Preclinical Optimization and Safety Studies of a New Lentiviral Gene Therapy for p47


Journal

Human gene therapy
ISSN: 1557-7422
Titre abrégé: Hum Gene Ther
Pays: United States
ID NLM: 9008950

Informations de publication

Date de publication:
09 2021
Historique:
pubmed: 21 3 2021
medline: 1 2 2022
entrez: 20 3 2021
Statut: ppublish

Résumé

Chronic granulomatous disease (CGD) is an inherited blood disorder of phagocytic cells that renders patients susceptible to infections and inflammation. A recent clinical trial of lentiviral gene therapy for the most frequent form of CGD, X-linked, has demonstrated stable correction over time, with no adverse events related to the gene therapy procedure. We have recently developed a parallel lentiviral vector for p47

Identifiants

pubmed: 33740872
doi: 10.1089/hum.2020.276
pmc: PMC8575060
doi:

Substances chimiques

NADPH Oxidases EC 1.6.3.-

Types de publication

Journal Article Research Support, N.I.H., Intramural Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

949-958

Subventions

Organisme : Wellcome Trust
ID : 217112/Z/19/Z
Pays : United Kingdom
Organisme : Intramural NIH HHS
ID : ZIA AI000989
Pays : United States
Organisme : Intramural NIH HHS
ID : ZIA AI000644
Pays : United States

Références

Cell Stem Cell. 2018 Dec 6;23(6):820-832.e9
pubmed: 30416070
Mol Ther. 2009 Nov;17(11):1919-28
pubmed: 19672245
Nat Med. 2006 Apr;12(4):401-9
pubmed: 16582916
J Pediatric Infect Dis Soc. 2018 May 9;7(suppl_1):S2-S5
pubmed: 29746675
J Allergy Clin Immunol. 2013 Nov;132(5):1156-1163.e5
pubmed: 23910690
J Clin Immunol. 2011 Aug;31(4):699-709
pubmed: 21544592
Gene Ther. 2020 Sep;27(9):459-469
pubmed: 32533104
Scand J Immunol. 2019 Feb;89(2):e12737
pubmed: 30506560
Hum Gene Ther Clin Dev. 2017 Mar;28(1):17-27
pubmed: 28319446
N Engl J Med. 2010 Dec 30;363(27):2600-10
pubmed: 21190454
J Immunol. 2012 May 15;188(10):5003-11
pubmed: 22491245
J Am Assoc Lab Anim Sci. 2010 Jul;49(4):480-6
pubmed: 20819397
Mol Ther. 2011 Jan;19(1):122-32
pubmed: 20978475
Mol Ther. 2021 Jan 6;29(1):86-102
pubmed: 33010230
Nat Med. 2010 Feb;16(2):198-204
pubmed: 20098431
Mol Ther Methods Clin Dev. 2019 Apr 04;13:390-398
pubmed: 31024981
Hum Gene Ther. 2016 Sep;27(9):668-78
pubmed: 27056660
Front Pediatr. 2020 Jun 26;8:327
pubmed: 32676488
Blood. 2006 Oct 15;108(8):2545-53
pubmed: 16825499
Scand J Immunol. 2019 Jul;90(1):e12767
pubmed: 30963593
J Allergy Clin Immunol. 2018 Jan;141(1):365-371
pubmed: 28528201
Am J Pathol. 2009 Jan;174(1):153-63
pubmed: 19095958
Nat Med. 2020 Feb;26(2):200-206
pubmed: 31988463
Mol Ther Methods Clin Dev. 2019 Jun 07;14:134-147
pubmed: 31338385
J Gene Med. 2012 Aug;14(8):549-60
pubmed: 22887595
Adv Ther. 2017 Dec;34(12):2543-2557
pubmed: 29168144
Blood. 2019 Jun 6;133(23):2546-2549
pubmed: 30952673
Hum Gene Ther Clin Dev. 2018 Jun;29(2):69-79
pubmed: 29664709

Auteurs

Andrea Schejtman (A)

Molecular and Cellular Immunology Unit, UCL Great Ormond Street Institute of Child Health, University College London, London, United Kingdom.

Winston Vetharoy (W)

Molecular and Cellular Immunology Unit, UCL Great Ormond Street Institute of Child Health, University College London, London, United Kingdom.

Uimook Choi (U)

Laboratory of Clinical Immunology and Microbiology, National Institute of Allergy and Infectious Diseases, National Institutes of Health, Bethesda, Maryland, USA.

Christine Rivat (C)

Great Ormond Street Hospital for Children, NHS Foundation Trust, London, United Kingdom.

Narda Theobald (N)

Laboratory of Clinical Immunology and Microbiology, National Institute of Allergy and Infectious Diseases, National Institutes of Health, Bethesda, Maryland, USA.

Giuseppa Piras (G)

Molecular and Cellular Immunology Unit, UCL Great Ormond Street Institute of Child Health, University College London, London, United Kingdom.

Diego Leon-Rico (D)

Molecular and Cellular Immunology Unit, UCL Great Ormond Street Institute of Child Health, University College London, London, United Kingdom.

Karen Buckland (K)

Molecular and Cellular Immunology Unit, UCL Great Ormond Street Institute of Child Health, University College London, London, United Kingdom.

Elena Armenteros-Monterroso (E)

Molecular and Cellular Immunology Unit, UCL Great Ormond Street Institute of Child Health, University College London, London, United Kingdom.

Sara Benedetti (S)

Molecular and Cellular Immunology Unit, UCL Great Ormond Street Institute of Child Health, University College London, London, United Kingdom.

Michael T Ashworth (MT)

Department of Histopathology, Great Ormond Street Hospital for Children, NHS Foundation Trust, London, United Kingdom.

Michael Rothe (M)

Institute of Experimental Hematology, Hannover Medical School, Hannover, Germany.

Axel Schambach (A)

Institute of Experimental Hematology, Hannover Medical School, Hannover, Germany.
Division of Hematology/Oncology, Boston Children's Hospital, Harvard Medical School, Boston, Massachusetts, USA.

Hubert Bobby Gaspar (HB)

Orchard Therapeutics, London, United Kingdom.

Elizabeth M Kang (EM)

Laboratory of Clinical Immunology and Microbiology, National Institute of Allergy and Infectious Diseases, National Institutes of Health, Bethesda, Maryland, USA.

Harry L Malech (HL)

Laboratory of Clinical Immunology and Microbiology, National Institute of Allergy and Infectious Diseases, National Institutes of Health, Bethesda, Maryland, USA.

Adrian J Thrasher (AJ)

Molecular and Cellular Immunology Unit, UCL Great Ormond Street Institute of Child Health, University College London, London, United Kingdom.
Great Ormond Street Hospital for Children, NHS Foundation Trust, London, United Kingdom.

Giorgia Santilli (G)

Molecular and Cellular Immunology Unit, UCL Great Ormond Street Institute of Child Health, University College London, London, United Kingdom.

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Classifications MeSH