction osteogenesis. J Craniofac Surg 2010;21:1565–1570
Paes EC, Mink van der Molen AB, Muradin MS, et al. A systematic review on the outcome of mandibular distraction osteogenesis in infants suffering Robin sequence. Clin Oral Investig 2013;17:1807–1820
Lam DJ, Tabangin ME, Shikary TA, et al. Outcomes of mandibular distraction osteogenesis in the treatment of severe micrognathia. JAMA Otolaryngol Head Neck Surg 2014;140:338–345
Morovic CG, Torres J, Jorquera C. Unusual mandibular distraction complication in two neonatal Pierre Robin sequence patients. J Craniofac Surg 2022;33:e201–e203
Edwards RM, Chapman T, Horn DL, et al. Imaging of pediatric floor of mouth lesions. Pediatr Radiol 2013;43:523–535
Bowers EMR, Schaitkin B. Management of mucoceles, sialoceles, and ranulas. Otolaryngol Clin North Am 2021;54:543–551
Yang X, Ow A, Zhang CP, et al. Clinical analysis of 120 cases of intraoral lymphoepithelial cyst. Oral Surg Oral Med Oral Pathol Oral Radiol 2012;113:448–452