The Cost of Raising Individuals with Fragile X or Chromosome 15 Imprinting Disorders in Australia.
Angelman syndrome
Chromosome 15 Duplication syndrome
Fragile X syndrome
Health Economics
Prader-Willi syndrome
Journal
Journal of autism and developmental disorders
ISSN: 1573-3432
Titre abrégé: J Autism Dev Disord
Pays: United States
ID NLM: 7904301
Informations de publication
Date de publication:
Apr 2023
Apr 2023
Historique:
accepted:
08
07
2021
medline:
4
4
2023
pubmed:
23
7
2021
entrez:
22
7
2021
Statut:
ppublish
Résumé
The study characterised differences in costs associated with raising a child between four rare disorders and examined the associations between these costs with clinical severity. Caregivers of 108 individuals with Prader-Willi, Angelman (AS), Chromosome 15q Duplication and fragile X (FXS) syndromes completed a modified Client Services Receipt Inventory and participants completed intellectual/developmental functioning and autism assessments. AS incurred the highest yearly costs per individual ($AUD96,994), while FXS had the lowest costs ($AUD33,221). Intellectual functioning negatively predicted total costs, after controlling for diagnosis. The effect of intellectual functioning on total costs for those with AS was significantly different to the other syndromes. The study highlights the significant costs associated with these syndromes, particularly AS, linked with severity of intellectual functioning.
Identifiants
pubmed: 34292487
doi: 10.1007/s10803-021-05193-4
pii: 10.1007/s10803-021-05193-4
doi:
Types de publication
Journal Article
Langues
eng
Sous-ensembles de citation
IM
Pagination
1682-1692Subventions
Organisme : National Health and Medical Research Council
ID : 1049299
Organisme : National Health and Medical Research Council
ID : 1103389
Organisme : Medical Research Future Fund
ID : MRF1141334
Organisme : Financial Markets Foundation for Children
ID : 2017 - 361
Informations de copyright
© 2021. The Author(s), under exclusive licence to Springer Science+Business Media, LLC, part of Springer Nature.
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