Evidence for a lipofibroblast-to-


Journal

The European respiratory journal
ISSN: 1399-3003
Titre abrégé: Eur Respir J
Pays: England
ID NLM: 8803460

Informations de publication

Date de publication:
10 Oct 2024
Historique:
received: 21 03 2023
accepted: 24 09 2024
medline: 15 10 2024
pubmed: 15 10 2024
entrez: 14 10 2024
Statut: aheadofprint

Résumé

Fibrosis is often associated with aberrant repair mechanisms that ultimately lead to organ failure. In the lung, idiopathic pulmonary fibrosis (IPF) is a fatal form of interstitial lung disease (ILD) to which there is currently no curative therapy. From the cell biology point of view, the cell of origin and eventual fate of activated myofibroblasts (aMYFs) have taken center stage as these cells are believed to drive structural remodeling and lung function impairment. While aMYFs are now widely believed to originate from resident fibroblasts, the heterogeneity of aMYFs and ultimate fate during fibrosis resolution remain elusive. We have previously shown that aMYFs dedifferentiation and acquisition of a lipofibroblast (LIF)-like phenotype represent a route of fibrosis resolution. In this study, we combined genetic lineage tracing and single-cell transcriptomics in mice, and data mining of human IPF datasets to decipher the heterogeneity of aMYFs and investigate differentiation trajectories during fibrosis resolution. Furthermore, organoid cultures were utilized as a functional readout for the alveolar mesenchymal niche activity during various phases of injury and repair in mice. Our data demonstrate that aMYFs consist of four subclusters displaying unique pro-alveologenic Our work identifies a subcluster of aMYFs that is potentially relevant for future management of IPF.

Sections du résumé

BACKGROUND BACKGROUND
Fibrosis is often associated with aberrant repair mechanisms that ultimately lead to organ failure. In the lung, idiopathic pulmonary fibrosis (IPF) is a fatal form of interstitial lung disease (ILD) to which there is currently no curative therapy. From the cell biology point of view, the cell of origin and eventual fate of activated myofibroblasts (aMYFs) have taken center stage as these cells are believed to drive structural remodeling and lung function impairment. While aMYFs are now widely believed to originate from resident fibroblasts, the heterogeneity of aMYFs and ultimate fate during fibrosis resolution remain elusive. We have previously shown that aMYFs dedifferentiation and acquisition of a lipofibroblast (LIF)-like phenotype represent a route of fibrosis resolution.
METHODS METHODS
In this study, we combined genetic lineage tracing and single-cell transcriptomics in mice, and data mining of human IPF datasets to decipher the heterogeneity of aMYFs and investigate differentiation trajectories during fibrosis resolution. Furthermore, organoid cultures were utilized as a functional readout for the alveolar mesenchymal niche activity during various phases of injury and repair in mice.
RESULTS RESULTS
Our data demonstrate that aMYFs consist of four subclusters displaying unique pro-alveologenic
CONCLUSION CONCLUSIONS
Our work identifies a subcluster of aMYFs that is potentially relevant for future management of IPF.

Identifiants

pubmed: 39401861
pii: 13993003.00482-2023
doi: 10.1183/13993003.00482-2023
pii:
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Informations de copyright

Copyright ©The authors 2024. For reproduction rights and permissions contact permissions@ersnet.org.

Auteurs

Arun Lingampally (A)

Department of Medicine II, Internal Medicine, Pulmonary and Critical Care, Universities of Giessen and Marburg Lung Center (UGMLC), German Center for Lung Research (DZL), Justus-Liebig University Giessen, Giessen, Germany.
Department of Medicine V, Internal Medicine, Infectious Diseases and Infection Control, Universities of Giessen and Marburg Lung Center (UGMLC), German Center for Lung Research (DZL), Justus-Liebig University Giessen, Giessen, Germany.
Cardio-Pulmonary Institute (CPI), Giessen, Germany.
Institute for Lung Health (ILH), Giessen, Germany.
Equal contribution.

Marin Truchi (M)

Université Côte d'Azur, UMR CNRS 7275 Inserm 1323, IPMC, FHU-OncoAge, IHU RespiERA, , Valbonne, France.
Equal contribution.

Olivier Mauduit (O)

Department of Molecular Medicine, The Scripps Research Institute, La Jolla, CA, USA.

Vanessa Delcroix (V)

Department of Molecular Medicine, The Scripps Research Institute, La Jolla, CA, USA.

Esmeralda Vasquez-Pacheco (E)

Department of Medicine II, Internal Medicine, Pulmonary and Critical Care, Universities of Giessen and Marburg Lung Center (UGMLC), German Center for Lung Research (DZL), Justus-Liebig University Giessen, Giessen, Germany.
Cardio-Pulmonary Institute (CPI), Giessen, Germany.
Institute for Lung Health (ILH), Giessen, Germany.

