STR mutations on chromosome 15q cause thyrotropin resistance by activating a primate-specific enhancer of MIR7-2/MIR1179.


Journal

Nature genetics
ISSN: 1546-1718
Titre abrégé: Nat Genet
Pays: United States
ID NLM: 9216904

Informations de publication

Date de publication:
07 May 2024
Historique:
received: 30 07 2023
accepted: 14 03 2024
medline: 8 5 2024
pubmed: 8 5 2024
entrez: 7 5 2024
Statut: aheadofprint

Résumé

Thyrotropin (TSH) is the master regulator of thyroid gland growth and function. Resistance to TSH (RTSH) describes conditions with reduced sensitivity to TSH. Dominantly inherited RTSH has been linked to a locus on chromosome 15q, but its genetic basis has remained elusive. Here we show that non-coding mutations in a (TTTG)

Identifiants

pubmed: 38714869
doi: 10.1038/s41588-024-01717-7
pii: 10.1038/s41588-024-01717-7
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Informations de copyright

© 2024. The Author(s), under exclusive licence to Springer Nature America, Inc.

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Auteurs

Helmut Grasberger (H)

Department of Internal Medicine, Medical School, University of Michigan, Ann Arbor, MI, USA.

Alexandra M Dumitrescu (AM)

Department of Medicine, The University of Chicago, Chicago, IL, USA.
Committee on Molecular Metabolism and Nutrition, The University of Chicago, Chicago, IL, USA.

Xiao-Hui Liao (XH)

Department of Medicine, The University of Chicago, Chicago, IL, USA.

Elliott G Swanson (EG)

Division of Medical Genetics, Department of Medicine, University of Washington, Seattle, WA, USA.
Department of Genome Sciences, University of Washington, Seattle, WA, USA.

Roy E Weiss (RE)

Department of Medicine, University of Miami Miller School of Medicine, Miami, FL, USA.

Panudda Srichomkwun (P)

Department of Medicine, The University of Chicago, Chicago, IL, USA.

Theodora Pappa (T)

Department of Medicine, The University of Chicago, Chicago, IL, USA.

Junfeng Chen (J)

Institute of Transformative Bio-Molecules (WPI-ITbM) and Graduate School of Bioagricultural Sciences, Nagoya University, Nagoya, Japan.

Takashi Yoshimura (T)

Institute of Transformative Bio-Molecules (WPI-ITbM) and Graduate School of Bioagricultural Sciences, Nagoya University, Nagoya, Japan.

Phillip Hoffmann (P)

Interuniversity Institute of Bioinformatics in Brussels, Université Libre de Bruxelles-Vrije Universiteit Brussel, Brussels, Belgium.

Monica Malheiros França (MM)

Department of Medicine, The University of Chicago, Chicago, IL, USA.

Rebecca Tagett (R)

Michigan Medicine BRCF Bioinformatics Core, University of Michigan, Ann Arbor, MI, USA.

Kazumichi Onigata (K)

Department of Medicine, The University of Chicago, Chicago, IL, USA.

Sabine Costagliola (S)

Institut de Recherche Interdisciplinaire en Biologie Humaine et Moléculaire (IRIBHM), Université Libre de Bruxelles, Brussels, Belgium.

Jane Ranchalis (J)

Division of Medical Genetics, Department of Medicine, University of Washington, Seattle, WA, USA.

Mitchell R Vollger (MR)

Division of Medical Genetics, Department of Medicine, University of Washington, Seattle, WA, USA.

Andrew B Stergachis (AB)

Division of Medical Genetics, Department of Medicine, University of Washington, Seattle, WA, USA.
Department of Genome Sciences, University of Washington, Seattle, WA, USA.
Brotman-Baty Institute for Precision Medicine, Seattle, WA, USA.

Jessica X Chong (JX)

Division of Medical Genetics, Department of Medicine, University of Washington, Seattle, WA, USA.
Brotman-Baty Institute for Precision Medicine, Seattle, WA, USA.

Michael J Bamshad (MJ)

Division of Medical Genetics, Department of Medicine, University of Washington, Seattle, WA, USA.
Department of Genome Sciences, University of Washington, Seattle, WA, USA.
Brotman-Baty Institute for Precision Medicine, Seattle, WA, USA.

Guillaume Smits (G)

Interuniversity Institute of Bioinformatics in Brussels, Université Libre de Bruxelles-Vrije Universiteit Brussel, Brussels, Belgium.
Center of Human Genetics, Hôpital Erasme, Hôpital Universitaire de Bruxelles, and Department of Genetics, Hôpital Universitaire des Enfants Reine Fabiola, Hôpital Universitaire de Bruxelles, Université Libre de Bruxelles, Brussels, Belgium.

Gilbert Vassart (G)

Institut de Recherche Interdisciplinaire en Biologie Humaine et Moléculaire (IRIBHM), Université Libre de Bruxelles, Brussels, Belgium.

Samuel Refetoff (S)

Department of Medicine, The University of Chicago, Chicago, IL, USA. refetoff@uchicago.edu.
Committee on Genetics, The University of Chicago, Chicago, IL, USA. refetoff@uchicago.edu.
Department of Pediatrics, The University of Chicago, Chicago, IL, USA. refetoff@uchicago.edu.

Classifications MeSH