Chromatin accessibility landscape of pediatric T-lymphoblastic leukemia and human T-cell precursors.


Journal

EMBO molecular medicine
ISSN: 1757-4684
Titre abrégé: EMBO Mol Med
Pays: England
ID NLM: 101487380

Informations de publication

Date de publication:
07 09 2020
Historique:
received: 01 02 2020
revised: 19 06 2020
accepted: 24 06 2020
pubmed: 6 8 2020
medline: 19 8 2021
entrez: 6 8 2020
Statut: ppublish

Résumé

We aimed at identifying the developmental stage at which leukemic cells of pediatric T-ALLs are arrested and at defining leukemogenic mechanisms based on ATAC-Seq. Chromatin accessibility maps of seven developmental stages of human healthy T cells revealed progressive chromatin condensation during T-cell maturation. Developmental stages were distinguished by 2,823 signature chromatin regions with 95% accuracy. Open chromatin surrounding SAE1 was identified to best distinguish thymic developmental stages suggesting a potential role of SUMOylation in T-cell development. Deconvolution using signature regions revealed that T-ALLs, including those with mature immunophenotypes, resemble the most immature populations, which was confirmed by TF-binding motif profiles. We integrated ATAC-Seq and RNA-Seq and found DAB1, a gene not related to leukemia previously, to be overexpressed, abnormally spliced and hyper-accessible in T-ALLs. DAB1-negative patients formed a distinct subgroup with particularly immature chromatin profiles and hyper-accessible binding sites for SPI1 (PU.1), a TF crucial for normal T-cell maturation. In conclusion, our analyses of chromatin accessibility and TF-binding motifs showed that pediatric T-ALL cells are most similar to immature thymic precursors, indicating an early developmental arrest.

Identifiants

pubmed: 32755029
doi: 10.15252/emmm.202012104
pmc: PMC7507092
doi:

Substances chimiques

Chromatin 0

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

e12104

Subventions

Organisme : José Carreras Leukämie-Stiftung (José Carreras Leukämie-Stiftung e.V.)
Pays : International
Organisme : Manfred Lautenschläger-Stiftung (Manfred Lautenschläger Foundation)
Pays : International
Organisme : Aktion fuer krebskranke Kinder e.V. Heidelberg
Pays : International
Organisme : Baden-Württemberg Stiftung (Baden-Württemberg Foundation)
Pays : International

Informations de copyright

© 2020 The Authors. Published under the terms of the CC BY 4.0 license.

