Cognitive Outcomes and Relationships with Phenylalanine in Phenylketonuria: A Comparison between Italian and English Adult Samples.
Adolescent
Adult
Cognition
Cognitive Dysfunction
/ diagnosis
Cross-Cultural Comparison
Female
Humans
Italy
/ ethnology
Language
Male
Neuropsychological Tests
/ statistics & numerical data
Phenylalanine
/ blood
Phenylketonurias
/ blood
Reproducibility of Results
United Kingdom
/ ethnology
White People
/ psychology
Young Adult
PKU
Phe associations
cognitive outcomes
cross-countries
cross-cultural
Journal
Nutrients
ISSN: 2072-6643
Titre abrégé: Nutrients
Pays: Switzerland
ID NLM: 101521595
Informations de publication
Date de publication:
03 Oct 2020
03 Oct 2020
Historique:
received:
26
08
2020
revised:
23
09
2020
accepted:
24
09
2020
entrez:
7
10
2020
pubmed:
8
10
2020
medline:
15
4
2021
Statut:
epublish
Résumé
We aimed to assess if the same cognitive batteries can be used cross-nationally to monitor the effect of Phenylketonuria (PKU). We assessed whether a battery, previously used with English adults with PKU (AwPKU), was also sensitive to impairments in Italian AwPKU. From our original battery, we selected a number of tasks that comprehensively assessed visual attention, visuo-motor coordination, executive functions (particularly, reasoning, planning, and monitoring), sustained attention, and verbal and visual memory and learning. When verbal stimuli/or responses were involved, stimuli were closely matched between the two languages for psycholinguistic variables. We administered the tasks to 19 Italian AwPKU and 19 Italian matched controls and compared results from with 19 English AwPKU and 19 English matched controls selected from a previously tested cohort. Participant election was blind to cognitive performance and metabolic control, but participants were closely matched for age and education. The Italian AwPKU group had slightly worse metabolic control but showed levels of performance and patterns of impairment similar to the English AwPKU group. The Italian results also showed extensive correlations between adult cognitive measures and metabolic measures across the life span, both in terms of Phenylalanine (Phe) levels and Phe fluctuations, replicating previous results in English. These results suggest that batteries with the same and/or matched tasks can be used to assess cognitive outcomes across countries allowing results to be compared and accrued. Future studies should explore potential differences in metabolic control across countries to understand what variables make metabolic control easier to achieve.
Identifiants
pubmed: 33022955
pii: nu12103033
doi: 10.3390/nu12103033
pmc: PMC7599948
pii:
doi:
Substances chimiques
Phenylalanine
47E5O17Y3R
Types de publication
Comparative Study
Journal Article
Langues
eng
Sous-ensembles de citation
IM
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