A novel mechanism of phenotypic heterogeneity in Creutzfeldt-Jakob disease.


Journal

Acta neuropathologica communications
ISSN: 2051-5960
Titre abrégé: Acta Neuropathol Commun
Pays: England
ID NLM: 101610673

Informations de publication

Date de publication:
19 06 2020
Historique:
received: 09 06 2020
accepted: 11 06 2020
entrez: 21 6 2020
pubmed: 21 6 2020
medline: 29 5 2021
Statut: epublish

Résumé

One of remarkable features of sporadic Creutzfeldt-Jakob disease (sCJD) is the great phenotypic variability. Understanding the molecular basis of this variability has important implications for the development of therapeutic approaches. It is well established that, in many cases, phenotypic heterogeneity of sCJD is under control of two determinants: the genotype at the methionine (M)/valine (V) polymorphic codon 129 of the human prion protein gene and the type, 1 or 2, of the pathogenic and disease-related form of the prion protein, PrP

Identifiants

pubmed: 32560672
doi: 10.1186/s40478-020-00966-x
pii: 10.1186/s40478-020-00966-x
pmc: PMC7304206
doi:

Substances chimiques

Prion Proteins 0
Methionine AE28F7PNPL
Valine HG18B9YRS7

Types de publication

Journal Article Research Support, N.I.H., Extramural Research Support, Non-U.S. Gov't Research Support, U.S. Gov't, P.H.S.

Langues

eng

Sous-ensembles de citation

IM

Pagination

85

Subventions

Organisme : National Institute of Allergy and Infectious Diseases
ID : P01AI106705
Pays : International
Organisme : NCEZID CDC HHS
ID : UR8/CCU515004
Pays : United States
Organisme : National Institute of Allergy and Infectious Diseases
ID : 5R01NS083687
Pays : International
Organisme : NIAID NIH HHS
ID : P01 AI077774
Pays : United States
Organisme : NIGMS NIH HHS
ID : R01 GM094357
Pays : United States
Organisme : NIAID NIH HHS
ID : P01 AI106705
Pays : United States

Références

Proc Natl Acad Sci U S A. 2004 Feb 3;101(5):1380-5
pubmed: 14734804
Am J Pathol. 2005 Dec;167(6):1729-38
pubmed: 16314483
Proc Natl Acad Sci U S A. 2000 Aug 29;97(18):10168-72
pubmed: 10963679
Proc Natl Acad Sci U S A. 2010 Jun 29;107(26):12005-10
pubmed: 20547859
Acta Neuropathol. 2011 Jan;121(1):91-112
pubmed: 21107851
J Biol Chem. 1999 Dec 24;274(52):36859-65
pubmed: 10601237
Brain. 2006 Sep;129(Pt 9):2266-77
pubmed: 16923954
BMC Vet Res. 2006 Jun 09;2:19
pubmed: 16764717
Brain. 2010 Oct;133(10):3030-42
pubmed: 20823086
Front Mol Biosci. 2015 Mar 11;2:7
pubmed: 25988175
J Virol. 2010 Apr;84(7):3230-8
pubmed: 20089646
PLoS Pathog. 2015 Apr 14;11(4):e1004832
pubmed: 25875953
J Med Chem. 2014 Aug 28;57(16):6919-29
pubmed: 24762293
Handb Clin Neurol. 2018;153:271-299
pubmed: 29887141
Handb Clin Neurol. 2018;153:155-174
pubmed: 29887134
Ann Neurol. 1996 Jun;39(6):767-78
pubmed: 8651649
J Biol Chem. 2005 Mar 25;280(12):11247-58
pubmed: 15618225
Br Med Bull. 2003;66:213-39
pubmed: 14522861
J Virol. 1987 Dec;61(12):3688-93
pubmed: 2446004
Ann Neurol. 1999 Aug;46(2):224-33
pubmed: 10443888
Acta Neuropathol Commun. 2018 Jan 8;6(1):5
pubmed: 29310723
Acta Neuropathol Commun. 2019 May 29;7(1):85
pubmed: 31142381
FEBS Lett. 1997 Nov 17;417(3):400-4
pubmed: 9409760
PLoS Pathog. 2016 Feb 03;12(2):e1005416
pubmed: 26840342
Brain. 2009 Oct;132(Pt 10):2643-58
pubmed: 19734292
Acta Neuropathol. 2012 Oct;124(4):517-29
pubmed: 22744790
Brain Pathol. 2019 Mar;29(2):278-300
pubmed: 30588685
Anal Bioanal Chem. 2012 Sep;404(4):939-65
pubmed: 22772140
Brain Pathol. 2012 Sep;22(5):662-9
pubmed: 22288561
Acta Neuropathol Commun. 2013 Nov 13;1:74
pubmed: 24252157
Sci Rep. 2020 Jan 30;10(1):1503
pubmed: 32001774
Am J Pathol. 2006 Jan;168(1):151-7
pubmed: 16400018
Nature. 1997 Mar 20;386(6622):232-4
pubmed: 9069279
J Biol Chem. 2004 Apr 16;279(16):16797-804
pubmed: 14754888
Sci Rep. 2017 Jan 16;7:38280
pubmed: 28091514

Auteurs

Satish K Nemani (SK)

Department of Pathology, Case Western Reserve University, School of Medicine, Cleveland, OH, 44106, USA.

Xiangzhu Xiao (X)

Department of Physiology and Biophysics, Case Western Reserve University, School of Medicine, Cleveland, OH, 44106, USA.

Ignazio Cali (I)

Department of Pathology, Case Western Reserve University, School of Medicine, Cleveland, OH, 44106, USA.
National Prion Disease Pathology Surveillance Center, Case Western Reserve University, School of Medicine, Cleveland, OH, 44106, USA.

Laura Cracco (L)

Department of Pathology, Case Western Reserve University, School of Medicine, Cleveland, OH, 44106, USA.

Gianfranco Puoti (G)

Department of Advanced Medical and Surgical Sciences, University of Campania "L. Vanvitelli", 81100, Caserta, Italy.

Massimiliano Nigro (M)

Department of Mental Health and Emergency Psychiatry, P. O. "Maresca", Asl Napoli 3 Sud, 80059, Torre del Greco, Italy.

Jody Lavrich (J)

Department of Pathology, Case Western Reserve University, School of Medicine, Cleveland, OH, 44106, USA.

Anuradha Bharara Singh (A)

Vascular Medicine Institute, University of Pittsburgh, Pittsburgh, PA, 15261, USA.

Brian S Appleby (BS)

Department of Pathology, Case Western Reserve University, School of Medicine, Cleveland, OH, 44106, USA.
National Prion Disease Pathology Surveillance Center, Case Western Reserve University, School of Medicine, Cleveland, OH, 44106, USA.
Department of Neurology, Case Western Reserve University, School of Medicine, Cleveland, OH, 44106, USA.
Department of Psychiatry, Case Western Reserve University, Cleveland, OH, 44106, USA.

Valerie L Sim (VL)

Centre for Prions and Protein Folding Diseases, University of Alberta, Edmonton, T6G2M8, Canada.

Silvio Notari (S)

Department of Pathology, Case Western Reserve University, School of Medicine, Cleveland, OH, 44106, USA.

Witold K Surewicz (WK)

Department of Physiology and Biophysics, Case Western Reserve University, School of Medicine, Cleveland, OH, 44106, USA.

Pierluigi Gambetti (P)

Department of Pathology, Case Western Reserve University, School of Medicine, Cleveland, OH, 44106, USA. pxg13@case.edu.

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Classifications MeSH