Comparison of juvenile and adult myasthenia gravis in a French cohort with focus on thymic histology.


Journal

Scientific reports
ISSN: 2045-2322
Titre abrégé: Sci Rep
Pays: England
ID NLM: 101563288

Informations de publication

Date de publication:
17 06 2024
Historique:
received: 02 02 2024
accepted: 26 05 2024
medline: 18 6 2024
pubmed: 18 6 2024
entrez: 17 6 2024
Statut: epublish

Résumé

Myasthenia gravis (MG) is an autoimmune disease characterized by muscle fatigability due to acetylcholine receptor (AChR) autoantibodies. To better characterize juvenile MG (JMG), we analyzed 85 pre- and 132 post-pubescent JMG (with a cutoff age of 13) compared to 721 adult MG patients under 40 years old using a French database. Clinical data, anti-AChR antibody titers, thymectomy, and thymic histology were analyzed. The proportion of females was higher in each subgroup. No significant difference in the anti-AChR titers was observed. Interestingly, the proportion of AChR

Identifiants

pubmed: 38886398
doi: 10.1038/s41598-024-63162-0
pii: 10.1038/s41598-024-63162-0
doi:

Substances chimiques

Autoantibodies 0
Receptors, Cholinergic 0

Types de publication

Journal Article Comparative Study

Langues

eng

Sous-ensembles de citation

IM

Pagination

13955

Subventions

Organisme : FP7 Health
ID : FIGHT-MG/HEALTH-2009-242-210
Organisme : FP7 Health
ID : FIGHT-MG/HEALTH-2009-242-210
Organisme : European Commission
ID : MYASTAID/LSHM-CT-2006-037833

Informations de copyright

© 2024. The Author(s).

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Auteurs

Frédérique Truffault (F)

Center of Research in Myology, Institute of Myology, INSERM, Sorbonne University, 105, Boulevard de l'Hôpital, 75013, Paris, France.

Ludivine Auger (L)

Center of Research in Myology, Institute of Myology, INSERM, Sorbonne University, 105, Boulevard de l'Hôpital, 75013, Paris, France.

Nadine Dragin (N)

Center of Research in Myology, Institute of Myology, INSERM, Sorbonne University, 105, Boulevard de l'Hôpital, 75013, Paris, France.

Jean-Thomas Vilquin (JT)

Center of Research in Myology, Institute of Myology, INSERM, Sorbonne University, 105, Boulevard de l'Hôpital, 75013, Paris, France.

Elie Fadel (E)

Marie Lannelongue Hospital, Paris Saclay University, Le Plessis-Robinson, France.

Vincent Thomas de Montpreville (V)

Marie Lannelongue Hospital, Paris Saclay University, Le Plessis-Robinson, France.

Audrey Mansuet-Lupo (A)

Department of Pathology, Cochin University Hospital Group, AP-HP, Paris-Descartes University, Paris, France.

Jean-François Regnard (JF)

Department of Pathology, Cochin University Hospital Group, AP-HP, Paris-Descartes University, Paris, France.

Marco Alifano (M)

Department of Pathology, Cochin University Hospital Group, AP-HP, Paris-Descartes University, Paris, France.

Tarek Sharshar (T)

Anesthesia and Intensive Care Department, GHU Paris Psychiatrie et Neurosciences, Pole Neuro, Sainte‑Anne Hospital, Paris, Institute of Psychiatry and Neurosciences of Paris, INSERM U1266, Université Paris Cité, Paris, France.

Anthony Behin (A)

AP-HP, Referral Center for Neuromuscular Disorders, Institute of Myology, Pitié-Salpêtrière Hospital, AP-HP, Paris, France.

Bruno Eymard (B)

AP-HP, Referral Center for Neuromuscular Disorders, Institute of Myology, Pitié-Salpêtrière Hospital, AP-HP, Paris, France.

Francis Bolgert (F)

Neuro-Intensive Care Unit, Pitié-Salpêtrière Hospital, AP-HP, Sorbonne University, Paris, France.

Sophie Demeret (S)

Neuro-Intensive Care Unit, Pitié-Salpêtrière Hospital, AP-HP, Sorbonne University, Paris, France.

Sonia Berrih-Aknin (S)

Center of Research in Myology, Institute of Myology, INSERM, Sorbonne University, 105, Boulevard de l'Hôpital, 75013, Paris, France.

Rozen Le Panse (R)

Center of Research in Myology, Institute of Myology, INSERM, Sorbonne University, 105, Boulevard de l'Hôpital, 75013, Paris, France. rozen.lepanse@upmc.fr.

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