High-Throughput


Journal

Human gene therapy
ISSN: 1557-7422
Titre abrégé: Hum Gene Ther
Pays: United States
ID NLM: 9008950

Informations de publication

Date de publication:
05 2020
Historique:
pubmed: 1 2 2020
medline: 24 8 2021
entrez: 1 2 2020
Statut: ppublish

Résumé

Adeno-associated virus (AAV) vectors are quickly becoming the vectors of choice for therapeutic gene delivery. To date, hundreds of natural isolates and bioengineered variants have been reported. While factors such as high production titer and low immunoreactivity are important to consider, the ability to deliver the genetic payload (physical transduction) and to drive high transgene expression (functional transduction) remains the most important feature when selecting AAV variants for clinical applications. Reporter expression assays are the most commonly used methods for determining vector fitness. However, such approaches are time consuming and become impractical when evaluating a large number of variants. Limited access to primary human tissues or challenging model systems further complicates vector testing. To address this problem, convenient high-throughput methods based on next-generation sequencing (NGS) are being developed. To this end, we built an AAV Testing Kit that allows inherent flexibility in regard to number and type of AAV variants included, and is compatible with

Identifiants

pubmed: 32000541
doi: 10.1089/hum.2019.264
pmc: PMC7232709
doi:

Substances chimiques

DNA, Viral 0
EPHB2 protein, human EC 2.7.10.1
Receptor, EphB2 EC 2.7.10.1

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

575-589

Subventions

Organisme : Wellcome Trust
ID : 104807/Z/14/Z
Pays : United Kingdom
Organisme : Department of Health
Pays : United Kingdom

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Auteurs

Adrian Westhaus (A)

Translational Vectorology Research Unit, Children's Medical Research Institute, The University of Sydney, Westmead, Australia.
Great Ormond Street Institute of Child Health, University College London, London, United Kingdom.

Marti Cabanes-Creus (M)

Translational Vectorology Research Unit, Children's Medical Research Institute, The University of Sydney, Westmead, Australia.

Arkadiusz Rybicki (A)

Translational Vectorology Research Unit, Children's Medical Research Institute, The University of Sydney, Westmead, Australia.

Grober Baltazar (G)

Translational Vectorology Research Unit, Children's Medical Research Institute, The University of Sydney, Westmead, Australia.

Renina Gale Navarro (RG)

Translational Vectorology Research Unit, Children's Medical Research Institute, The University of Sydney, Westmead, Australia.

Erhua Zhu (E)

Gene Therapy Research Unit, Children's Medical Research Institute and Sydney Children's Hospitals Network, The University of Sydney, Westmead, Australia.

Matthieu Drouyer (M)

Translational Vectorology Research Unit, Children's Medical Research Institute, The University of Sydney, Westmead, Australia.

Maddison Knight (M)

Vector and Genome Engineering Facility, Children's Medical Research Institute, , The University of Sydney, Westmead, Australia.

Razvan F Albu (RF)

Vector and Genome Engineering Facility, Children's Medical Research Institute, , The University of Sydney, Westmead, Australia.

Boaz H Ng (BH)

Vector and Genome Engineering Facility, Children's Medical Research Institute, , The University of Sydney, Westmead, Australia.

Predrag Kalajdzic (P)

Vector and Genome Engineering Facility, Children's Medical Research Institute, , The University of Sydney, Westmead, Australia.

Magdalena Kwiatek (M)

Military Institute of Hygiene and Epidemiology, The Biological Threats Identification and Countermeasure Centre, Puławy, Poland.

Kenneth Hsu (K)

Children's Cancer Research Unit, The Children's Hospital at Westmead, Westmead, Australia.

Giorgia Santilli (G)

Great Ormond Street Institute of Child Health, University College London, London, United Kingdom.

Wendy Gold (W)

Molecular Neurobiology Research Lab, The Children's Hospital at Westmead, Westmead, Australia.
Discipline of Child and Adolescent Health, Faculty of Medicine and Health, The University of Sydney, Sydney, Australia.
Kids Neuroscience Centre, Kids Research, The Children's Hospital at Westmead, Westmead, Australia.

Belinda Kramer (B)

Children's Cancer Research Unit, The Children's Hospital at Westmead, Westmead, Australia.

Anai Gonzalez-Cordero (A)

Stem Cell & Organoid Facility and Stem Cell Medicine Group, Children's Medical Research Institute, Faculty of Medicine and Health, The University of Sydney, Westmead, Australia.

Adrian J Thrasher (AJ)

Great Ormond Street Institute of Child Health, University College London, London, United Kingdom.

Ian E Alexander (IE)

Gene Therapy Research Unit, Children's Medical Research Institute and Sydney Children's Hospitals Network, The University of Sydney, Westmead, Australia.
Discipline of Child and Adolescent Health, Faculty of Medicine and Health, The University of Sydney, Sydney, Australia.

Leszek Lisowski (L)

Translational Vectorology Research Unit, Children's Medical Research Institute, The University of Sydney, Westmead, Australia.
Vector and Genome Engineering Facility, Children's Medical Research Institute, , The University of Sydney, Westmead, Australia.
Military Institute of Hygiene and Epidemiology, The Biological Threats Identification and Countermeasure Centre, Puławy, Poland.

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Classifications MeSH