Marine Gautier-Isola (M)

Université Côte d'Azur, UMR CNRS 7275 Inserm 1323, IPMC, FHU-OncoAge, IHU RespiERA, , Valbonne, France.

Xuran Chu (X)

Oujiang Laboratory (Zhejiang lab for regenerative medicine, Vision and Brain health), School of Pharmaceutical Science, Wenzhou Medical University, Wenzhou, Zhejiang, P.R. China.

Ali Khadim (A)

Department of Medicine V, Internal Medicine, Infectious Diseases and Infection Control, Universities of Giessen and Marburg Lung Center (UGMLC), German Center for Lung Research (DZL), Justus-Liebig University Giessen, Giessen, Germany.
Cardio-Pulmonary Institute (CPI), Giessen, Germany.
Institute for Lung Health (ILH), Giessen, Germany.

Cho-Ming Chao (CM)

Cardio-Pulmonary Institute (CPI), Giessen, Germany.

Mahsa Zabihi (M)

Department of Medicine V, Internal Medicine, Infectious Diseases and Infection Control, Universities of Giessen and Marburg Lung Center (UGMLC), German Center for Lung Research (DZL), Justus-Liebig University Giessen, Giessen, Germany.
Cardio-Pulmonary Institute (CPI), Giessen, Germany.
Institute for Lung Health (ILH), Giessen, Germany.

Sara Taghizadeh (S)

Department of Medicine II, Internal Medicine, Pulmonary and Critical Care, Universities of Giessen and Marburg Lung Center (UGMLC), German Center for Lung Research (DZL), Justus-Liebig University Giessen, Giessen, Germany.
Cardio-Pulmonary Institute (CPI), Giessen, Germany.
Institute for Lung Health (ILH), Giessen, Germany.

Stefano Rivetti (S)

Department of Medicine II, Internal Medicine, Pulmonary and Critical Care, Universities of Giessen and Marburg Lung Center (UGMLC), German Center for Lung Research (DZL), Justus-Liebig University Giessen, Giessen, Germany.
Cardio-Pulmonary Institute (CPI), Giessen, Germany.
Institute for Lung Health (ILH), Giessen, Germany.

Manuela Marega (M)

Department of Medicine II, Internal Medicine, Pulmonary and Critical Care, Universities of Giessen and Marburg Lung Center (UGMLC), German Center for Lung Research (DZL), Justus-Liebig University Giessen, Giessen, Germany.
Cardio-Pulmonary Institute (CPI), Giessen, Germany.
Institute for Lung Health (ILH), Giessen, Germany.

Alena Moiseenko (A)

Immunology and Respiratory Department, Boehringer Ingelheim Pharma GmbH, Biberach an der Riss, Germany.

Stefan Hadzic (S)

Department of Medicine II, Internal Medicine, Pulmonary and Critical Care, Universities of Giessen and Marburg Lung Center (UGMLC), German Center for Lung Research (DZL), Justus-Liebig University Giessen, Giessen, Germany.
Cardio-Pulmonary Institute (CPI), Giessen, Germany.
Institute for Lung Health (ILH), Giessen, Germany.

Ana Ivonne Vazquez-Armendariz (AI)

University of Bonn, Transdisciplinary Research Area Life and Health, Organoid Biology, Life & Medical Sciences Institute, Bonn, Germany.

Susanne Herold (S)

Department of Medicine V, Internal Medicine, Infectious Diseases and Infection Control, Universities of Giessen and Marburg Lung Center (UGMLC), German Center for Lung Research (DZL), Justus-Liebig University Giessen, Giessen, Germany.
Cardio-Pulmonary Institute (CPI), Giessen, Germany.
Institute for Lung Health (ILH), Giessen, Germany.

Stefan Günther (S)

Max Planck Institute for Heart and Lung Research, W.G. Kerckhoff Institute, Bad Nauheim, Germany.

Pamela Millar-Büchner (P)

Department of Medicine II, Internal Medicine, Pulmonary and Critical Care, Universities of Giessen and Marburg Lung Center (UGMLC), German Center for Lung Research (DZL), Justus-Liebig University Giessen, Giessen, Germany.
Cardio-Pulmonary Institute (CPI), Giessen, Germany.
Institute for Lung Health (ILH), Giessen, Germany.

Janine Koepke (J)

Department of Medicine II, Internal Medicine, Pulmonary and Critical Care, Universities of Giessen and Marburg Lung Center (UGMLC), German Center for Lung Research (DZL), Justus-Liebig University Giessen, Giessen, Germany.
Cardio-Pulmonary Institute (CPI), Giessen, Germany.
Institute for Lung Health (ILH), Giessen, Germany.

