A biobank of pediatric patient-derived-xenograft models in cancer precision medicine trial MAPPYACTS for relapsed and refractory tumors.


Journal

Communications biology
ISSN: 2399-3642
Titre abrégé: Commun Biol
Pays: England
ID NLM: 101719179

Informations de publication

Date de publication:
18 09 2023
Historique:
received: 17 02 2023
accepted: 04 09 2023
medline: 20 9 2023
pubmed: 19 9 2023
entrez: 18 9 2023
Statut: epublish

Résumé

Pediatric patients with recurrent and refractory cancers are in most need for new treatments. This study developed patient-derived-xenograft (PDX) models within the European MAPPYACTS cancer precision medicine trial (NCT02613962). To date, 131 PDX models were established following heterotopical and/or orthotopical implantation in immunocompromised mice: 76 sarcomas, 25 other solid tumors, 12 central nervous system tumors, 15 acute leukemias, and 3 lymphomas. PDX establishment rate was 43%. Histology, whole exome and RNA sequencing revealed a high concordance with the primary patient's tumor profile, human leukocyte-antigen characteristics and specific metabolic pathway signatures. A detailed patient molecular characterization, including specific mutations prioritized in the clinical molecular tumor boards are provided. Ninety models were shared with the IMI2 ITCC Pediatric Preclinical Proof-of-concept Platform (IMI2 ITCC-P4) for further exploitation. This PDX biobank of unique recurrent childhood cancers provides an essential support for basic and translational research and treatments development in advanced pediatric malignancies.

Identifiants

pubmed: 37723198
doi: 10.1038/s42003-023-05320-0
pii: 10.1038/s42003-023-05320-0
pmc: PMC10507044
doi:

Banques de données

ClinicalTrials.gov
['NCT02613962']

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

949

Informations de copyright

© 2023. Springer Nature Limited.

