Caspase 1 activity influences juvenile Batten disease (CLN3) pathogenesis.


Journal

Journal of neurochemistry
ISSN: 1471-4159
Titre abrégé: J Neurochem
Pays: England
ID NLM: 2985190R

Informations de publication

Date de publication:
03 2019
Historique:
received: 18 04 2018
revised: 30 05 2018
accepted: 04 06 2018
pubmed: 7 6 2018
medline: 29 10 2019
entrez: 7 6 2018
Statut: ppublish

Résumé

Juvenile Neuronal Ceroid Lipofuscinosis (JNCL) is an autosomal recessive lysosomal storage disease caused by loss-of-function mutations in CLN3. Symptoms appear between 5 and 10 years of age, beginning with blindness and seizures, followed by progressive cognitive and motor decline, and premature death. Glial activation and impaired neuronal activity are early signs of pathology in the Cln3

Identifiants

pubmed: 29873075
doi: 10.1111/jnc.14480
doi:

Substances chimiques

Casp1 protein, mouse EC 3.4.22.36
Caspase 1 EC 3.4.22.36

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

652-668

Informations de copyright

© 2018 International Society for Neurochemistry.

Auteurs

Maria Burkovetskaya (M)

Department of Pathology and Microbiology, University of Nebraska Medical Center, Omaha, Nebraska, USA.

Megan E Bosch (ME)

Department of Pathology and Microbiology, University of Nebraska Medical Center, Omaha, Nebraska, USA.

Nikolay Karpuk (N)

Department of Pathology and Microbiology, University of Nebraska Medical Center, Omaha, Nebraska, USA.

Rachel Fallet (R)

Department of Pathology and Microbiology, University of Nebraska Medical Center, Omaha, Nebraska, USA.

Tammy Kielian (T)

Department of Pathology and Microbiology, University of Nebraska Medical Center, Omaha, Nebraska, USA.

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Classifications MeSH