A harmonized meta-knowledgebase of clinical interpretations of somatic genomic variants in cancer.


Journal

Nature genetics
ISSN: 1546-1718
Titre abrégé: Nat Genet
Pays: United States
ID NLM: 9216904

Informations de publication

Date de publication:
04 2020
Historique:
received: 25 04 2019
accepted: 26 02 2020
pubmed: 5 4 2020
medline: 27 6 2020
entrez: 5 4 2020
Statut: ppublish

Résumé

Precision oncology relies on accurate discovery and interpretation of genomic variants, enabling individualized diagnosis, prognosis and therapy selection. We found that six prominent somatic cancer variant knowledgebases were highly disparate in content, structure and supporting primary literature, impeding consensus when evaluating variants and their relevance in a clinical setting. We developed a framework for harmonizing variant interpretations to produce a meta-knowledgebase of 12,856 aggregate interpretations. We demonstrated large gains in overlap between resources across variants, diseases and drugs as a result of this harmonization. We subsequently demonstrated improved matching between a patient cohort and harmonized interpretations of potential clinical significance, observing an increase from an average of 33% per individual knowledgebase to 57% in aggregate. Our analyses illuminate the need for open, interoperable sharing of variant interpretation data. We also provide a freely available web interface (search.cancervariants.org) for exploring the harmonized interpretations from these six knowledgebases.

Identifiants

pubmed: 32246132
doi: 10.1038/s41588-020-0603-8
pii: 10.1038/s41588-020-0603-8
pmc: PMC7127986
doi:

Types de publication

Journal Article Meta-Analysis Research Support, N.I.H., Extramural Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

448-457

Subventions

Organisme : NCI NIH HHS
ID : U24 CA237719
Pays : United States
Organisme : NCI NIH HHS
ID : U01 CA231844
Pays : United States
Organisme : NCI NIH HHS
ID : P30 CA008748
Pays : United States
Organisme : NIH HHS
ID : R24 OD011883
Pays : United States
Organisme : Medical Research Council
Pays : United Kingdom
Organisme : NHGRI NIH HHS
ID : U41 HG009649
Pays : United States
Organisme : NHGRI NIH HHS
ID : U41 HG009650
Pays : United States
Organisme : NCI NIH HHS
ID : F32 CA206247
Pays : United States
Organisme : Cancer Research UK
Pays : United Kingdom
Organisme : NCI NIH HHS
ID : R01 CA180778
Pays : United States
Organisme : NHGRI NIH HHS
ID : R00 HG007940
Pays : United States
Organisme : NHGRI NIH HHS
ID : K99 HG010157
Pays : United States
Organisme : NHGRI NIH HHS
ID : U41 HG006834
Pays : United States
Organisme : NCI NIH HHS
ID : U01 CA217862
Pays : United States
Organisme : NHGRI NIH HHS
ID : U01 HG007437
Pays : United States
Organisme : NCI NIH HHS
ID : U01 CA209936
Pays : United States

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Auteurs

Alex H Wagner (AH)

Washington University School of Medicine, St. Louis, MO, USA.

Brian Walsh (B)

Oregon Health and Science University, Portland, OR, USA.

Georgia Mayfield (G)

Oregon Health and Science University, Portland, OR, USA.

David Tamborero (D)

Pompeu Fabra University, Barcelona, Spain.
Karolinska Institute, Solna, Sweden.

Dmitriy Sonkin (D)

National Cancer Institute, Rockville, MD, USA.

Kilannin Krysiak (K)

Washington University School of Medicine, St. Louis, MO, USA.

Jordi Deu-Pons (J)

Institute for Research in Biomedicine, Barcelona, Spain.
Catalan Institution for Research and Advanced Studies, Barcelona, Spain.

Ryan P Duren (RP)

MolecularMatch, Houston, TX, USA.

Jianjiong Gao (J)

Memorial Sloan Kettering Cancer Center, New York, NY, USA.

Julie McMurry (J)

Oregon Health and Science University, Portland, OR, USA.

Sara Patterson (S)

The Jackson Laboratory for Genomic Medicine, Farmington, CT, USA.

Catherine Del Vecchio Fitz (C)

Dana-Farber Cancer Institute, Boston, MA, USA.

Beth A Pitel (BA)

Mayo Clinic, Rochester, MN, USA.

Ozman U Sezerman (OU)

Acibadem University, Istanbul, Turkey.

Kyle Ellrott (K)

Oregon Health and Science University, Portland, OR, USA.

Jeremy L Warner (JL)

Vanderbilt University, Nashville, TN, USA.

Damian T Rieke (DT)

Charité-Berlin University of Medicine, Berlin, Germany.

Tero Aittokallio (T)

Institute for Molecular Medicine Finland, Helsinki, Finland.
University of Turku, Turku, Finland.

Ethan Cerami (E)

Dana-Farber Cancer Institute, Boston, MA, USA.

Deborah I Ritter (DI)

Baylor College of Medicine, Houston, TX, USA.
Texas Children's Hospital, Houston, TX, USA.

Lynn M Schriml (LM)

University of Maryland School of Medicine, Baltimore, MD, USA.

Robert R Freimuth (RR)

Mayo Clinic, Rochester, MN, USA.

Melissa Haendel (M)

Oregon Health and Science University, Portland, OR, USA.
Linus Pauling Institute at Oregon State University, Corvallis, OR, USA.

Gordana Raca (G)

Children's Hospital Los Angeles, Los Angeles, CA, USA.
Keck School of Medicine of USC, Los Angeles, CA, USA.

Subha Madhavan (S)

Georgetown University Medical Center, Washington, DC, USA.

Michael Baudis (M)

University of Zurich, Zurich, Switzerland.

Jacques S Beckmann (JS)

University of Lausanne, Lausanne, Switzerland.

Rodrigo Dienstmann (R)

Vall d'Hebron Institute of Oncology, Barcelona, Spain.

Debyani Chakravarty (D)

Memorial Sloan Kettering Cancer Center, New York, NY, USA.

Xuan Shirley Li (XS)

MolecularMatch, Houston, TX, USA.

Susan Mockus (S)

The Jackson Laboratory for Genomic Medicine, Farmington, CT, USA.

Olivier Elemento (O)

Weill Cornell Medicine, New York, NY, USA.

Nikolaus Schultz (N)

Memorial Sloan Kettering Cancer Center, New York, NY, USA.

Nuria Lopez-Bigas (N)

Pompeu Fabra University, Barcelona, Spain.
Institute for Research in Biomedicine, Barcelona, Spain.
Catalan Institution for Research and Advanced Studies, Barcelona, Spain.

Mark Lawler (M)

Queen's University Belfast, Belfast, UK.

Jeremy Goecks (J)

Oregon Health and Science University, Portland, OR, USA.

Malachi Griffith (M)

Washington University School of Medicine, St. Louis, MO, USA. mgriffit@wustl.edu.

Obi L Griffith (OL)

Washington University School of Medicine, St. Louis, MO, USA. obigriffith@wustl.edu.

Adam A Margolin (AA)

Oregon Health and Science University, Portland, OR, USA.

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