Christos Samakovlis (C)

Department of Medicine II, Internal Medicine, Pulmonary and Critical Care, Universities of Giessen and Marburg Lung Center (UGMLC), German Center for Lung Research (DZL), Justus-Liebig University Giessen, Giessen, Germany.
Cardio-Pulmonary Institute (CPI), Giessen, Germany.
Institute for Lung Health (ILH), Giessen, Germany.

Jochen Wilhelm (J)

Department of Medicine II, Internal Medicine, Pulmonary and Critical Care, Universities of Giessen and Marburg Lung Center (UGMLC), German Center for Lung Research (DZL), Justus-Liebig University Giessen, Giessen, Germany.
Cardio-Pulmonary Institute (CPI), Giessen, Germany.
Institute for Lung Health (ILH), Giessen, Germany.

Marek Bartkuhn (M)

Cardio-Pulmonary Institute (CPI), Giessen, Germany.
Institute for Lung Health (ILH), Giessen, Germany.

Thomas Braun (T)

Max Planck Institute for Heart and Lung Research, W.G. Kerckhoff Institute, Bad Nauheim, Germany.

Norbert Weissmann (N)

Department of Medicine II, Internal Medicine, Pulmonary and Critical Care, Universities of Giessen and Marburg Lung Center (UGMLC), German Center for Lung Research (DZL), Justus-Liebig University Giessen, Giessen, Germany.
Cardio-Pulmonary Institute (CPI), Giessen, Germany.
Institute for Lung Health (ILH), Giessen, Germany.

JinSan Zhang (J)

The Quzhou Affiliated Hospital of Wenzhou Medical University, Quzhou People's Hospital, Quzhou, Zhejiang, China.

Malgorzata Wygrecka (M)

Department of Medicine II, Internal Medicine, Pulmonary and Critical Care, Universities of Giessen and Marburg Lung Center (UGMLC), German Center for Lung Research (DZL), Justus-Liebig University Giessen, Giessen, Germany.
Cardio-Pulmonary Institute (CPI), Giessen, Germany.
Institute for Lung Health (ILH), Giessen, Germany.

Helen P Makarenkova (HP)

Department of Molecular Medicine, The Scripps Research Institute, La Jolla, CA, USA.

Andreas Günther (A)

Department of Medicine II, Internal Medicine, Pulmonary and Critical Care, Universities of Giessen and Marburg Lung Center (UGMLC), German Center for Lung Research (DZL), Justus-Liebig University Giessen, Giessen, Germany.
Cardio-Pulmonary Institute (CPI), Giessen, Germany.
Institute for Lung Health (ILH), Giessen, Germany.

Werner Seeger (W)

Department of Medicine II, Internal Medicine, Pulmonary and Critical Care, Universities of Giessen and Marburg Lung Center (UGMLC), German Center for Lung Research (DZL), Justus-Liebig University Giessen, Giessen, Germany.
Department of Medicine V, Internal Medicine, Infectious Diseases and Infection Control, Universities of Giessen and Marburg Lung Center (UGMLC), German Center for Lung Research (DZL), Justus-Liebig University Giessen, Giessen, Germany.
Cardio-Pulmonary Institute (CPI), Giessen, Germany.
Institute for Lung Health (ILH), Giessen, Germany.

Chengshui Chen (C)

The Quzhou Affiliated Hospital of Wenzhou Medical University, Quzhou People's Hospital, Quzhou, Zhejiang, China ChengshuiChen@wmu.edu.cn elie.el-agha@innere.med.uni-giessen.de bernard.mari@unice.fr saverio.bellusci@innere.med.uni-giessen.de.

Elie El Agha (E)

Department of Medicine V, Internal Medicine, Infectious Diseases and Infection Control, Universities of Giessen and Marburg Lung Center (UGMLC), German Center for Lung Research (DZL), Justus-Liebig University Giessen, Giessen, Germany.
Cardio-Pulmonary Institute (CPI), Giessen, Germany.
Institute for Lung Health (ILH), Giessen, Germany.

Bernard Mari (B)

Université Côte d'Azur, UMR CNRS 7275 Inserm 1323, IPMC, FHU-OncoAge, IHU RespiERA, , Valbonne, France.

Saverio Bellusci (S)

The Quzhou Affiliated Hospital of Wenzhou Medical University, Quzhou People's Hospital, Quzhou, Zhejiang, China.
Laboratory of Extracellular Lung Matrix Remodelling, Department of Internal Medicine, Cardio-Pulmonary Institute and Institute for Lung Health, Universities of Giessen and Marburg Lung Center (UGMLC), The German Center for Lung Research (DZL), Justus-Liebig University Giessen, Giessen, Germany.

Classifications MeSH