Tuberous Sclerosis Complex and the kidneys: what nephrologists need to know.


Journal

Jornal brasileiro de nefrologia
ISSN: 2175-8239
Titre abrégé: J Bras Nefrol
Pays: Brazil
ID NLM: 9426946

Informations de publication

Date de publication:
2024
Historique:
received: 18 01 2024
accepted: 24 04 2024
medline: 11 7 2024
pubmed: 11 7 2024
entrez: 11 7 2024
Statut: epublish

Résumé

Tuberous sclerosis complex (TSC) is an autosomal dominant disease characterized by the development of hamartomas in the central nervous system, heart, skin, lungs, and kidneys and other manifestations including seizures, cortical tubers, radial migration lines, autism and cognitive disability. The disease is associated with pathogenic variants in the TSC1 or TSC2 genes, resulting in the hyperactivation of the mTOR pathway, a key regulator of cell growth and metabolism. Consequently, the hyperactivation of the mTOR pathway leads to abnormal tissue proliferation and the development of solid tumors. Kidney involvement in TSC is characterized by the development of cystic lesions, renal cell carcinoma and renal angiomyolipomas, which may progress and cause pain, bleeding, and loss of kidney function. Over the past years, there has been a notable shift in the therapeutic approach to TSC, particularly in addressing renal manifestations. mTOR inhibitors have emerged as the primary therapeutic option, whereas surgical interventions like nephrectomy and embolization being reserved primarily for complications unresponsive to clinical treatment, such as severe renal hemorrhage. This review focuses on the main clinical characteristics of TSC, the mechanisms underlying kidney involvement, the recent advances in therapy for kidney lesions, and the future perspectives.

Identifiants

pubmed: 38991206
pii: S0101-28002024000300402
doi: 10.1590/2175-8239-JBN-2024-0013en
pii:
doi:

Substances chimiques

MTOR Inhibitors 0
TOR Serine-Threonine Kinases EC 2.7.11.1
Tuberous Sclerosis Complex 1 Protein 0

Types de publication

Journal Article Review

Langues

eng por

Sous-ensembles de citation

IM

Pagination

e20240013

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Auteurs

Aline Grosskopf Monich (AG)

Universidade Federal do Paraná, Departamento de Clínica Médica, Programa de Pós-Graduação em Medicina Interna e Ciências da Saúde, Curitiba, PR, Brazil.
Hospital Universitário Evangélico Mackenzie, Serviço de Nefrologia, Curitiba, PR, Brazil.

John J Bissler (JJ)

University of Tennessee, Health Science Center, Le Bonheur Children's Hospital, Department of Pediatrics, Memphis, TN, USA.
Le Bonheur Children's Hospital, Children's Foundation Research Institute, Memphis, TN, USA.
St. Jude Children's Research Hospital, Pediatric Medicine Department, Memphis, TN, USA.

Fellype Carvalho Barreto (FC)

Universidade Federal do Paraná, Departamento de Clínica Médica, Programa de Pós-Graduação em Medicina Interna e Ciências da Saúde, Curitiba, PR, Brazil.
Universidade Federal do Paraná, Departamento de Clínica Médica, Serviço de Nefrologia, Curitiba, PR, Brazil.

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Classifications MeSH