Regional variation and cost implications of prescribed extended half-life factor concentrates among U.S. Haemophilia Treatment Centres for patients with moderate and severe haemophilia.


Journal

Haemophilia : the official journal of the World Federation of Hemophilia
ISSN: 1365-2516
Titre abrégé: Haemophilia
Pays: England
ID NLM: 9442916

Informations de publication

Date de publication:
Jul 2019
Historique:
received: 13 02 2019
revised: 17 03 2019
accepted: 18 03 2019
pubmed: 18 4 2019
medline: 19 12 2019
entrez: 18 4 2019
Statut: ppublish

Résumé

Extended half-life (EHL) factor VIII (FVIII) and IX (FIX) products are intended to decrease the burden of prophylaxis for patients with haemophilia A or B. Whether these newer concentrates have led to meaningful clinical practice change remains vague. To characterize the longitudinal use of standard (SHL) and EHL factor concentrates at haemophilia treatment centres (HTCs), using the ATHNdataset, a US database of 138 ATHN-affiliated HTCs. Factor concentrate use among moderate and severe haemophilia A and B patients without inhibitors was analysed at three time points over 18 months. Use of EHL concentrates rose from 10% of patients to 22% during this study. EHL FVIII prophylaxis is prescribed to the minority of patients, 28%; EHL FIX now predominates for prophylaxis, 52%. Rates of prescribed EHL products varied significantly by age group and HTC region. Median prescribed prophylaxis for SHL compared to EHL products was FVIII 6240 and 5200 and FIX 6968 and FIX 3900 IU/kg/y, respectively. On-demand EHL use has grown but has minimal contribution to overall usage (2%). Haemophilia treatment centre region and patient age impact the rate of adoption of EHL products; however, EHL prescribing continues to rise nationally, particularly for EHL FIX. Careful attention to annual cost of prophylaxis is imperative as the decrease in median EHL prophylaxis consumption is not offset by the higher unit cost of these products. It is unclear how further growth in use of EHLs will be impacted by emerging non-factor replacement and gene therapies.

Sections du résumé

BACKGROUND BACKGROUND
Extended half-life (EHL) factor VIII (FVIII) and IX (FIX) products are intended to decrease the burden of prophylaxis for patients with haemophilia A or B. Whether these newer concentrates have led to meaningful clinical practice change remains vague.
AIM OBJECTIVE
To characterize the longitudinal use of standard (SHL) and EHL factor concentrates at haemophilia treatment centres (HTCs), using the ATHNdataset, a US database of 138 ATHN-affiliated HTCs.
METHODS METHODS
Factor concentrate use among moderate and severe haemophilia A and B patients without inhibitors was analysed at three time points over 18 months.
RESULTS RESULTS
Use of EHL concentrates rose from 10% of patients to 22% during this study. EHL FVIII prophylaxis is prescribed to the minority of patients, 28%; EHL FIX now predominates for prophylaxis, 52%. Rates of prescribed EHL products varied significantly by age group and HTC region. Median prescribed prophylaxis for SHL compared to EHL products was FVIII 6240 and 5200 and FIX 6968 and FIX 3900 IU/kg/y, respectively. On-demand EHL use has grown but has minimal contribution to overall usage (2%).
CONCLUSION CONCLUSIONS
Haemophilia treatment centre region and patient age impact the rate of adoption of EHL products; however, EHL prescribing continues to rise nationally, particularly for EHL FIX. Careful attention to annual cost of prophylaxis is imperative as the decrease in median EHL prophylaxis consumption is not offset by the higher unit cost of these products. It is unclear how further growth in use of EHLs will be impacted by emerging non-factor replacement and gene therapies.

Identifiants

pubmed: 30993845
doi: 10.1111/hae.13758
doi:

Substances chimiques

Factor VIII 9001-27-8
Factor IX 9001-28-9

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

668-675

Subventions

Organisme : Hemostasis and Thrombosis Research Society
Organisme : American Thrombosis and Hemostasis Network
Organisme : Hemophilia of Georgia

Informations de copyright

© 2019 John Wiley & Sons Ltd.

Auteurs

Stacy E Croteau (SE)

Boston Children's Hospital, Boston, Massachusetts.

Dunlei Cheng (D)

American Thrombosis and Hemostasis Network, Rochester, New York.

Alice J Cohen (AJ)

Newark Beth Israel Medical Center, Newark, New Jersey.

Chris E Holmes (CE)

University of Vermont, Burlington, Vermont.

Lynn M Malec (LM)

Versiti Blood Center of Wisconsin, Milwaukee, Wisconsin.

Michael Silvey (M)

Children's Mercy Hospital, Kansas City, Missouri.

Courtney D Thornburg (CD)

Rady Children's Hospital San Diego, San Diego, California.

Allison P Wheeler (AP)

Monroe Carell Jr. Children's Hospital at Vanderbilt, Nashville, Tennessee.

Peter A Kouides (PA)

Mary M. Gooley Hemophilia Center, Rochester, New York.

Leslie J Raffini (LJ)

Children's Hospital of Philadelphia, Philadelphia, Pennsylvania.

Ellis J Neufeld (EJ)

St. Jude Children's Research Hospital, Memphis, Tennessee.

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