22q11.2 Deletion Syndrome: Influence of Parental Origin on Clinical Heterogeneity.


Journal

Genes
ISSN: 2073-4425
Titre abrégé: Genes (Basel)
Pays: Switzerland
ID NLM: 101551097

Informations de publication

Date de publication:
21 Apr 2024
Historique:
received: 22 03 2024
revised: 18 04 2024
accepted: 18 04 2024
medline: 27 4 2024
pubmed: 27 4 2024
entrez: 27 4 2024
Statut: epublish

Résumé

22q11.2 deletion syndrome (22q11.2DS) shows significant clinical heterogeneity. This study aimed to explore the association between clinical heterogeneity in 22q11.2DS and the parental origin of the deletion. The parental origin of the deletion was determined for 61 individuals with 22q11.2DS by genotyping DNA microsatellite markers and single-nucleotide polymorphisms (SNPs). Among the 61 individuals, 29 (47.5%) had a maternal origin of the deletion, and 32 (52.5%) a paternal origin. Comparison of the frequency of the main clinical features between individuals with deletions of maternal or paternal origin showed no statistically significant difference. However,

Identifiants

pubmed: 38674452
pii: genes15040518
doi: 10.3390/genes15040518
pii:
doi:

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Subventions

Organisme : Fundação de Amparo à Pesquisa do Estado de São Paulo
ID : 2012/51799-6; 2018/08890-9
Organisme : National Council for Scientific and Technological Development
ID : 304684/2023-6
Organisme : Coordenação de Aperfeicoamento de Pessoal de Nível Superior
ID : 88887.615832/2021-00

Auteurs

Melissa Bittencourt de Wallau (MB)

Medical Genetics and Genomic Medicine, Department of Translational Medicine, School of Medical Sciences, State University of Campinas, Campinas 13083-887, São Paulo, Brazil.

Ana Carolina Xavier (AC)

Centrinho Prefeito Luiz Gomes, Joinville 89203-020, Santa Catarina, Brazil.

Carolina Araújo Moreno (CA)

Medical Genetics and Genomic Medicine, Department of Translational Medicine, School of Medical Sciences, State University of Campinas, Campinas 13083-887, São Paulo, Brazil.

Chong Ae Kim (CA)

Instituto da Criança, Hospital de Clínicas, FMUSP, São Paulo 05403-000, São Paulo, Brazil.

Elaine Lustosa Mendes (EL)

Serviço de Genética do Hospital de Clínicas da UFPR, Curitiba 80060-900, Paraná, Brazil.

Erlane Marques Ribeiro (EM)

Serviço de Genética do Hospital Infantil Albert Sabin-HIAS, Fortaleza 60410-794, Ceará, Brazil.

Amanda Oliveira (A)

Centro de Atenção aos Defeitos da Face-CADEFI, Recife 50060-293, Pernambuco, Brazil.

Têmis Maria Félix (TM)

Serviço de Genética Médica do Hospital de Clínicas de Porto Alegre-HCPA, Porto Alegre 90035-903, Rio Grande do Sul, Brazil.

Agnes Cristina Fett-Conte (AC)

Serviço de Genética da Faculdade de Medicina de São José do Rio Preto (FAMERP/FUNFARME), São José do Rio Preto 15090-000, São Paulo, Brazil.

Luciana Cardoso Bonadia (LC)

Medical Genetics and Genomic Medicine, Department of Translational Medicine, School of Medical Sciences, State University of Campinas, Campinas 13083-887, São Paulo, Brazil.

Gabriela Roldão Correia-Costa (GR)

Medical Genetics and Genomic Medicine, Department of Translational Medicine, School of Medical Sciences, State University of Campinas, Campinas 13083-887, São Paulo, Brazil.

Isabella Lopes Monlleó (IL)

Serviço de Genética Médica do Hospital Universitário Prof. Alberto Antunes (HUPAA), Faculdade de Medicina, Universidade Federal de Alagoas (UFAL), Maceió 57072-900, Alagoas, Brazil.

Vera Lúcia Gil-da-Silva-Lopes (VL)

Medical Genetics and Genomic Medicine, Department of Translational Medicine, School of Medical Sciences, State University of Campinas, Campinas 13083-887, São Paulo, Brazil.

Társis Paiva Vieira (TP)

Medical Genetics and Genomic Medicine, Department of Translational Medicine, School of Medical Sciences, State University of Campinas, Campinas 13083-887, São Paulo, Brazil.

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Classifications MeSH