Références

Nat Commun. 2016 Jun 27;7:11938
pubmed: 27346425
Blood. 2011 Aug 18;118(7):1854-64
pubmed: 21670474
Nat Genet. 2017 Aug;49(8):1274-1281
pubmed: 28671687
Nat Genet. 2016 Oct;48(10):1193-203
pubmed: 27526324
EMBO Mol Med. 2020 Sep 7;12(9):e12104
pubmed: 32755029
Bioinformatics. 2019 Jul 15;35(14):2489-2491
pubmed: 30520945
Nat Methods. 2013 Dec;10(12):1213-8
pubmed: 24097267
Cell. 1997 Mar 7;88(5):627-36
pubmed: 9054502
Nat Biotechnol. 2010 May;28(5):495-501
pubmed: 20436461
Mol Cell Biol. 2007 Oct;27(20):7113-24
pubmed: 17698586
Immunology. 1997 Jul;91(3):340-5
pubmed: 9301521
Genome Res. 2018 Oct;28(10):1508-1519
pubmed: 30171019
Nature. 1985 Mar 7-13;314(6006):103-7
pubmed: 2983227
Front Cell Neurosci. 2016 Jun 30;10:166
pubmed: 27445693
Database (Oxford). 2017 Jan 1;2017:
pubmed: 28605766
EMBO Mol Med. 2018 Dec;10(12):
pubmed: 30389682
Cold Spring Harb Perspect Biol. 2018 May 1;10(5):
pubmed: 28716889
Genome Biol. 2019 Feb 26;20(1):45
pubmed: 30808370
Nature. 1987 Mar 5-11;326(6108):79-81
pubmed: 3102971
Leukemia. 2008 Dec;22(12):2142-50
pubmed: 18818707
Leukemia. 1995 Oct;9(10):1783-6
pubmed: 7564526
Dev Biol. 2002 Jun 1;246(1):103-21
pubmed: 12027437
Nat Rev Immunol. 2008 Jan;8(1):9-21
pubmed: 18097446
Genome Biol. 2014;15(12):550
pubmed: 25516281
Genome Res. 2009 Jul;19(7):1316-23
pubmed: 19498102
Br J Haematol. 2008 Oct;143(2):153-68
pubmed: 18691165
Blood. 2017 Mar 2;129(9):1113-1123
pubmed: 28115373
Nat Immunol. 2013 Jun;14(6):619-32
pubmed: 23644507
Nat Methods. 2015 May;12(5):453-7
pubmed: 25822800
Neuron. 2008 Oct 23;60(2):273-84
pubmed: 18957219
J Clin Invest. 2012 Oct;122(10):3398-406
pubmed: 23023710
Nat Genet. 2014 Apr;46(4):364-70
pubmed: 24584072
Stem Cell Reports. 2015 Nov 10;5(5):728-740
pubmed: 26489895
Cell. 2019 Feb 7;176(4):897-912.e20
pubmed: 30686579
Front Cell Neurosci. 2016 May 09;10:122
pubmed: 27242434
Lancet Oncol. 2009 Feb;10(2):147-56
pubmed: 19147408
Nucleic Acids Res. 2013 Jan;41(Database issue):D991-5
pubmed: 23193258
Br J Haematol. 2012 Feb;156(3):358-65
pubmed: 22128890
Immunity. 1999 Dec;11(6):653-63
pubmed: 10626888
Nat Rev Mol Cell Biol. 2011 Jan;12(1):36-47
pubmed: 21179060
Nat Rev Immunol. 2014 Aug;14(8):529-45
pubmed: 25060579
Pediatr Blood Cancer. 2016 Jul;63(7):1185-92
pubmed: 26928953
Mol Cell. 2010 May 28;38(4):576-89
pubmed: 20513432
Nucleic Acids Res. 2018 Jan 4;46(D1):D260-D266
pubmed: 29140473
Bioinformatics. 2013 Jan 1;29(1):15-21
pubmed: 23104886
Immunity. 2002 Feb;16(2):285-96
pubmed: 11869688
Annu Rev Immunol. 1999;17:523-54
pubmed: 10358767
Development. 2012 Dec 1;139(23):4321-9
pubmed: 23132242
Nat Med. 2018 Jun;24(6):868-880
pubmed: 29785028

Auteurs

Büşra Erarslan-Uysal (B)

Department of Pediatric Oncology, Hematology, and Immunology, University of Heidelberg, Heidelberg, Germany.
Hopp Children's Cancer Center (KiTZ) Heidelberg, Heidelberg, Germany.
Molecular Medicine Partnership Unit (MMPU), European Molecular Biology Laboratory (EMBL), Heidelberg, Germany.

Joachim B Kunz (JB)

Department of Pediatric Oncology, Hematology, and Immunology, University of Heidelberg, Heidelberg, Germany.
Hopp Children's Cancer Center (KiTZ) Heidelberg, Heidelberg, Germany.
Molecular Medicine Partnership Unit (MMPU), European Molecular Biology Laboratory (EMBL), Heidelberg, Germany.
German Consortium for Translational Cancer Research (DKTK), Heidelberg, Germany.

Tobias Rausch (T)

Molecular Medicine Partnership Unit (MMPU), European Molecular Biology Laboratory (EMBL), Heidelberg, Germany.
Genome Biology Unit, European Molecular Biology Laboratory (EMBL), Heidelberg, Germany.
Genomics Core Facility, European Molecular Biology Laboratory (EMBL), Heidelberg, Germany.

Paulina Richter-Pechańska (P)

Department of Pediatric Oncology, Hematology, and Immunology, University of Heidelberg, Heidelberg, Germany.
Hopp Children's Cancer Center (KiTZ) Heidelberg, Heidelberg, Germany.
Molecular Medicine Partnership Unit (MMPU), European Molecular Biology Laboratory (EMBL), Heidelberg, Germany.