Références

Leukemia. 2019 Oct;33(10):2429-2441
pubmed: 30914792
J Immunol. 2014 Nov 15;193(10):4790-802
pubmed: 25311805
N Engl J Med. 2015 Nov 12;373(20):1895-8
pubmed: 26559569
Nat Biotechnol. 2019 Aug;37(8):907-915
pubmed: 31375807
Nat Rev Clin Oncol. 2012 Apr 17;9(6):338-50
pubmed: 22508028
Nat Rev Cancer. 2018 Jul;18(7):407-418
pubmed: 29692415
Hum Mutat. 2017 Jul;38(7):788-797
pubmed: 28419628
Pediatr Blood Cancer. 2007 Dec;49(7):928-40
pubmed: 17066459
Cell Rep Methods. 2021 Jul 26;1(3):
pubmed: 34761247
Cancer Cell. 2019 Oct 14;36(4):385-401.e8
pubmed: 31564637
Nat Genet. 2017 Sep;49(9):1408-1413
pubmed: 28740262
Cell. 2016 Sep 22;167(1):260-274.e22
pubmed: 27641504
Cell. 2011 Mar 4;144(5):646-74
pubmed: 21376230
Cell. 2017 Feb 9;168(4):613-628
pubmed: 28187284
Nat Genet. 2021 Jan;53(1):86-99
pubmed: 33414553
Cancer Med. 2018 Mar;7(3):665-676
pubmed: 29473324
Clin Cancer Res. 2020 Jul 1;26(13):3307-3318
pubmed: 32220889
Cancer Cell. 2021 Jun 14;39(6):827-844.e10
pubmed: 34129824
F1000Res. 2015 Jul 10;4:214
pubmed: 26925222
Cancer Discov. 2014 Sep;4(9):998-1013
pubmed: 25185190
Sci Rep. 2020 Mar 17;10(1):4897
pubmed: 32184413
Immunogenetics. 1999 Nov;50(3-4):201-12
pubmed: 10602880
Eur J Pharmacol. 2021 Apr 5;896:173921
pubmed: 33529725
Proc Natl Acad Sci U S A. 2017 Jul 25;114(30):8059-8064
pubmed: 28674023
Clin Cancer Res. 2019 Dec 15;25(24):7294-7302
pubmed: 31506385
Methods Mol Biol. 2021;2226:223-242
pubmed: 33326106
Eur J Cancer. 2021 Nov;157:268-277
pubmed: 34543871
Genome Med. 2017 Sep 27;9(1):86
pubmed: 28954626
Nature. 2017 Sep 7;549(7670):96-100
pubmed: 28854174
Cancer Discov. 2022 May 2;12(5):1266-1281
pubmed: 35292802
J Immunol. 2004 Apr 1;172(7):4314-23
pubmed: 15034046
Cell Rep. 2019 Nov 5;29(6):1675-1689.e9
pubmed: 31693904
Front Oncol. 2023 Jun 12;13:1166063
pubmed: 37377921
Nat Commun. 2020 Sep 15;11(1):4629
pubmed: 32934208
Cancer. 2014 Aug 15;120(16):2497-506
pubmed: 24853691
Nat Rev Dis Primers. 2018 Jul 5;4(1):5
pubmed: 29977059
Clin Cancer Res. 2023 Apr 3;29(7):1317-1331
pubmed: 36602782
Cancer Res. 2021 Oct 1;81(19):4994-5006
pubmed: 34341072
Tumori. 2023 Jun;109(3):314-323
pubmed: 36114629
Cancer Discov. 2014 Feb;4(2):216-31
pubmed: 24436047
Cell Tissue Res. 2018 May;372(2):233-243
pubmed: 28924803
Clin Cancer Res. 2017 Oct 15;23(20):6101-6112
pubmed: 28733441
Cancer Res. 2022 Nov 15;82(22):4126-4138
pubmed: 36069866
Cells. 2019 Aug 13;8(8):
pubmed: 31412684
Nat Commun. 2021 Aug 24;12(1):5086
pubmed: 34429404
Nat Med. 2018 Nov;24(11):1752-1761
pubmed: 30349086
Cell Rep. 2020 Feb 11;30(6):1767-1779.e6
pubmed: 32049009
Int J Cancer. 2013 Oct 1;133(7):1547-56
pubmed: 23526331
J Clin Oncol. 2017 Jun 10;35(17):1879-1883
pubmed: 28426373
Acta Neuropathol. 2020 Aug;140(2):209-225
pubmed: 32519082
Cancer Immunol Immunother. 2005 Apr;54(4):400-6
pubmed: 15449039
BMC Immunol. 2008 Jan 22;9:1
pubmed: 18211710
Nat Commun. 2015 Jan 27;6:6125
pubmed: 25625758
J Clin Oncol. 2008 May 10;26(14):2384-9
pubmed: 18467730
J Clin Oncol. 2023 Jan 20;41(3):664-674
pubmed: 36375115
Cancer Res. 2020 Jun 1;80(11):2286-2297
pubmed: 32152150
Blood. 2020 Oct 1;136(14):1657-1669
pubmed: 32573700
Bioinformatics. 2017 Aug 01;33(15):2402-2404
pubmed: 28369222
Bioinformatics. 2014 Dec 1;30(23):3310-6
pubmed: 25143287
Neuro Oncol. 2017 Feb 1;19(2):153-161
pubmed: 27282398

Auteurs

Maria Eugénia Marques Da Costa (ME)

INSERM U1015, Gustave Roussy Cancer Campus, Université Paris-Saclay, Villejuif, France.
Department of Pediatric and Adolescent Oncology, Gustave Roussy Cancer Campus, Villejuif, France.

Sakina Zaidi (S)

INSERM U830, Equipe Labellisée LNCC, Diversity and Plasticity of Childhood Tumors Lab, PSL Research University, SIREDO Oncology Centre, Institut Curie Research Centre, Paris, France.

Jean-Yves Scoazec (JY)

Department of Pathology and Laboratory Medicine, Translational Research Laboratory and Biobank, AMMICA, INSERM US23/CNRS UMS3655, Gustave Roussy Cancer Campus, Université Paris-Saclay, Villejuif, France.

Robin Droit (R)

INSERM U1015, Gustave Roussy Cancer Campus, Université Paris-Saclay, Villejuif, France.
Gustave Roussy Cancer Campus, Bioinformatics Platform, AMMICA, INSERM US23/CNRS, UAR3655, Villejuif, France.

