In vitro and in vivo drug screens of tumor cells identify novel therapies for high-risk child cancer.


Journal

EMBO molecular medicine
ISSN: 1757-4684
Titre abrégé: EMBO Mol Med
Pays: England
ID NLM: 101487380

Informations de publication

Date de publication:
07 04 2022
Historique:
revised: 25 11 2021
received: 28 05 2021
accepted: 01 12 2021
pubmed: 21 12 2021
medline: 9 4 2022
entrez: 20 12 2021
Statut: ppublish

Résumé

Biomarkers which better match anticancer drugs with cancer driver genes hold the promise of improved clinical responses and cure rates. We developed a precision medicine platform of rapid high-throughput drug screening (HTS) and patient-derived xenografting (PDX) of primary tumor tissue, and evaluated its potential for treatment identification among 56 consecutively enrolled high-risk pediatric cancer patients, compared with conventional molecular genomics and transcriptomics. Drug hits were seen in the majority of HTS and PDX screens, which identified therapeutic options for 10 patients for whom no targetable molecular lesions could be found. Screens also provided orthogonal proof of drug efficacy suggested by molecular analyses and negative results for some molecular findings. We identified treatment options across the whole testing platform for 70% of patients. Only molecular therapeutic recommendations were provided to treating oncologists and led to a change in therapy in 53% of patients, of whom 29% had clinical benefit. These data indicate that in vitro and in vivo drug screening of tumor cells could increase therapeutic options and improve clinical outcomes for high-risk pediatric cancer patients.

Identifiants

pubmed: 34927798
doi: 10.15252/emmm.202114608
pmc: PMC8988207
doi:

Substances chimiques

Antineoplastic Agents 0

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

e14608

Informations de copyright

© 2021 The Authors. Published under the terms of the CC BY 4.0 license.

Références

Nat Protoc. 2007;2(2):247-50
pubmed: 17406581
Cancer Discov. 2013 Dec;3(12):1416-29
pubmed: 24056683
JAMA. 2015 Sep 1;314(9):913-25
pubmed: 26325560
Cancer Biol Ther. 2018;19(12):1078-1087
pubmed: 30299205
Cancer Cell. 2014 Apr 14;25(4):516-29
pubmed: 24684846
Nat Rev Clin Oncol. 2018 Sep;15(9):564-576
pubmed: 29955114
JAMA Oncol. 2016 May 01;2(5):608-615
pubmed: 26822149
Clin Cancer Res. 2017 Oct 15;23(20):6101-6112
pubmed: 28733441
Genome Med. 2016 Dec 23;8(1):133
pubmed: 28007021
Nat Med. 2018 Nov;24(11):1752-1761
pubmed: 30349086
Science. 2013 Nov 15;342(6160):809-11
pubmed: 24233712
Nat Rev Cancer. 2015 Dec;15(12):747-56
pubmed: 26536825
Proc Natl Acad Sci U S A. 2010 Sep 28;107(39):16910-5
pubmed: 20837533
Nat Biotechnol. 2013 Mar;31(3):213-9
pubmed: 23396013
Pediatr Blood Cancer. 2017 Jun;64(6):
pubmed: 27896933
J Vis Exp. 2017 Mar 7;(121):
pubmed: 28362421
Nature. 2017 Sep 7;549(7670):96-100
pubmed: 28854174
Sci Rep. 2019 Apr 23;9(1):6426
pubmed: 31015508
Cancer Cytopathol. 2021 Oct;129(10):805-818
pubmed: 34043284
Nature. 2018 Mar 15;555(7696):371-376
pubmed: 29489755
Bioinformatics. 2016 Oct 1;32(19):3047-8
pubmed: 27312411
Genome Res. 2017 Dec;27(12):2050-2060
pubmed: 29097403
Genome Med. 2017 Apr 24;9(1):38
pubmed: 28438193
Sci Transl Med. 2021 Jan 20;13(577):
pubmed: 33472956
J Neurooncol. 2019 Jan;141(2):253-263
pubmed: 30446898
Eur J Cancer. 2016 Sep;65:91-101
pubmed: 27479119
EMBO Mol Med. 2022 Jan 11;14(1):e14408
pubmed: 34859598
Nat Chem Biol. 2017 Dec;13(12):1222-1231
pubmed: 28991240
Blood. 2004 May 15;103(10):3905-14
pubmed: 14764536
Nat Med. 2020 Nov;26(11):1742-1753
pubmed: 33020650
Nature. 2018 Mar 15;555(7696):321-327
pubmed: 29489754
JAMA Oncol. 2016 May 01;2(5):616-624
pubmed: 26822237
Nat Commun. 2021 Jul 2;12(1):4089
pubmed: 34215733
JAMA Netw Open. 2019 Apr 5;2(4):e192906
pubmed: 31026031
Pediatr Blood Cancer. 2007 Dec;49(7):928-40
pubmed: 17066459
Cancer Discov. 2017 May;7(5):462-477
pubmed: 28331002
Cell. 2017 Jul 27;170(3):564-576.e16
pubmed: 28753430
Lancet Haematol. 2017 Dec;4(12):e595-e606
pubmed: 29153976
Clin Cancer Res. 2016 Aug 1;22(15):3810-20
pubmed: 26994145
Acta Neuropathol. 2020 Aug;140(2):209-225
pubmed: 32519082
Br J Cancer. 2020 Mar;122(5):680-691
pubmed: 31919402
Nat Med. 2017 Sep 8;23(9):1028-1035
pubmed: 28886003

Auteurs

Loretta M S Lau (LMS)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.
School of Women's and Children's Health, UNSW Sydney, Kensington, NSW, Australia.
Kids Cancer Centre, Sydney Children's Hospital, Randwick, NSW, Australia.

