Secondary actionable findings identified by exome sequencing: expected impact on the organisation of care from the study of 700 consecutive tests.
Journal
European journal of human genetics : EJHG
ISSN: 1476-5438
Titre abrégé: Eur J Hum Genet
Pays: England
ID NLM: 9302235
Informations de publication
Date de publication:
08 2019
08 2019
Historique:
received:
23
02
2018
accepted:
05
03
2019
revised:
08
02
2019
pubmed:
26
4
2019
medline:
17
6
2020
entrez:
26
4
2019
Statut:
ppublish
Résumé
With exome/genome sequencing (ES/GS) integrated into the practice of medicine, there is some potential for reporting incidental/secondary findings (IFs/SFs). The issue of IFs/SFs has been studied extensively over the last 4 years. In order to evaluate their implications in care organisation, we retrospectively evaluated, in a cohort of 700 consecutive probands, the frequency and burden of introducing the search for variants in a maximum list of 244 medically actionable genes (genes that predispose carriers to a preventable or treatable disease in childhood/adulthood and genes for genetic counselling issues). We also focused on the 59 PharmGKB class IA/IB pharmacogenetic variants. We also compared the results in different gene lists. We identified variants (likely) affecting protein function in genes for care in 26 cases (3.7%) and heterozygous variants in genes for genetic counselling in 29 cases (3.8%). Mean time for the 700 patients was about 6.3 min/patient for medically actionable genes and 1.3 min/patient for genes for genetic counselling, and a mean time of 37 min/patients for the reinterpreted variants. These results would lead to all 700 pre-test counselling sessions being longer, to 55 post-test genetic consultations and to 27 secondary specialised medical evaluations. ES also detected 42/59 pharmacogenetic variants or combinations of variants in the majority of cases. An extremely low metabolizer status in genes relevant for neurodevelopmental disorders (CYP2C9 and CYP2C19) was found in 57/700 cases. This study provides information regarding the need to anticipate the implementation of genomic medicine, notably the work overload at various steps of the process.
Identifiants
pubmed: 31019283
doi: 10.1038/s41431-019-0384-7
pii: 10.1038/s41431-019-0384-7
pmc: PMC6777608
doi:
Types de publication
Journal Article
Research Support, N.I.H., Extramural
Research Support, Non-U.S. Gov't
Langues
eng
Sous-ensembles de citation
IM
Pagination
1197-1214Subventions
Organisme : NHLBI NIH HHS
ID : UC2 HL103010
Pays : United States
Organisme : NHLBI NIH HHS
ID : RC2 HL102926
Pays : United States
Organisme : NHLBI NIH HHS
ID : RC2 HL102924
Pays : United States
Organisme : NHLBI NIH HHS
ID : RC2 HL103010
Pays : United States
Organisme : NHLBI NIH HHS
ID : RC2 HL102923
Pays : United States
Organisme : NHLBI NIH HHS
ID : UC2 HL102926
Pays : United States
Organisme : NHLBI NIH HHS
ID : UC2 HL102923
Pays : United States
Organisme : NHLBI NIH HHS
ID : UC2 HL102924
Pays : United States
Organisme : NHLBI NIH HHS
ID : RC2 HL102925
Pays : United States
Organisme : NHLBI NIH HHS
ID : UC2 HL102925
Pays : United States
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