Xenografts Show Signs of Concentric Hypertrophy and Dynamic Left Ventricular Outflow Tract Obstruction After Orthotopic Pig-to-baboon Heart Transplantation.


Journal

Transplantation
ISSN: 1534-6080
Titre abrégé: Transplantation
Pays: United States
ID NLM: 0132144

Informations de publication

Date de publication:
01 Dec 2023
Historique:
medline: 28 11 2023
pubmed: 29 8 2023
entrez: 29 8 2023
Statut: ppublish

Résumé

Orthotopic cardiac xenotransplantation has seen substantial advancement in the last years and the initiation of a clinical pilot study is close. However, donor organ overgrowth has been a major hurdle for preclinical experiments, resulting in loss of function and the decease of the recipient. A better understanding of the pathogenesis of organ overgrowth after xenotransplantation is necessary before clinical application. Hearts from genetically modified ( GGTA1-KO , hCD46/hTBM transgenic) juvenile pigs were orthotopically transplanted into male baboons. Group I (control, n = 3) received immunosuppression based on costimulation blockade, group II (growth inhibition, n = 9) was additionally treated with mechanistic target of rapamycin inhibitor, antihypertensive medication, and fast corticoid tapering. Thyroid hormones and insulin-like growth factor 1 were measured before transplantation and before euthanasia, left ventricular (LV) growth was assessed by echocardiography, and hemodynamic data were recorded via a wireless implant. Insulin-like growth factor 1 was higher in baboons than in donor piglets but dropped to porcine levels at the end of the experiments in group I. LV mass increase was 10-fold faster in group I than in group II. This increase was caused by nonphysiological LV wall enlargement. Additionally, pressure gradients between LV and the ascending aorta developed, and signs of dynamic left ventricular outflow tract (LVOT) obstruction appeared. After orthotopic xenotransplantation in baboon recipients, untreated porcine hearts showed rapidly progressing concentric hypertrophy with dynamic LVOT obstruction, mimicking hypertrophic obstructive cardiomyopathy in humans. Antihypertensive and antiproliferative drugs reduced growth rate and inhibited LVOT obstruction, thereby preventing loss of function.

Sections du résumé

BACKGROUND BACKGROUND
Orthotopic cardiac xenotransplantation has seen substantial advancement in the last years and the initiation of a clinical pilot study is close. However, donor organ overgrowth has been a major hurdle for preclinical experiments, resulting in loss of function and the decease of the recipient. A better understanding of the pathogenesis of organ overgrowth after xenotransplantation is necessary before clinical application.
METHODS METHODS
Hearts from genetically modified ( GGTA1-KO , hCD46/hTBM transgenic) juvenile pigs were orthotopically transplanted into male baboons. Group I (control, n = 3) received immunosuppression based on costimulation blockade, group II (growth inhibition, n = 9) was additionally treated with mechanistic target of rapamycin inhibitor, antihypertensive medication, and fast corticoid tapering. Thyroid hormones and insulin-like growth factor 1 were measured before transplantation and before euthanasia, left ventricular (LV) growth was assessed by echocardiography, and hemodynamic data were recorded via a wireless implant.
RESULTS RESULTS
Insulin-like growth factor 1 was higher in baboons than in donor piglets but dropped to porcine levels at the end of the experiments in group I. LV mass increase was 10-fold faster in group I than in group II. This increase was caused by nonphysiological LV wall enlargement. Additionally, pressure gradients between LV and the ascending aorta developed, and signs of dynamic left ventricular outflow tract (LVOT) obstruction appeared.
CONCLUSIONS CONCLUSIONS
After orthotopic xenotransplantation in baboon recipients, untreated porcine hearts showed rapidly progressing concentric hypertrophy with dynamic LVOT obstruction, mimicking hypertrophic obstructive cardiomyopathy in humans. Antihypertensive and antiproliferative drugs reduced growth rate and inhibited LVOT obstruction, thereby preventing loss of function.

Identifiants

pubmed: 37643028
doi: 10.1097/TP.0000000000004765
pii: 00007890-990000000-00531
doi:

Substances chimiques

Insulin-Like Growth Factor I 67763-96-6
Antihypertensive Agents 0

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

e328-e338

Informations de copyright

Copyright © 2023 Wolters Kluwer Health, Inc. All rights reserved.

Déclaration de conflit d'intérêts

M.L., B.R., E.W., A.S., P.B., and J.-M.A. are founders of XTransplant GmbH. U.B. and A.S. are shareholders of XL-protein GmbH. D.A. is chief executive officer and chief scientific officer of Revivicor, Inc. XTransplant, XL-Protein, and Revivicor were not involved in the study design, collection, analysis, interpretation of data, the writing of this article, or the decision to submit it for publication. The other authors declare no conflicts of interest.

