Celiac Disease After Administration of Immune Checkpoint Inhibitors: A Case Report.


Journal

Frontiers in immunology
ISSN: 1664-3224
Titre abrégé: Front Immunol
Pays: Switzerland
ID NLM: 101560960

Informations de publication

Date de publication:
2021
Historique:
received: 21 10 2021
accepted: 30 11 2021
entrez: 3 1 2022
pubmed: 4 1 2022
medline: 16 2 2022
Statut: epublish

Résumé

Immune checkpoint inhibitors (ICI) reinvigorate the immune system to recognize and destroy tumor cells. Because of this biological mechanism, patients might develop autoimmune toxicities, notably in the digestive tract (most frequently, hepatitis or colitis). A 70-year-old man with relapsed mesothelioma was treated with nivolumab in 3rd line. He was hospitalized for watery and foul-smelling diarrhea. He underwent gastrointestinal endoscopy, showing duodenitis and villous atrophy and measurement of serum IgA antibodies to tissue transglutaminase (tTG-IgA+), leading to the diagnosis of ICI-induced celiac disease. He was treated with steroids, proton pump inhibitors, and a gluten-free diet. If ICI-induced celiac disease is rare in the literature, increasing reports suggest that celiac disease might represent an underestimated ICI toxicity. This case highlights the necessity of complementary investigation (including tTG-IgA and endoscopic biopsies) in patients with atypical digestive symptoms during immunotherapy.

Identifiants

pubmed: 34975913
doi: 10.3389/fimmu.2021.799666
pmc: PMC8718638
doi:

Substances chimiques

Autoantibodies 0
Glucocorticoids 0
Immune Checkpoint Inhibitors 0
Immunoglobulin A 0
PDCD1 protein, human 0
Programmed Cell Death 1 Receptor 0
Proton Pump Inhibitors 0
TGM2 protein, human 0
Nivolumab 31YO63LBSN
Protein Glutamine gamma Glutamyltransferase 2 EC 2.3.2.13

Types de publication

Case Reports Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

799666

Informations de copyright

Copyright © 2021 Leblanc, Hoibian, Boucraut, Ratone, Stoffaes, Dano, Louvel-Perrot, Chanez, Chretien, Madroszyk and Rochigneux.

Déclaration de conflit d'intérêts

The authors declare that the research was conducted in the absence of any commercial or financial relationships that could be construed as a potential conflict of interest.

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Auteurs

Julie Leblanc (J)

Medical Oncology Department, Paoli-Calmettes Institute, Aix-Marseille University, Marseille, France.

Solene Hoibian (S)

Gastroenterology Department, Paoli-Calmettes Institute, Aix-Marseille University, Marseille, France.

Agathe Boucraut (A)

Pathology Department, Paoli-Calmettes Institute, Aix-Marseille University, Marseille, France.

Jean-Philippe Ratone (JP)

Gastroenterology Department, Paoli-Calmettes Institute, Aix-Marseille University, Marseille, France.

Louis Stoffaes (L)

Medical Oncology Department, Paoli-Calmettes Institute, Aix-Marseille University, Marseille, France.

Domitille Dano (D)

Medical Oncology Department, Paoli-Calmettes Institute, Aix-Marseille University, Marseille, France.

Delphine Louvel-Perrot (D)

Medical Oncology Department, Paoli-Calmettes Institute, Aix-Marseille University, Marseille, France.

Brice Chanez (B)

Medical Oncology Department, Paoli-Calmettes Institute, Aix-Marseille University, Marseille, France.

Anne-Sophie Chretien (AS)

Team Immunity and Cancer, Centre de Recherche en Cancérologie de Marseille (CRCM), Inserm, U1068, CNRS, UMR7258, Paoli-Calmettes Institute, Aix-Marseille University, Marseille, France.

Anne Madroszyk (A)

Medical Oncology Department, Paoli-Calmettes Institute, Aix-Marseille University, Marseille, France.

Philippe Rochigneux (P)

Medical Oncology Department, Paoli-Calmettes Institute, Aix-Marseille University, Marseille, France.
Team Immunity and Cancer, Centre de Recherche en Cancérologie de Marseille (CRCM), Inserm, U1068, CNRS, UMR7258, Paoli-Calmettes Institute, Aix-Marseille University, Marseille, France.

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Classifications MeSH