Germline rare variants of lectin pathway genes predispose to asymptomatic SARS-CoV-2 infection in elderly individuals.


Journal

Genetics in medicine : official journal of the American College of Medical Genetics
ISSN: 1530-0366
Titre abrégé: Genet Med
Pays: United States
ID NLM: 9815831

Informations de publication

Date de publication:
08 2022
Historique:
received: 27 10 2021
revised: 04 04 2022
accepted: 05 04 2022
pubmed: 6 5 2022
medline: 11 8 2022
entrez: 5 5 2022
Statut: ppublish

Résumé

Emerging evidence suggest that infection-dependent hyperactivation of complement system (CS) may worsen COVID-19 outcome. We investigated the role of predicted high impact rare variants - referred as qualifying variants (QVs) - of CS genes in predisposing asymptomatic COVID-19 in elderly individuals, known to be more susceptible to severe disease. Exploiting exome sequencing data and 56 CS genes, we performed a gene-based collapsing test between 164 asymptomatic subjects (aged ≥60 years) and 56,885 European individuals from the Genome Aggregation Database. We replicated this test comparing the same asymptomatic individuals with 147 hospitalized patients with COVID-19. We found an enrichment of QVs in 3 genes (MASP1, COLEC11, and COLEC10), which belong to the lectin pathway, in the asymptomatic cohort. Analyses of complement activity in serum showed decreased activity of lectin pathway in asymptomatic individuals with QVs. Finally, we found allelic variants associated with asymptomatic COVID-19 phenotype and with a decreased expression of MASP1, COLEC11, and COLEC10 in lung tissue. This study suggests that genetic rare variants can protect from severe COVID-19 by mitigating the activity of lectin pathway and prothrombin. The genetic data obtained through ES of 786 asymptomatic and 147 hospitalized individuals are publicly available at http://espocovid.ceinge.unina.it/.

Identifiants

pubmed: 35511137
pii: S1098-3600(22)00724-9
doi: 10.1016/j.gim.2022.04.007
pmc: PMC9068606
pii:
doi:

Substances chimiques

COLEC10 protein, human 0
Collectins 0
Lectins 0

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

1653-1663

Informations de copyright

Copyright © 2022 The Authors. Published by Elsevier Inc. All rights reserved.

Déclaration de conflit d'intérêts

Conflict of Interest The authors declare no conflicts of interest.

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Auteurs

Giuseppe D'Alterio (G)

European School of Molecular Medicine, Università degli Studi di Milano, Milan, Italy; CEINGE Biotecnologie Avanzate, Naples, Italy.

Vito Alessandro Lasorsa (VA)

CEINGE Biotecnologie Avanzate, Naples, Italy.

Ferdinando Bonfiglio (F)

Department of Chemical, Materials and Production Engineering, University of Naples Federico II, Naples, Italy.

Sueva Cantalupo (S)

CEINGE Biotecnologie Avanzate, Naples, Italy; Department of Molecular Medicine and Medical Biotechnology, University of Naples Federico II, Naples, Italy.

Barbara Eleni Rosato (BE)

CEINGE Biotecnologie Avanzate, Naples, Italy; Department of Molecular Medicine and Medical Biotechnology, University of Naples Federico II, Naples, Italy.

Immacolata Andolfo (I)

CEINGE Biotecnologie Avanzate, Naples, Italy; Department of Molecular Medicine and Medical Biotechnology, University of Naples Federico II, Naples, Italy.

Roberta Russo (R)

CEINGE Biotecnologie Avanzate, Naples, Italy; Department of Molecular Medicine and Medical Biotechnology, University of Naples Federico II, Naples, Italy.

Umberto Esposito (U)

CEINGE Biotecnologie Avanzate, Naples, Italy.

Giulia Frisso (G)

CEINGE Biotecnologie Avanzate, Naples, Italy; Department of Molecular Medicine and Medical Biotechnology, University of Naples Federico II, Naples, Italy.

Pasquale Abete (P)

COVID Hospital, P.O.S. Anna e SS. Madonna della Neve di Boscotrecase, Ospedali Riuniti Area Vesuviana, Naples, Italy.

Gian Marco Cassese (GM)

COVID Hospital, P.O.S. Anna e SS. Madonna della Neve di Boscotrecase, Ospedali Riuniti Area Vesuviana, Naples, Italy.

Giuseppe Servillo (G)

Department of Neuroscience, Reproductive Sciences and Dentistry, University of Naples Federico II, Naples, Italy.

Ivan Gentile (I)

Department of Clinical Medicine and Surgery, University of Naples Federico II, Naples, Italy.

Carmelo Piscopo (C)

Medical and Laboratory Genetics Unit, A.O.R.N. Antonio Cardarelli, Naples, Italy.

Matteo Della Monica (M)

Medical and Laboratory Genetics Unit, A.O.R.N. Antonio Cardarelli, Naples, Italy.

Giuseppe Fiorentino (G)

Cotugno Hospital, Azienda Ospedaliera di Rilievo Nazionale Ospedali dei Colli, Naples, Italy.

Angelo Boccia (A)

CEINGE Biotecnologie Avanzate, Naples, Italy.

Giovanni Paolella (G)

CEINGE Biotecnologie Avanzate, Naples, Italy; Department of Molecular Medicine and Medical Biotechnology, University of Naples Federico II, Naples, Italy.

Veronica Ferrucci (V)

CEINGE Biotecnologie Avanzate, Naples, Italy; Department of Molecular Medicine and Medical Biotechnology, University of Naples Federico II, Naples, Italy.

Pasqualino de Antonellis (P)

CEINGE Biotecnologie Avanzate, Naples, Italy; Department of Molecular Medicine and Medical Biotechnology, University of Naples Federico II, Naples, Italy.

Roberto Siciliano (R)

CEINGE Biotecnologie Avanzate, Naples, Italy; Department of Molecular Medicine and Medical Biotechnology, University of Naples Federico II, Naples, Italy.

Fathem Asadzadeh (F)

European School of Molecular Medicine, Università degli Studi di Milano, Milan, Italy; CEINGE Biotecnologie Avanzate, Naples, Italy.

Pellegrino Cerino (P)

Istituto Zooprofilattico Sperimentale del Mezzogiorno, Napoli, Italy.

Carlo Buonerba (C)

Department of Medicine, Surgery and Dentistry "Scuola Medica Salernitana," University of Salerno, Baronissi, Italy.

Biancamaria Pierri (B)

Istituto Zooprofilattico Sperimentale del Mezzogiorno, Napoli, Italy; Department of Medicine, Surgery and Dentistry "Scuola Medica Salernitana," University of Salerno, Baronissi, Italy.

Massimo Zollo (M)

CEINGE Biotecnologie Avanzate, Naples, Italy; Department of Molecular Medicine and Medical Biotechnology, University of Naples Federico II, Naples, Italy.

Achille Iolascon (A)

CEINGE Biotecnologie Avanzate, Naples, Italy; Department of Molecular Medicine and Medical Biotechnology, University of Naples Federico II, Naples, Italy.

Mario Capasso (M)

CEINGE Biotecnologie Avanzate, Naples, Italy; Department of Molecular Medicine and Medical Biotechnology, University of Naples Federico II, Naples, Italy. Electronic address: mario.capasso@unina.it.

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Classifications MeSH