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Auteurs

Matthias Längin (M)

Department of Anaesthesiology, LMU University Hospital, LMU Munich, Munich, Germany.

Ines Buttgereit (I)

Department of Anaesthesiology, LMU University Hospital, LMU Munich, Munich, Germany.
Transregional Collaborative Research Center 127, Walter Brendel Centre of Experimental Medicine, LMU Munich, Munich, Germany.

Bruno Reichart (B)

Transregional Collaborative Research Center 127, Walter Brendel Centre of Experimental Medicine, LMU Munich, Munich, Germany.

Alessandro Panelli (A)

Transregional Collaborative Research Center 127, Walter Brendel Centre of Experimental Medicine, LMU Munich, Munich, Germany.

Julia Radan (J)

Transregional Collaborative Research Center 127, Walter Brendel Centre of Experimental Medicine, LMU Munich, Munich, Germany.

Maren Mokelke (M)

Transregional Collaborative Research Center 127, Walter Brendel Centre of Experimental Medicine, LMU Munich, Munich, Germany.

Elisabeth Neumann (E)

Transregional Collaborative Research Center 127, Walter Brendel Centre of Experimental Medicine, LMU Munich, Munich, Germany.

Martin Bender (M)

Department of Anaesthesiology, LMU University Hospital, LMU Munich, Munich, Germany.

Sebastian Michel (S)

Department of Cardiac Surgery, LMU University Hospital, LMU Munich, Munich, Germany.

Reinhard Ellgass (R)

Department of Cardiac Surgery, LMU University Hospital, LMU Munich, Munich, Germany.

Jiawei Ying (J)

Transregional Collaborative Research Center 127, Walter Brendel Centre of Experimental Medicine, LMU Munich, Munich, Germany.

Ann Kathrin Fresch (AK)

Transregional Collaborative Research Center 127, Walter Brendel Centre of Experimental Medicine, LMU Munich, Munich, Germany.

Tanja Mayr (T)

Department of Anaesthesiology, LMU University Hospital, LMU Munich, Munich, Germany.

Stig Steen (S)

Department of Cardiothoracic Surgery, Lund University and Skåne University Hospital, Lund, Sweden.

Audrius Paskevicius (A)

Department of Cardiothoracic Surgery, Lund University and Skåne University Hospital, Lund, Sweden.

Stefanie Egerer (S)

Institute of Molecular Animal Breeding and Biotechnology, Gene Center, and Department of Veterinary Sciences, LMU Munich, Munich, Germany.

Andrea Bähr (A)

Institute of Molecular Animal Breeding and Biotechnology, Gene Center, and Department of Veterinary Sciences, LMU Munich, Munich, Germany.

Barbara Kessler (B)

Institute of Molecular Animal Breeding and Biotechnology, Gene Center, and Department of Veterinary Sciences, LMU Munich, Munich, Germany.

Nikolai Klymiuk (N)

Institute of Molecular Animal Breeding and Biotechnology, Gene Center, and Department of Veterinary Sciences, LMU Munich, Munich, Germany.

Uli Binder (U)

XL-protein GmbH, Freising, Germany.

Arne Skerra (A)

Lehrstuhl für Biologische Chemie, School of Life Sciences, Technical University of Munich, Munich, Germany.

Stephan Ledderose (S)

Institute of Pathology, Faculty of Medicine, LMU Munich, Munich, Germany.

Susanna Müller (S)

Institute of Pathology, Faculty of Medicine, LMU Munich, Munich, Germany.

Christoph Walz (C)

Institute of Pathology, Faculty of Medicine, LMU Munich, Munich, Germany.

Christian Hagl (C)

Department of Cardiac Surgery, LMU University Hospital, LMU Munich, Munich, Germany.

Eckhard Wolf (E)

Institute of Molecular Animal Breeding and Biotechnology, Gene Center, and Department of Veterinary Sciences, LMU Munich, Munich, Germany.
Center for Innovative Medical Models (CiMM), LMU Munich, Munich, Germany.
Interfaculty Center for Endocrine and Cardiovascular Disease Network Modelling and Clinical Transfer (ICONLMU), LMU Munich, Munich, Germany.

David Ayares (D)

Revivicor, Blacksburg, VA.

Paolo Brenner (P)

Department of Cardiac Surgery, LMU University Hospital, LMU Munich, Munich, Germany.

Jan-Michael Abicht (JM)

Department of Anaesthesiology, LMU University Hospital, LMU Munich, Munich, Germany.

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