Wan Ching Lim (WC)

INSERM U1015, Gustave Roussy Cancer Campus, Université Paris-Saclay, Villejuif, France.
School of Data Sciences, Perdana University, Kuala Lumpur, Malaysia.

Antonin Marchais (A)

INSERM U1015, Gustave Roussy Cancer Campus, Université Paris-Saclay, Villejuif, France.
Department of Pediatric and Adolescent Oncology, Gustave Roussy Cancer Campus, Villejuif, France.

Jerome Salmon (J)

INSERM U1015, Gustave Roussy Cancer Campus, Université Paris-Saclay, Villejuif, France.

Sarah Cherkaoui (S)

INSERM U1015, Gustave Roussy Cancer Campus, Université Paris-Saclay, Villejuif, France.
Division of Oncology and Children's Research Center, University Children's Hospital Zurich, University of Zurich, Zurich, Switzerland.

Raphael J Morscher (RJ)

INSERM U1015, Gustave Roussy Cancer Campus, Université Paris-Saclay, Villejuif, France.
Division of Oncology and Children's Research Center, University Children's Hospital Zurich, University of Zurich, Zurich, Switzerland.

Anouchka Laurent (A)

Gustave Roussy Cancer Campus, INSERM U1170, Université Paris-Saclay, Equipe labellisée Ligue Nationale Contre le Cancer, PEDIAC program, Villejuif, France.

Sébastien Malinge (S)

Gustave Roussy Cancer Campus, INSERM U1170, Université Paris-Saclay, Equipe labellisée Ligue Nationale Contre le Cancer, PEDIAC program, Villejuif, France.
Telethon Kids Institute - Cancer Centre, Perth Children's Hospital, Nedlands, WA, Australia.

Thomas Mercher (T)

Gustave Roussy Cancer Campus, INSERM U1170, Université Paris-Saclay, Equipe labellisée Ligue Nationale Contre le Cancer, PEDIAC program, Villejuif, France.

Séverine Tabone-Eglinger (S)

Biological Ressources Center, Centre Léon Bérard, Lyon, France.

Isabelle Goddard (I)

Small Animal Platform, Cancer Research Center of Lyon, INSERM U1052, CNRS UMR 5286, Centre Léon Bérard, Claude Bernard Université Lyon 1, Lyon, France.

Francoise Pflumio (F)

UMR-E008 Stabilité Génétique, Cellules Souches et Radiations, Commissariat à l'Energie Atomique et aux Energies Alternatives (CEA), Université de Paris-Université Paris-Saclay, 92260, Fontenay-aux-Roses, France.

Julien Calvo (J)

UMR-E008 Stabilité Génétique, Cellules Souches et Radiations, Commissariat à l'Energie Atomique et aux Energies Alternatives (CEA), Université de Paris-Université Paris-Saclay, 92260, Fontenay-aux-Roses, France.

Francoise Redini (F)

INSERM UMR 1238, Université Nantes, Nantes, France.

Natacha Entz-Werlé (N)

Pediatric Onco-Hematology Unit, University Hospital of Strasbourg, Strasbourg, UMR CNRS 7021, team tumoral signaling and therapeutic targets, University of Strasbourg, Faculty of Pharmacy, Illkirch, France.

Aroa Soriano (A)

Vall d'Hebron Research Institute (VHIR), Childhood Cancer and Blood Disorders Research Group, Division of Pediatric Hematology and Oncology, Vall d'Hebron Barcelona Hospital Campus, Barcelona, Spain.

Alberto Villanueva (A)

Chemoresistance and Predictive Factors Group, Program Against Cancer Therapeutic Resistance (ProCURE), Catalan Institute of Oncology (ICO), Oncobell Program, Bellvitge Biomedical Research Institute (IDIBELL), L'Hospitalet del Llobregat, Xenopat SL, Parc Cientific de Barcelona (PCB), Barcelona, Spain.

Stefano Cairo (S)

XenTech, Evry, France.

Pascal Chastagner (P)

Children University Hospital, Vandoeuvre‑lès‑Nancy, University of Nancy, Nancy, France.