Chelsea Mayoh (C)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.
School of Women's and Children's Health, UNSW Sydney, Kensington, NSW, Australia.

Jinhan Xie (J)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.

Paulette Barahona (P)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.

Karen L MacKenzie (KL)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.

Marie Wong (M)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.
School of Women's and Children's Health, UNSW Sydney, Kensington, NSW, Australia.

Alvin Kamili (A)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.
School of Women's and Children's Health, UNSW Sydney, Kensington, NSW, Australia.

Maria Tsoli (M)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.

Tim W Failes (TW)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.
ACRF Drug Discovery Centre for Childhood Cancer, Children's Cancer Institute, Lowy Cancer Research Centre, UNSW Sydney, Sydney, NSW, Australia.

Amit Kumar (A)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.
Children's Cancer Centre, Royal Children's Hospital, Parkville, Vic., Australia.

Emily V A Mould (EVA)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.

Andrew Gifford (A)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.
School of Women's and Children's Health, UNSW Sydney, Kensington, NSW, Australia.

Shu-Oi Chow (SO)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.
ACRF Drug Discovery Centre for Childhood Cancer, Children's Cancer Institute, Lowy Cancer Research Centre, UNSW Sydney, Sydney, NSW, Australia.

Mark Pinese (M)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.
School of Women's and Children's Health, UNSW Sydney, Kensington, NSW, Australia.

Jamie I Fletcher (JI)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.
School of Women's and Children's Health, UNSW Sydney, Kensington, NSW, Australia.

Greg M Arndt (GM)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.
ACRF Drug Discovery Centre for Childhood Cancer, Children's Cancer Institute, Lowy Cancer Research Centre, UNSW Sydney, Sydney, NSW, Australia.

Dong-Anh Khuong-Quang (DA)

Children's Cancer Centre, Royal Children's Hospital, Parkville, Vic., Australia.
Murdoch Children's Research Institute, Royal Children's Hospital, Parkville, Vic., Australia.

Carol Wadham (C)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.

Daniel Batey (D)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.

Georgina Eden (G)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.

Peter Trebilcock (P)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.

Swapna Joshi (S)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.

Stephanie Alfred (S)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.

Anjana Gopalakrishnan (A)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.

Aaminah Khan (A)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.

Dylan Grebert Wade (D)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.

Patrick A Strong (PA)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.

Elodie Manouvrier (E)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.

Lisa T Morgan (LT)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.

Miriam Span (M)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.

Jin Yi Lim (JY)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.

Roxanne Cadiz (R)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.

Caitlin Ung (C)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.

David M Thomas (DM)

Kinghorn Cancer Centre, Garvan Institute of Medical Research, Darlinghurst, NSW, Australia.
Faculty of Medicine, St Vincent's Clinical School, UNSW Sydney, Kensington, NSW, Australia.

Katherine M Tucker (KM)

Hereditary Cancer Centre, Prince of Wales Hospital, Randwick, NSW, Australia.
Prince of Wales Hospital Clinical School, UNSW Sydney, Randwick, NSW, Australia.

Meera Warby (M)

Hereditary Cancer Centre, Prince of Wales Hospital, Randwick, NSW, Australia.

Geoffrey B McCowage (GB)

Cancer Centre for Children, The Children's Hospital at Westmead, Westmead, NSW, Australia.

Luciano Dalla-Pozza (L)

Cancer Centre for Children, The Children's Hospital at Westmead, Westmead, NSW, Australia.

Jennifer A Byrne (JA)

Children's Cancer Research Unit, Kids Research, Westmead, NSW, Australia.
Faculty of Medicine and Health, The University of Sydney, NSW, Australia.

Federica Saletta (F)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.

Andrew Fellowes (A)

Peter MacCallum Cancer Centre, Melbourne, Vic., Australia.

Stephen B Fox (SB)

Peter MacCallum Cancer Centre, Melbourne, Vic., Australia.
Department of Medical Oncology, University of Melbourne, Melbourne, Vic., Australia.

Murray D Norris (MD)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.
School of Women's and Children's Health, UNSW Sydney, Kensington, NSW, Australia.
University of New South Wales Centre for Childhood Cancer Research, UNSW Sydney, Kensington, Vic., Australia.

Vanessa Tyrrell (V)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.

Toby N Trahair (TN)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.
School of Women's and Children's Health, UNSW Sydney, Kensington, NSW, Australia.
Kids Cancer Centre, Sydney Children's Hospital, Randwick, NSW, Australia.

Richard B Lock (RB)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.
School of Women's and Children's Health, UNSW Sydney, Kensington, NSW, Australia.

Mark J Cowley (MJ)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.
School of Women's and Children's Health, UNSW Sydney, Kensington, NSW, Australia.
Kinghorn Centre for Clinical Genomics, Garvan Institute of Medical Research, Darlinghurst, NSW, Australia.

Paul G Ekert (PG)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.
School of Women's and Children's Health, UNSW Sydney, Kensington, NSW, Australia.
Peter MacCallum Cancer Centre, Melbourne, Vic., Australia.

Michelle Haber (M)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.
School of Women's and Children's Health, UNSW Sydney, Kensington, NSW, Australia.

David S Ziegler (DS)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.
School of Women's and Children's Health, UNSW Sydney, Kensington, NSW, Australia.
Kids Cancer Centre, Sydney Children's Hospital, Randwick, NSW, Australia.

Glenn M Marshall (GM)

Children's Cancer Institute, Lowy Cancer Centre, UNSW Sydney, Kensington, NSW, Australia.
School of Women's and Children's Health, UNSW Sydney, Kensington, NSW, Australia.
Kids Cancer Centre, Sydney Children's Hospital, Randwick, NSW, Australia.

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