Rare loss-of-function variants in type I IFN immunity genes are not associated with severe COVID-19.


Journal

The Journal of clinical investigation
ISSN: 1558-8238
Titre abrégé: J Clin Invest
Pays: United States
ID NLM: 7802877

Informations de publication

Date de publication:
15 07 2021
Historique:
received: 19 01 2021
accepted: 25 05 2021
pubmed: 28 5 2021
medline: 23 7 2021
entrez: 27 5 2021
Statut: ppublish

Résumé

A recent report found that rare predicted loss-of-function (pLOF) variants across 13 candidate genes in TLR3- and IRF7-dependent type I IFN pathways explain up to 3.5% of severe COVID-19 cases. We performed whole-exome or whole-genome sequencing of 1,864 COVID-19 cases (713 with severe and 1,151 with mild disease) and 15,033 ancestry-matched population controls across 4 independent COVID-19 biobanks. We tested whether rare pLOF variants in these 13 genes were associated with severe COVID-19. We identified only 1 rare pLOF mutation across these genes among 713 cases with severe COVID-19 and observed no enrichment of pLOFs in severe cases compared to population controls or mild COVID-19 cases. We found no evidence of association of rare LOF variants in the 13 candidate genes with severe COVID-19 outcomes.

Identifiants

pubmed: 34043590
pii: e147834
doi: 10.1172/JCI147834
pmc: PMC8279578
doi:
pii:

Substances chimiques

IRF7 protein, human 0
Interferon Regulatory Factor-7 0
Interferon Type I 0
TLR3 protein, human 0
Toll-Like Receptor 3 0

Types de publication

Journal Article Research Support, N.I.H., Extramural Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Subventions

Organisme : NIA NIH HHS
ID : RF1 AG054023
Pays : United States
Organisme : NCATS NIH HHS
ID : UL1 TR001873
Pays : United States

Commentaires et corrections

Type : UpdateOf
Type : CommentIn

Références

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pubmed: 19189911
Nat Rev Genet. 2019 Dec;20(12):747-759
pubmed: 31605095
Science. 2020 Oct 23;370(6515):
pubmed: 32972995
JAMA Cardiol. 2021 Apr 1;6(4):379-386
pubmed: 33326012

Auteurs

Gundula Povysil (G)

Institute for Genomic Medicine, Columbia University, New York, New York, USA.

Guillaume Butler-Laporte (G)

Lady Davis Institute for Medical Research, Montréal, Québec, Canada.
Department of Epidemiology, Biostatistics, and Occupational Health, McGill University, Montréal, Québec, Canada.

Ning Shang (N)

Division of Nephrology, Department of Medicine, Vagelos College of Physicians & Surgeons, Columbia University, New York, New York, USA.

Chen Wang (C)

Division of Nephrology, Department of Medicine, Vagelos College of Physicians & Surgeons, Columbia University, New York, New York, USA.

Atlas Khan (A)

Division of Nephrology, Department of Medicine, Vagelos College of Physicians & Surgeons, Columbia University, New York, New York, USA.

Manal Alaamery (M)

Developmental Medicine Department, King Abdullah International Medical Research Center, King Saud Bin Abdulaziz University for Health Sciences, King Abdulaziz Medical City, Ministry of National Guard Health Affairs, Riyadh, Saudi Arabia.
Saudi Human Genome Project at King Abdulaziz City for Science and Technology, Riyadh, Saudi Arabia.

Tomoko Nakanishi (T)

Lady Davis Institute for Medical Research, Montréal, Québec, Canada.
Department of Human Genetics, McGill University, Montréal, Québec, Canada.
Kyoto-McGill International Collaborative School in Genomic Medicine, Graduate School of Medicine, Kyoto University, Kyoto, Japan.

Sirui Zhou (S)

Lady Davis Institute for Medical Research, Montréal, Québec, Canada.

Vincenzo Forgetta (V)

Lady Davis Institute for Medical Research, Montréal, Québec, Canada.

