Vaginal Metastases of Wilms' Tumor in a Pediatric Patient: A Rare Case.


Journal

Journal of pediatric and adolescent gynecology
ISSN: 1873-4332
Titre abrégé: J Pediatr Adolesc Gynecol
Pays: United States
ID NLM: 9610774

Informations de publication

Date de publication:
Aug 2023
Historique:
received: 02 09 2022
revised: 06 12 2022
accepted: 05 01 2023
medline: 7 8 2023
pubmed: 21 1 2023
entrez: 20 1 2023
Statut: ppublish

Résumé

Wilms' tumor is the second most common pediatric abdominal cancer; however, it rarely involves the female reproductive tract. There are few cases reported in the literature describing uterine, ovarian, cervical, and vaginal involvement. We report the case of a 7-year-old girl presenting with a large renal mass with retroperitoneal nodal and lung metastases; she was diagnosed with stage 4 favorable histology Wilms' tumor. She was treated with surgery, chemotherapy, and radiation. She presented with vaginal bleeding 10 months after completing treatment; biopsy of a vaginal mass confirmed recurrence, and this was sent for molecular profiling, which did not identify an inherited cancer predisposition or targetable mutation. She was again treated with chemotherapy; examination redemonstrated a small vaginal mass, but re-biopsy of the lesion was negative for malignancy. Due to high risk of local relapse, ongoing chemotherapy and pelvic radiation ensued. End-of-treatment imaging and vaginoscopy showed no residual disease. Vaginal metastases of Wilms' tumor are very rare; this is the second reported case in the literature. Pediatric clinicians should have a strong suspicion for vaginal metastases in cancer patients presenting with vaginal bleeding, especially when their pubertal development does not suggest that bleeding would be secondary to menarche. Long-term gynecologic care for these patients is paramount to reduce morbidity from chemotherapy and pelvic radiation. Fertility preservation counselling should be made early, through referral to a specialist.

Sections du résumé

BACKGROUND BACKGROUND
Wilms' tumor is the second most common pediatric abdominal cancer; however, it rarely involves the female reproductive tract. There are few cases reported in the literature describing uterine, ovarian, cervical, and vaginal involvement.
CASE METHODS
We report the case of a 7-year-old girl presenting with a large renal mass with retroperitoneal nodal and lung metastases; she was diagnosed with stage 4 favorable histology Wilms' tumor. She was treated with surgery, chemotherapy, and radiation. She presented with vaginal bleeding 10 months after completing treatment; biopsy of a vaginal mass confirmed recurrence, and this was sent for molecular profiling, which did not identify an inherited cancer predisposition or targetable mutation. She was again treated with chemotherapy; examination redemonstrated a small vaginal mass, but re-biopsy of the lesion was negative for malignancy. Due to high risk of local relapse, ongoing chemotherapy and pelvic radiation ensued. End-of-treatment imaging and vaginoscopy showed no residual disease.
SUMMARY AND CONCLUSION CONCLUSIONS
Vaginal metastases of Wilms' tumor are very rare; this is the second reported case in the literature. Pediatric clinicians should have a strong suspicion for vaginal metastases in cancer patients presenting with vaginal bleeding, especially when their pubertal development does not suggest that bleeding would be secondary to menarche. Long-term gynecologic care for these patients is paramount to reduce morbidity from chemotherapy and pelvic radiation. Fertility preservation counselling should be made early, through referral to a specialist.

Identifiants

pubmed: 36669618
pii: S1083-3188(23)00001-3
doi: 10.1016/j.jpag.2023.01.001
pii:
doi:

Types de publication

Case Reports

Langues

eng

Sous-ensembles de citation

IM

Pagination

424-427

Informations de copyright

Copyright © 2023. Published by Elsevier Inc.

Auteurs

Kristina Arion (K)

Dalhousie University, Department of Obstetrics and Gynecology, Halifax, Nova Scotia, Canada. Electronic address: Kristina.arion@dal.ca.

Stephanie Dufour (S)

Children's Hospital of Eastern Ontario, Department of Surgery, Division of Pediatric and Adolescent Gynecology, Ottawa, Ontario, Canada.

Raveena Ramphal (R)

PRecision Oncology For Young peopLE (PROFYLE) Consortium, Canada; Department of Pediatric Oncology, Children's Hospital of Eastern Ontario, Ottawa, Ontario, Canada.

Anita Villani (A)

PRecision Oncology For Young peopLE (PROFYLE) Consortium, Canada; Division of Hematology/Oncology, The Hospital for Sick Children, Toronto, Ontario, Canada; Department of Pediatrics, University of Toronto, Toronto, Ontario, Canada.

David Malkin (D)

PRecision Oncology For Young peopLE (PROFYLE) Consortium, Canada; Division of Hematology/Oncology, The Hospital for Sick Children, Toronto, Ontario, Canada; Department of Pediatrics, University of Toronto, Toronto, Ontario, Canada; Genetics and Genome Biology Program, The Hospital for Sick Children Research Institute, Toronto, Ontario, Canada.

Adam Shlien (A)

PRecision Oncology For Young peopLE (PROFYLE) Consortium, Canada; Genetics and Genome Biology Program, The Hospital for Sick Children Research Institute, Toronto, Ontario, Canada; Department of Pediatric Laboratory Medicine, The Hospital for Sick Children, Toronto, Ontario, Canada.

Nisha Kanwar (N)

PRecision Oncology For Young peopLE (PROFYLE) Consortium, Canada; Department of Pediatric Laboratory Medicine, The Hospital for Sick Children, Toronto, Ontario, Canada.

Sarah Sawyer (S)

PRecision Oncology For Young peopLE (PROFYLE) Consortium, Canada; Department of Genetics, Children's Hospital of Eastern Ontario, Ottawa, Ontario, Canada; Children's Hospital of Eastern Ontario (CHEO) Research Institute, Ottawa, Ontario, Canada.

Tania Dumont (T)

Children's Hospital of Eastern Ontario, Department of Surgery, Division of Pediatric and Adolescent Gynecology, Ottawa, Ontario, Canada; Children's Hospital of Eastern Ontario (CHEO) Research Institute, Ottawa, Ontario, Canada; The Ottawa Hospital, Department of Obstetrics, Gynecology and Newborn Care, Ottawa, Ontario, Canada; University of Ottawa, Department of Obstetrics and Gynecology, Ottawa, Ontario, Canada; The Ottawa Hospital Research Institute, Ottawa, Ontario, Canada.

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