Massimo Moro (M)

Fondazione IRCCS Istituto Nazionale dei Tumori, Milan, Italy.

Cormac Owens (C)

Paediatric Haematology/Oncology, Children's Health Ireland, Crumlin, Dublin, Republic of Ireland.

Michela Casanova (M)

Fondazione IRCCS Istituto Nazionale dei Tumori, Milan, Italy.

Raquel Hladun-Alvaro (R)

Vall d'Hebron Research Institute (VHIR), Childhood Cancer and Blood Disorders Research Group, Division of Pediatric Hematology and Oncology, Vall d'Hebron Barcelona Hospital Campus, Barcelona, Spain.

Pablo Berlanga (P)

Department of Pediatric and Adolescent Oncology, Gustave Roussy Cancer Campus, Villejuif, France.

Estelle Daudigeos-Dubus (E)

INSERM U1015, Gustave Roussy Cancer Campus, Université Paris-Saclay, Villejuif, France.

Philippe Dessen (P)

INSERM U1015, Gustave Roussy Cancer Campus, Université Paris-Saclay, Villejuif, France.
Gustave Roussy Cancer Campus, Bioinformatics Platform, AMMICA, INSERM US23/CNRS, UAR3655, Villejuif, France.

Laurence Zitvogel (L)

INSERM U1015, Gustave Roussy Cancer Campus, Université Paris-Saclay, Villejuif, France.

Ludovic Lacroix (L)

Department of Pathology and Laboratory Medicine, Translational Research Laboratory and Biobank, AMMICA, INSERM US23/CNRS UMS3655, Gustave Roussy Cancer Campus, Université Paris-Saclay, Villejuif, France.

Gaelle Pierron (G)

Unité de Génétique Somatique, Service d'oncogénétique, Institut Curie, Paris, France.

Olivier Delattre (O)

INSERM U830, Equipe Labellisée LNCC, Diversity and Plasticity of Childhood Tumors Lab, PSL Research University, SIREDO Oncology Centre, Institut Curie Research Centre, Paris, France.
Unité de Génétique Somatique, Service d'oncogénétique, Institut Curie, Paris, France.
SiRIC RTOP (Recherche Translationnelle en Oncologie Pédiatrique); Translational Research Department, Institut Curie Research Center, PSL Research University, Institut Curie, Paris, France.

Gudrun Schleiermacher (G)

INSERM U830, Equipe Labellisée LNCC, Diversity and Plasticity of Childhood Tumors Lab, PSL Research University, SIREDO Oncology Centre, Institut Curie Research Centre, Paris, France.
SiRIC RTOP (Recherche Translationnelle en Oncologie Pédiatrique); Translational Research Department, Institut Curie Research Center, PSL Research University, Institut Curie, Paris, France.

Didier Surdez (D)

INSERM U830, Equipe Labellisée LNCC, Diversity and Plasticity of Childhood Tumors Lab, PSL Research University, SIREDO Oncology Centre, Institut Curie Research Centre, Paris, France.
Balgrist University Hospital, University of Zurich, Zurich, Switzerland.

Birgit Geoerger (B)

INSERM U1015, Gustave Roussy Cancer Campus, Université Paris-Saclay, Villejuif, France. birgit.geoerger@gustaveroussy.fr.
Department of Pediatric and Adolescent Oncology, Gustave Roussy Cancer Campus, Villejuif, France. birgit.geoerger@gustaveroussy.fr.

Articles similaires

[Redispensing of expensive oral anticancer medicines: a practical application].

Lisanne N van Merendonk, Kübra Akgöl, Bastiaan Nuijen
1.00
Humans Antineoplastic Agents Administration, Oral Drug Costs Counterfeit Drugs

Smoking Cessation and Incident Cardiovascular Disease.

Jun Hwan Cho, Seung Yong Shin, Hoseob Kim et al.
1.00
Humans Male Smoking Cessation Cardiovascular Diseases Female
Humans United States Aged Cross-Sectional Studies Medicare Part C
1.00
Humans Yoga Low Back Pain Female Male

Classifications MeSH