Robert Jm Eveleigh (RJ)

Canadian Centre for Computational Genomics, McGill University, Montréal, Québec, Canada.
McGill Genome Center, McGill University, Montréal, Québec, Canada.

Mathieu Bourgey (M)

Canadian Centre for Computational Genomics, McGill University, Montréal, Québec, Canada.
McGill Genome Center, McGill University, Montréal, Québec, Canada.

Naveed Aziz (N)

Canadian COVID Genomics Network, HostSeq Project, Canada.

Steven Jm Jones (SJ)

Canadian COVID Genomics Network, HostSeq Project, Canada.

Bartha Knoppers (B)

Canadian COVID Genomics Network, HostSeq Project, Canada.

Stephen W Scherer (SW)

Canadian COVID Genomics Network, HostSeq Project, Canada.

Lisa J Strug (LJ)

Canadian COVID Genomics Network, HostSeq Project, Canada.

Pierre Lepage (P)

Canadian Centre for Computational Genomics, McGill University, Montréal, Québec, Canada.

Jiannis Ragoussis (J)

Department of Human Genetics, McGill University, Montréal, Québec, Canada.
Canadian Centre for Computational Genomics, McGill University, Montréal, Québec, Canada.

Guillaume Bourque (G)

Department of Human Genetics, McGill University, Montréal, Québec, Canada.
McGill Genome Center, McGill University, Montréal, Québec, Canada.
Canadian Centre for Computational Genomics, McGill University, Montréal, Québec, Canada.

Nora Aljawini (N)

KACST-BWH Centre of Excellence for Biomedicine, Joint Centers of Excellence Program, King Abdulaziz City for Science and Technology, Riyadh, Saudi Arabia.

Nour Albes (N)

KACST-BWH Centre of Excellence for Biomedicine, Joint Centers of Excellence Program, King Abdulaziz City for Science and Technology, Riyadh, Saudi Arabia.

Hani M Al-Afghani (HM)

Laboratory Department, Security Forces Hospital, General Directorate of Medical Services, Ministry of Interior, Makkah, Saudi Arabia.

Bader Alghamdi (B)

Developmental Medicine Department, King Abdullah International Medical Research Center, King Saud Bin Abdulaziz University for Health Sciences, King Abdulaziz Medical City, Ministry of National Guard Health Affairs, Riyadh, Saudi Arabia.

Mansour S Almutairi (MS)

Developmental Medicine Department, King Abdullah International Medical Research Center, King Saud Bin Abdulaziz University for Health Sciences, King Abdulaziz Medical City, Ministry of National Guard Health Affairs, Riyadh, Saudi Arabia.

Ebrahim Sabri Mahmoud (ES)

Ministry of the National Guard Health Affairs, King Abdullah International Medical Research Center and King Saud Bin Abdulaziz University for Health Sciences, Riyadh, Saudi Arabia.

Leen Abu-Safieh (L)

Genomics Research Department, Saudi Human Genome Project, King Fahad Medical City and King Abdulaziz City for Science and Technology, Riyadh, Saudi Arabia.

Hadeel El Bardisy (H)

Genomics Research Department, Saudi Human Genome Project, King Fahad Medical City and King Abdulaziz City for Science and Technology, Riyadh, Saudi Arabia.

Fawz S Al Harthi (FSA)

Genomics Research Department, Saudi Human Genome Project, King Fahad Medical City and King Abdulaziz City for Science and Technology, Riyadh, Saudi Arabia.

Abdulraheem Alshareef (A)

College of Applied Medical Sciences, Taibah University, Madina, Saudi Arabia.

Bandar Ali Suliman (BA)

College of Applied Medical Sciences, Taibah University, Madina, Saudi Arabia.

Saleh A Alqahtani (SA)

Liver Transplant Unit, King Faisal Specialist Hospital and Research Centre, Riyadh, Saudi Arabia.
Division of Gastroenterology and Hepatology, Johns Hopkins University, Baltimore, Maryland, USA.

Abdulaziz Almalik (A)

Life Science and Environmental Institute, King Abdulaziz City for Science and Technology, Riyadh, Saudi Arabia.

