Pioglitazone and Deoxyribonucleoside Combination Treatment Increases Mitochondrial Respiratory Capacity in m.3243A>G MELAS Cybrid Cells.
Cell Line, Tumor
Cell Respiration
/ drug effects
DNA, Mitochondrial
/ genetics
Deoxyribonucleosides
/ pharmacology
Gene Dosage
Humans
Hybrid Cells
/ drug effects
MELAS Syndrome
/ genetics
Mitochondria
/ drug effects
Mutation
/ genetics
Oxidative Phosphorylation
/ drug effects
Pioglitazone
/ pharmacology
RNA, Messenger
/ genetics
MELAS
OXPHOS
cybrid
deoxyribonucleosides
mitochondrial biogenesis
mitochondrial disease
oxidative phosphorylation
pioglitazone
Journal
International journal of molecular sciences
ISSN: 1422-0067
Titre abrégé: Int J Mol Sci
Pays: Switzerland
ID NLM: 101092791
Informations de publication
Date de publication:
20 Mar 2020
20 Mar 2020
Historique:
received:
29
01
2020
revised:
17
03
2020
accepted:
17
03
2020
entrez:
5
4
2020
pubmed:
5
4
2020
medline:
6
1
2021
Statut:
epublish
Résumé
The lack of effective treatments for mitochondrial disease has seen the development of new approaches, including those that aim to stimulate mitochondrial biogenesis to boost ATP generation above a critical disease threshold. Here, we examine the effects of the peroxisome proliferator-activated receptor γ (PPARγ) activator pioglitazone (PioG), in combination with deoxyribonucleosides (dNs), on mitochondrial biogenesis in cybrid cells containing >90% of the m.3243A>G mutation associated with mitochondrial encephalopathy, lactic acidosis, and stroke-like episodes (MELAS). PioG + dNs combination treatment increased mtDNA copy number and mitochondrial mass in both control (CON) and m.3243A>G (MUT) cybrids, with no adverse effects on cell proliferation. PioG + dNs also increased mtDNA-encoded transcripts in CON cybrids, but had the opposite effect in MUT cybrids, reducing the already elevated transcript levels. Steady-state levels of mature oxidative phosphorylation (OXPHOS) protein complexes were increased by PioG + dNs treatment in CON cybrids, but were unchanged in MUT cybrids. However, treatment was able to significantly increase maximal mitochondrial oxygen consumption rates and cell respiratory control ratios in both CON and MUT cybrids. Overall, these findings highlight the ability of PioG + dNs to improve mitochondrial respiratory function in cybrid cells containing the m.3243A>G MELAS mutation, as well as their potential for development into novel therapies to treat mitochondrial disease.
Identifiants
pubmed: 32244971
pii: ijms21062139
doi: 10.3390/ijms21062139
pmc: PMC7139379
pii:
doi:
Substances chimiques
DNA, Mitochondrial
0
Deoxyribonucleosides
0
RNA, Messenger
0
Pioglitazone
X4OV71U42S
Types de publication
Journal Article
Langues
eng
Sous-ensembles de citation
IM
Subventions
Organisme : Department of Education, Employment and Workplace Relations, Australian Government
ID : XX
Organisme : Deakin University
ID : XX
Organisme : Australian Mitochondrial Disease Foundation
ID : XX
Organisme : National Health and Medical Research Council
ID : GNT1159795
Organisme : State Government of Victoria
ID : XX
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