VPOT: A Customizable Variant Prioritization Ordering Tool for Annotated Variants.


Journal

Genomics, proteomics & bioinformatics
ISSN: 2210-3244
Titre abrégé: Genomics Proteomics Bioinformatics
Pays: China
ID NLM: 101197608

Informations de publication

Date de publication:
10 2019
Historique:
received: 20 11 2018
revised: 26 08 2019
accepted: 08 11 2019
pubmed: 26 11 2019
medline: 14 4 2020
entrez: 26 11 2019
Statut: ppublish

Résumé

Next-generation sequencing (NGS) technologies generate thousands to millions of genetic variants per sample. Identification of potential disease-causal variants is labor intensive as it relies on filtering using various annotation metrics and consideration of multiple pathogenicity prediction scores. We have developed VPOT (variant prioritization ordering tool), a python-based command line tool that allows researchers to create a single fully customizable pathogenicity ranking score from any number of annotation values, each with a user-defined weighting. The use of VPOT can be informative when analyzing entire cohorts, as variants in a cohort can be prioritized. VPOT also provides additional functions to allow variant filtering based on a candidate gene list or by affected status in a family pedigree. VPOT outperforms similar tools in terms of efficacy, flexibility, scalability, and computational performance. VPOT is freely available for public use at GitHub (https://github.com/VCCRI/VPOT/). Documentation for installation along with a user tutorial, a default parameter file, and test data are provided.

Identifiants

pubmed: 31765830
pii: S1672-0229(19)30149-4
doi: 10.1016/j.gpb.2019.11.001
pmc: PMC7056850
pii:
doi:

Substances chimiques

3-Hydroxyanthranilate 3,4-Dioxygenase EC 1.13.11.6

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

540-545

Informations de copyright

Copyright © 2019 The Authors. Published by Elsevier B.V. All rights reserved.

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Auteurs

Eddie Ip (E)

Victor Chang Cardiac Research Institute, Sydney 2010, Australia; St Vincent's Clinical School, University of New South Wales, Sydney 2052, Australia.

Gavin Chapman (G)

Victor Chang Cardiac Research Institute, Sydney 2010, Australia; St Vincent's Clinical School, University of New South Wales, Sydney 2052, Australia.

David Winlaw (D)

Heart Centre for Children, The Children's Hospital at Westmead, Sydney 2145, Australia; Sydney Medical School, University of Sydney, Sydney 2050, Australia.

Sally L Dunwoodie (SL)

Victor Chang Cardiac Research Institute, Sydney 2010, Australia; St Vincent's Clinical School, University of New South Wales, Sydney 2052, Australia; School of Biotechnology and Biomolecular Sciences, University of New South Wales, Sydney 2033, Australia.

Eleni Giannoulatou (E)

Victor Chang Cardiac Research Institute, Sydney 2010, Australia; St Vincent's Clinical School, University of New South Wales, Sydney 2052, Australia. Electronic address: e.giannoulatou@victorchang.edu.au.

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Classifications MeSH