Clinical and Mutation Description of the First Iranian Cohort of Infantile Inflammatory Bowel Disease: The Iranian Primary Immunodeficiency Registry (IPIDR).


Journal

Immunological investigations
ISSN: 1532-4311
Titre abrégé: Immunol Invest
Pays: England
ID NLM: 8504629

Informations de publication

Date de publication:
May 2021
Historique:
pubmed: 8 7 2020
medline: 9 11 2021
entrez: 8 7 2020
Statut: ppublish

Résumé

We describe a cohort of 25 Iranian patients with infantile inflammatory bowel disease (IBD), 14 (56%) of whom had monogenic defects. After proper screening, patients were referred for whole exome sequencing (WES). Four patients had missense mutations in the

Identifiants

pubmed: 32633164
doi: 10.1080/08820139.2020.1776725
doi:

Substances chimiques

Receptors, Interleukin-10 0

Types de publication

Case Reports Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

445-459

Auteurs

Farzaneh Rahmani (F)

Department of Radiology, Washington University School of Medicine, St Louis, Missouri, USA.
Student's Scientific Research Center, Tehran University of Medical Sciences (TUMS), Tehran, Iran.
NeuroImaging Network (NIN), Universal Scientific Education and Research Network (USERN), Tehran, Iran.

Elham Rayzan (E)

International Hematology/Oncology of Pediatrics' Experts (IHOPE), Universal Scientific Education and Research Network (USERN), Tehran, Iran.
Research Center for Immunodeficiencies (RCID), Children's Medical Center, Tehran University of Medical Sciences, Tehran, Iran.

Mohammad Reza Rahmani (MR)

Department of Immunology & Hematology, Faculty of Medicine, Kurdistan University of Medical Sciences, Sanandaj, Iran.

Sepideh Shahkarami (S)

Medical Genetics Network (Megene), Universal Scientific Education and Research Network (USERN), Tehran, Iran.

Samaneh Zoghi (S)

Ludwig Boltzmann Institute for Rare and Undiagnosed Diseases, Vienna, Austria.

Arezoo Rezaei (A)

Research Center for Immunodeficiencies (RCID), Children's Medical Center, Tehran University of Medical Sciences, Tehran, Iran.

Zahra Aryan (Z)

Research Center for Immunodeficiencies (RCID), Children's Medical Center, Tehran University of Medical Sciences, Tehran, Iran.

Mehri Najafi (M)

Department of Gastroenterology, Children's Medical Center, Tehran University of Medical Sciences, Tehran, Iran.

Meino Rohlfs (M)

Department of Pediatrics, Dr. Von Hauner Children's Hospital, Ludwig Maximilians University, Munich, Germany.

Tim Jeske (T)

Department of Pediatrics, Dr. Von Hauner Children's Hospital, Ludwig Maximilians University, Munich, Germany.

Majid Aflatoonian (M)

Children's Medical Center, Tehran University of Medical Sciences, Tehran, Iran.

Zahra Chavoshzadeh (Z)

Pediatric Infectious Research Center, Mofid Children's Hospital, Shahid Beheshti University of Medical Sciences, Tehran, Iran.

Fatemeh Farahmand (F)

Department of Gastroenterology, Children's Medical Center, Tehran University of Medical Sciences, Tehran, Iran.

Farzaneh Motamed (F)

Department of Gastroenterology, Children's Medical Center, Tehran University of Medical Sciences, Tehran, Iran.

Pejman Rohani (P)

Pediatric Gastroenterology, Hepatology and Nutrition Research Center, Research Institute for Children's Health, Shahid Beheshti University of Medical Sciences, Tehran, Iran.

Hossein Alimadadi (H)

Department of Gastroenterology, Children's Medical Center, Tehran University of Medical Sciences, Tehran, Iran.

Alireza Mahdaviani (A)

Pediatric Congenital Hematologic Disorders Research Center, Shahid Beheshti University of Medical Sciences, Tehran, Iran.

Mahboubeh Mansouri (M)

Immunology and Allergy Department, Mofid Children Hospital, Shahid Behehshti University of Medical Sciences, Tehran, Iran.

Marzieh Tavakol (M)

Non-communicable Diseases Research Center, Alborz University of Medical Sciences, Karaj, Iran.

Mirjam Vanderberg (M)

Laboratory for Immunology, Dept. Of Pediatrics, Leiden University Medical Center, Netherlands.

Daniel Kotlarz (D)

Department of Pediatrics, Dr. Von Hauner Children's Hospital, Ludwig Maximilians University, Munich, Germany.

Christoph Klein (C)

Department of Pediatrics, Dr. Von Hauner Children's Hospital, Ludwig Maximilians University, Munich, Germany.

Nima Rezaei (N)

Research Center for Immunodeficiencies (RCID), Children's Medical Center, Tehran University of Medical Sciences, Tehran, Iran.
Department of Immunology, School of Medicine, Tehran University of Medical Sciences, Tehran, Iran.
Network of Immunity in Infection, Malignancy and Autoimmunity (NIIMA), Universal Scientific Education and Research Network (USERN), Tehran, Iran.

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