Ianthe Aem van Belzen (IA)

Genome Biology Unit, European Molecular Biology Laboratory (EMBL), Heidelberg, Germany.

Viktoras Frismantas (V)

Genomics Core Facility, European Molecular Biology Laboratory (EMBL), Heidelberg, Germany.

Beat Bornhauser (B)

Division of Pediatric Oncology, University Children's Hospital, Zürich, Switzerland.

Diana Ordoñez-Rueada (D)

Flow Cytometry Core Facility, European Molecular Biology Laboratory (EMBL), Heidelberg, Germany.

Malte Paulsen (M)

Flow Cytometry Core Facility, European Molecular Biology Laboratory (EMBL), Heidelberg, Germany.

Vladimir Benes (V)

Genomics Core Facility, European Molecular Biology Laboratory (EMBL), Heidelberg, Germany.

Martin Stanulla (M)

Department of Pediatric Hematology and Oncology, Hannover Medical School, Hannover, Germany.

Martin Schrappe (M)

Department of Pediatrics, University Hospital Schleswig-Holstein, Kiel, Germany.

Gunnar Cario (G)

Department of Pediatrics, University Hospital Schleswig-Holstein, Kiel, Germany.

Gabriele Escherich (G)

Clinic of Pediatric Hematology and Oncology, University Medical Center Hamburg-Eppendorf, Hamburg, Germany.

Kseniya Bakharevich (K)

Clinic of Pediatric Hematology and Oncology, University Medical Center Hamburg-Eppendorf, Hamburg, Germany.

Renate Kirschner-Schwabe (R)

Department of Pediatric Oncology/Hematology, Charité Universitätsmedizin Berlin, Berlin, Germany.

Cornelia Eckert (C)

Department of Pediatric Oncology/Hematology, Charité Universitätsmedizin Berlin, Berlin, Germany.

Tsvetomir Loukanov (T)

Department of Cardiac Surgery, University of Heidelberg, Heidelberg, Germany.

Matthias Gorenflo (M)

Department of Pediatric Cardiology and Congenital Heart Diseases, University of Heidelberg, Heidelberg, Germany.

Sebastian M Waszak (SM)

Genome Biology Unit, European Molecular Biology Laboratory (EMBL), Heidelberg, Germany.

Jean-Pierre Bourquin (JP)

Division of Pediatric Oncology, University Children's Hospital, Zürich, Switzerland.

Martina U Muckenthaler (MU)

Department of Pediatric Oncology, Hematology, and Immunology, University of Heidelberg, Heidelberg, Germany.
Hopp Children's Cancer Center (KiTZ) Heidelberg, Heidelberg, Germany.
Molecular Medicine Partnership Unit (MMPU), European Molecular Biology Laboratory (EMBL), Heidelberg, Germany.

Jan O Korbel (JO)

Molecular Medicine Partnership Unit (MMPU), European Molecular Biology Laboratory (EMBL), Heidelberg, Germany.
Genome Biology Unit, European Molecular Biology Laboratory (EMBL), Heidelberg, Germany.

Andreas E Kulozik (AE)

Department of Pediatric Oncology, Hematology, and Immunology, University of Heidelberg, Heidelberg, Germany.
Hopp Children's Cancer Center (KiTZ) Heidelberg, Heidelberg, Germany.
Molecular Medicine Partnership Unit (MMPU), European Molecular Biology Laboratory (EMBL), Heidelberg, Germany.

Articles similaires

[Redispensing of expensive oral anticancer medicines: a practical application].

Lisanne N van Merendonk, Kübra Akgöl, Bastiaan Nuijen
1.00
Humans Antineoplastic Agents Administration, Oral Drug Costs Counterfeit Drugs

Smoking Cessation and Incident Cardiovascular Disease.

Jun Hwan Cho, Seung Yong Shin, Hoseob Kim et al.
1.00
Humans Male Smoking Cessation Cardiovascular Diseases Female
Humans United States Aged Cross-Sectional Studies Medicare Part C
1.00
Humans Yoga Low Back Pain Female Male

Classifications MeSH