Successful Treatment of Auricular Dystonia by Unilateral Pallidothalamic Tractotomy.
auricular dystonia
ear dyskinesia
pallidothalamic tract
Journal
Tremor and other hyperkinetic movements (New York, N.Y.)
ISSN: 2160-8288
Titre abrégé: Tremor Other Hyperkinet Mov (N Y)
Pays: England
ID NLM: 101569493
Informations de publication
Date de publication:
22 01 2021
22 01 2021
Historique:
entrez:
8
2
2021
pubmed:
9
2
2021
medline:
15
12
2021
Statut:
epublish
Résumé
Ear movement disorders are rarely reported. Although some patients may respond to botulinum toxin injections, reports on surgical treatment options remain limited. A 57-year-old woman was diagnosed with auricular dystonia, which was refractory to botulinum toxin injections. Since involuntary movement and pain were predominantly present on the right side and the patient rejected the implantation of a mechanical device, we decided to perform left pallidothalamic tractotomy. Immediately following lesioning, bilateral ear movements and right auricular pain ceased with no complications. Stereotactic neurosurgical treatment can be an alternative for auricular dystonia. Ear movement disorders, such as auricular myoclonus or dystonia, are rarely reported.The present case was refractory to repetitive botulinum toxin injections and oral medications.To the best of our knowledge, this is the first case of auricular dystonia that successfully improved with stereotactic neurosurgical treatment (pallidothalamic tractotomy).
Sections du résumé
Background
Ear movement disorders are rarely reported. Although some patients may respond to botulinum toxin injections, reports on surgical treatment options remain limited.
Case Report
A 57-year-old woman was diagnosed with auricular dystonia, which was refractory to botulinum toxin injections. Since involuntary movement and pain were predominantly present on the right side and the patient rejected the implantation of a mechanical device, we decided to perform left pallidothalamic tractotomy. Immediately following lesioning, bilateral ear movements and right auricular pain ceased with no complications.
Discussion
Stereotactic neurosurgical treatment can be an alternative for auricular dystonia.
Highlights
Ear movement disorders, such as auricular myoclonus or dystonia, are rarely reported.The present case was refractory to repetitive botulinum toxin injections and oral medications.To the best of our knowledge, this is the first case of auricular dystonia that successfully improved with stereotactic neurosurgical treatment (pallidothalamic tractotomy).
Identifiants
pubmed: 33552671
doi: 10.5334/tohm.579
pmc: PMC7824976
doi:
Types de publication
Case Reports
Research Support, Non-U.S. Gov't
Langues
eng
Sous-ensembles de citation
IM
Pagination
4Informations de copyright
Copyright: © 2021 The Author(s).
Déclaration de conflit d'intérêts
The authors have no competing interests to declare.
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