May M Alrashed (MM)

Department of Clinical Laboratory Sciences, College of Applied Medical Sciences, King Saud University, Riyadh, Saudi Arabia.

Salam Massadeh (S)

Developmental Medicine Department, King Abdullah International Medical Research Center, King Saud Bin Abdulaziz University for Health Sciences, King Abdulaziz Medical City, Ministry of National Guard Health Affairs, Riyadh, Saudi Arabia.
Saudi Human Genome Project at King Abdulaziz City for Science and Technology, Riyadh, Saudi Arabia.

Vincent Mooser (V)

Department of Human Genetics, McGill University, Montréal, Québec, Canada.

Mark Lathrop (M)

Department of Human Genetics, McGill University, Montréal, Québec, Canada.
Canadian COVID Genomics Network, HostSeq Project, Canada.
Canadian Centre for Computational Genomics, McGill University, Montréal, Québec, Canada.

Mohamed Fawzy (M)

Genomics Research Department, Saudi Human Genome Project, King Fahad Medical City and King Abdulaziz City for Science and Technology, Riyadh, Saudi Arabia.

Yaseen M Arabi (YM)

Ministry of the National Guard Health Affairs, King Abdullah International Medical Research Center and King Saud Bin Abdulaziz University for Health Sciences, Riyadh, Saudi Arabia.

Hamdi Mbarek (H)

Qatar Genome Program, Qatar Foundation Research, Development and Innovation, Qatar Foundation, Doha, Qatar.

Chadi Saad (C)

Qatar Genome Program, Qatar Foundation Research, Development and Innovation, Qatar Foundation, Doha, Qatar.

Wadha Al-Muftah (W)

Qatar Genome Program, Qatar Foundation Research, Development and Innovation, Qatar Foundation, Doha, Qatar.

Junghyun Jung (J)

Department of Clinical Pharmacy, School of Pharmacy, University of Southern California, Los Angeles, California, USA.
Department of Preventive Medicine, Keck School of Medicine, University of Southern California, Los Angeles, California, USA.

Serghei Mangul (S)

Department of Clinical Pharmacy, School of Pharmacy, University of Southern California, Los Angeles, California, USA.

Radja Badji (R)

Qatar Genome Program, Qatar Foundation Research, Development and Innovation, Qatar Foundation, Doha, Qatar.

Asma Al Thani (AA)

Qatar Genome Program, Qatar Foundation Research, Development and Innovation, Qatar Foundation, Doha, Qatar.

Said I Ismail (SI)

Qatar Genome Program, Qatar Foundation Research, Development and Innovation, Qatar Foundation, Doha, Qatar.

Ali G Gharavi (AG)

Institute for Genomic Medicine, Columbia University, New York, New York, USA.
Division of Nephrology, Department of Medicine, Vagelos College of Physicians & Surgeons, Columbia University, New York, New York, USA.
Center for Precision Medicine and Genomics, Department of Medicine, Vagelos College of Physicians & Surgeons, Columbia University, New York, New York, USA.

Malak S Abedalthagafi (MS)

Genomics Research Department, Saudi Human Genome Project, King Fahad Medical City and King Abdulaziz City for Science and Technology, Riyadh, Saudi Arabia.

J Brent Richards (JB)

Lady Davis Institute for Medical Research, Montréal, Québec, Canada.
Department of Epidemiology, Biostatistics, and Occupational Health, McGill University, Montréal, Québec, Canada.
Kyoto-McGill International Collaborative School in Genomic Medicine, Graduate School of Medicine, Kyoto University, Kyoto, Japan.
Department of Twin Research, King's College London, London, United Kingdom.

David B Goldstein (DB)

Institute for Genomic Medicine, Columbia University, New York, New York, USA.
Department of Genetics & Development, Columbia University, New York, New York, USA.

Krzysztof Kiryluk (K)

Institute for Genomic Medicine, Columbia University, New York, New York, USA.
Division of Nephrology, Department of Medicine, Vagelos College of Physicians & Surgeons, Columbia University, New York, New York, USA.

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