Alpha-1-Antitrypsin Promoter Improves the Efficacy of an Adeno-Associated Virus Vector for the Treatment of Mitochondrial Neurogastrointestinal Encephalomyopathy.


Journal

Human gene therapy
ISSN: 1557-7422
Titre abrégé: Hum Gene Ther
Pays: United States
ID NLM: 9008950

Informations de publication

Date de publication:
08 2019
Historique:
pubmed: 23 3 2019
medline: 13 3 2020
entrez: 23 3 2019
Statut: ppublish

Résumé

Mitochondrial neurogastrointestinal encephalomyopathy (MNGIE) is a devastating disease caused by mutations in

Identifiants

pubmed: 30900470
doi: 10.1089/hum.2018.217
pmc: PMC7647930
doi:

Substances chimiques

SERPINA1 protein, human 0
alpha 1-Antitrypsin 0
Thymidine Phosphorylase EC 2.4.2.4
Tymp protein, mouse EC 2.4.2.4

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

985-998

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Auteurs

Raquel Cabrera-Pérez (R)

1Research Group on Neuromuscular and Mitochondrial Diseases, Vall d'Hebron Research Institute, Universitat Autònoma de Barcelona, Barcelona, Catalonia, Spain; Paris, France.
2Biomedical Network Research Centre on Rare Diseases, Instituto de Salud Carlos III, Madrid, Spain; Paris, France.

Ferran Vila-Julià (F)

1Research Group on Neuromuscular and Mitochondrial Diseases, Vall d'Hebron Research Institute, Universitat Autònoma de Barcelona, Barcelona, Catalonia, Spain; Paris, France.
2Biomedical Network Research Centre on Rare Diseases, Instituto de Salud Carlos III, Madrid, Spain; Paris, France.

Michio Hirano (M)

3Department of Neurology, H. Houston Merritt Neuromuscular Research Center, Columbia University Medical Center, New York, New York; Paris, France.

Federico Mingozzi (F)

4Genethon and INSERM U951, Evry, France; Paris, France.
5University Pierre and Marie Curie, Paris, France.

Javier Torres-Torronteras (J)

1Research Group on Neuromuscular and Mitochondrial Diseases, Vall d'Hebron Research Institute, Universitat Autònoma de Barcelona, Barcelona, Catalonia, Spain; Paris, France.
2Biomedical Network Research Centre on Rare Diseases, Instituto de Salud Carlos III, Madrid, Spain; Paris, France.

Ramon Martí (R)

1Research Group on Neuromuscular and Mitochondrial Diseases, Vall d'Hebron Research Institute, Universitat Autònoma de Barcelona, Barcelona, Catalonia, Spain; Paris, France.
2Biomedical Network Research Centre on Rare Diseases, Instituto de Salud Carlos III, Madrid, Spain; Paris, France.

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