B-Cell-Specific Myd88 L252P Expression Causes a Premalignant Gammopathy Resembling IgM MGUS.


Journal

Frontiers in immunology
ISSN: 1664-3224
Titre abrégé: Front Immunol
Pays: Switzerland
ID NLM: 101560960

Informations de publication

Date de publication:
2020
Historique:
received: 04 09 2020
accepted: 19 10 2020
entrez: 21 12 2020
pubmed: 22 12 2020
medline: 22 6 2021
Statut: epublish

Résumé

A highly recurrent somatic L265P mutation in the TIR domain of the signaling adapter MYD88 constitutively activates NF-κB. It occurs in nearly all human patients with Waldenström's macroglobulinemia (WM), a B cell malignancy caused by IgM-expressing cells. Here, we introduced an inducible leucine to proline point mutation into the mouse Myd88 locus, at the orthologous position L252P. When the mutation was introduced early during B cell development, B cells developed normally. However, IgM-expressing plasma cells accumulated with age in spleen and bone, leading to more than 20-fold elevated serum IgM titers. When introduced into germinal center B cells in the context of an immunization, the Myd88

Identifiants

pubmed: 33343574
doi: 10.3389/fimmu.2020.602868
pmc: PMC7747680
doi:

Substances chimiques

Immunoglobulin M 0
Myd88 protein, mouse 0
Myeloid Differentiation Factor 88 0
Paraproteins 0

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

602868

Informations de copyright

Copyright © 2020 Schmidt, Sack, Graf, Winkler, Popp, Mertins, Sommermann, Kocks and Rajewsky.

Déclaration de conflit d'intérêts

The authors declare that the research was conducted in the absence of any commercial or financial relationships that could be construed as a potential conflict of interest.

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Auteurs

Kristin Schmidt (K)

Immune Regulation and Cancer, Max Delbrück Center for Molecular Medicine in the Helmholtz Association, Berlin, Germany.

Ulrike Sack (U)

Immune Regulation and Cancer, Max Delbrück Center for Molecular Medicine in the Helmholtz Association, Berlin, Germany.

Robin Graf (R)

Immune Regulation and Cancer, Max Delbrück Center for Molecular Medicine in the Helmholtz Association, Berlin, Germany.

Wiebke Winkler (W)

Biology of Malignant Lymphomas, Max Delbrück Center for Molecular Medicine in the Helmholtz Association, Berlin, Germany.

Oliver Popp (O)

Proteomics, Max Delbrück Center for Molecular Medicine in the Helmholtz Association, Berlin, Germany.

Philipp Mertins (P)

Proteomics, Max Delbrück Center for Molecular Medicine in the Helmholtz Association, Berlin, Germany.

Thomas Sommermann (T)

Immune Regulation and Cancer, Max Delbrück Center for Molecular Medicine in the Helmholtz Association, Berlin, Germany.

Christine Kocks (C)

Immune Regulation and Cancer, Max Delbrück Center for Molecular Medicine in the Helmholtz Association, Berlin, Germany.
Transgenics, Max Delbrück Center for Molecular Medicine in the Helmholtz Association, Berlin, Germany.

Klaus Rajewsky (K)

Immune Regulation and Cancer, Max Delbrück Center for Molecular Medicine in the Helmholtz Association, Berlin, Germany.

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Classifications MeSH