KMT2D regulates activation, localization, and integrin expression by T-cells.


Journal

Frontiers in immunology
ISSN: 1664-3224
Titre abrégé: Front Immunol
Pays: Switzerland
ID NLM: 101560960

Informations de publication

Date de publication:
2024
Historique:
received: 20 11 2023
accepted: 26 03 2024
medline: 20 5 2024
pubmed: 20 5 2024
entrez: 20 5 2024
Statut: epublish

Résumé

Individuals with Kabuki syndrome present with immunodeficiency; however, how pathogenic variants in the gene encoding the histone-modifying enzyme lysine methyltransferase 2D (KMT2D) lead to immune alterations remain poorly understood. Following up on our prior report of KMT2D-altered integrin expression in B-cells, we performed targeted analyses of KMT2D's influence on integrin expression in T-cells throughout development (thymocytes through peripheral T-cells) in murine cells with constitutive- and conditional-targeted

Identifiants

pubmed: 38765012
doi: 10.3389/fimmu.2024.1341745
pmc: PMC11099208
doi:

Substances chimiques

Kmt2d protein, mouse 0

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

1341745

Informations de copyright

Copyright © 2024 Potter, Zhang, Kotliar, Wu, Schafer, Stefan, Boukas, Qu’d, Bodamer, Simpson, Barski, Lindsley and Bjornsson.

Déclaration de conflit d'intérêts

AB is a cofounder of Datirium, the developer of Scientific Data Analysis Platform https://SciDAP.com used here for processing RNA-Seq data. AB and MK developed CWL-Airflow licensed to Datirium, LLC. AL is an employee of Amgen Inc. HB is a consultant for Mahzi therapeutics. The remaining authors declare that the research was conducted in the absence of any commercial or financial relationships that could be construed as a potential conflict of interest.

Auteurs

Sarah J Potter (SJ)

Division of Allergy & Immunology, Cincinnati Children's Hospital Medical Center, Cincinnati, OH, United States.

Li Zhang (L)

McKusick-Nathans Department of Genetics, The Johns Hopkins University School of Medicine, Baltimore, MD, United States.

Michael Kotliar (M)

Division of Allergy & Immunology, Cincinnati Children's Hospital Medical Center, Cincinnati, OH, United States.

Yuehong Wu (Y)

Division of Allergy & Immunology, Cincinnati Children's Hospital Medical Center, Cincinnati, OH, United States.

Caitlin Schafer (C)

Division of Allergy & Immunology, Cincinnati Children's Hospital Medical Center, Cincinnati, OH, United States.

Kurtis Stefan (K)

Division of Allergy & Immunology, Cincinnati Children's Hospital Medical Center, Cincinnati, OH, United States.

Leandros Boukas (L)

McKusick-Nathans Department of Genetics, The Johns Hopkins University School of Medicine, Baltimore, MD, United States.
Department of Biostatistics, Johns Hopkins Bloomberg School of Public Health, Baltimore, MD, United States.

Dima Qu'd (D)

Division of Human Genetics, Cincinnati Children's Hospital Medical Center, Cincinnati, OH, United States.

Olaf Bodamer (O)

Division of Genetics and Genomics, Boston Children's Hospital, Boston, MA, United States.
The Roya Kabuki Program, Boston Children's Hospital, Boston, MA, United States.
Division of Genetics and Genomics, Broad Institute of MIT and Harvard University, Cambridge, MA, United States.

Brittany N Simpson (BN)

Division of Human Genetics, Cincinnati Children's Hospital Medical Center, Cincinnati, OH, United States.
Department of Pediatrics, University of Cincinnati College of Medicine, Cincinnati, OH, United States.

Artem Barski (A)

Division of Allergy & Immunology, Cincinnati Children's Hospital Medical Center, Cincinnati, OH, United States.
Division of Human Genetics, Cincinnati Children's Hospital Medical Center, Cincinnati, OH, United States.
Department of Pediatrics, University of Cincinnati College of Medicine, Cincinnati, OH, United States.

Andrew W Lindsley (AW)

Division of Allergy & Immunology, Cincinnati Children's Hospital Medical Center, Cincinnati, OH, United States.
Department of Pediatrics, University of Cincinnati College of Medicine, Cincinnati, OH, United States.

Hans T Bjornsson (HT)

McKusick-Nathans Department of Genetics, The Johns Hopkins University School of Medicine, Baltimore, MD, United States.
Faculty of Medicine, The University of Iceland, Reykjavik, Iceland.
Department of Genetics and Molecular Medicine, Landspitali University Hospital, Reykjavik, Iceland.

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Classifications MeSH