Cutaneous rhabdomyosarcoma with FUS::TFCP2 fusion: A case report emphasizing early detection.


Journal

Journal of cutaneous pathology
ISSN: 1600-0560
Titre abrégé: J Cutan Pathol
Pays: United States
ID NLM: 0425124

Informations de publication

Date de publication:
Dec 2023
Historique:
revised: 13 08 2023
received: 25 03 2023
accepted: 21 08 2023
medline: 10 11 2023
pubmed: 6 9 2023
entrez: 5 9 2023
Statut: ppublish

Résumé

Rhabdomyosarcoma with TFCP2 rearrangement is a recently identified malignant neoplasm characterized by immunohistochemical evidence of rhabdomyoblastic differentiation, keratin expression, upregulation of ALK, and an aggressive clinical course. This neoplasm has a tendency to affect craniofacial bones, with only a few reported cases of extra-osseous tumors. Here, we present a case of cutaneous rhabdomyosarcoma with FUS::TFCP2 fusion in a 35-year-old female. Notably, the tumor exhibited a pathologic spectrum, initially resembling sclerosing dermatitis at presentation but progressing into a high-grade malignant tumor within 8 months. The distinctive immunoprofile of this neoplasm highlights the importance of early molecular studies for diagnosis, even in the presence of low-grade cytomorphology. Early detection may offer an opportunity for timely resection before the tumor becomes unresectable.

Identifiants

pubmed: 37669767
doi: 10.1111/cup.14526
doi:

Substances chimiques

Transcription Factors 0
Biomarkers, Tumor 0
TFCP2 protein, human 0
DNA-Binding Proteins 0
FUS protein, human 0
RNA-Binding Protein FUS 0

Types de publication

Case Reports

Langues

eng

Sous-ensembles de citation

IM

Pagination

1059-1064

Informations de copyright

© 2023 John Wiley & Sons A/S. Published by John Wiley & Sons Ltd.

Références

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Auteurs

Cuyan Demirkesen (C)

Department of Pathology, Acıbadem University, School of Medicine, Istanbul, Turkey.

Ayça Erşen Danyeli (AE)

Department of Pathology, Acıbadem University, School of Medicine, Istanbul, Turkey.

Pelin Yıldız (P)

Department of Pathology, Acıbadem University, School of Medicine, Istanbul, Turkey.

Sümeyre Seda Ertekin (SS)

Department of Dermatology, Koç University School of Medicine, Istanbul, Turkey.

Berkhan Yılmaz (B)

Department of Plastic, Reconstructive & Aesthetic Surgery, Acıbadem Universiy School of Medicine, Istanbul, Turkey.

Süleyman İzzet Karahan (Sİ)

Department of Dermatology, Acıbadem Hospital, Istanbul, Turkey.

Armita Bahrami (A)

Department of Pathology and Laboratory Medicine, Emory University School of Medicine, Atlanta, Georgia, USA.

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Classifications MeSH