MCPH1: A Novel Case Report and a Review of the Literature.


Journal

Genes
ISSN: 2073-4425
Titre abrégé: Genes (Basel)
Pays: Switzerland
ID NLM: 101551097

Informations de publication

Date de publication:
02 04 2022
Historique:
received: 25 02 2022
revised: 19 03 2022
accepted: 31 03 2022
entrez: 23 4 2022
pubmed: 24 4 2022
medline: 27 4 2022
Statut: epublish

Résumé

Microcephaly primary hereditary (MCPH) is a congenital disease characterized by nonsyndromic reduction in brain size due to impaired neurogenesis, often associated with a variable degree of intellectual disability (ID). The genetic etiology of MCPH is heterogeneous and comprises more than 20 loci, nearly all following a recessive inheritance pattern. The first causative gene identified,

Identifiants

pubmed: 35456440
pii: genes13040634
doi: 10.3390/genes13040634
pmc: PMC9032034
pii:
doi:

Substances chimiques

Cell Cycle Proteins 0
Cytoskeletal Proteins 0
MCPH1 protein, human 0

Types de publication

Case Reports Journal Article Review

Langues

eng

Sous-ensembles de citation

IM

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Auteurs

Stefano Giuseppe Caraffi (SG)

Medical Genetics Unit, Azienda USL-IRCCS di Reggio Emilia, 42123 Reggio Emilia, Italy.

Marzia Pollazzon (M)

Medical Genetics Unit, Azienda USL-IRCCS di Reggio Emilia, 42123 Reggio Emilia, Italy.

Muhammad Farooq (M)

Department of Bioinformatics, Institute of Biochemistry, Biotechnology and Bioinformatics (IBBB), The Islamia University of Bahawalpur, Bahawalpur 63100, Pakistan.
Department of Biotechnology, Institute of Biochemistry, Biotechnology and Bioinformatics (IBBB), The Islamia University of Bahawalpur, Bahawalpur 63100, Pakistan.
Department of Cellular and Molecular Medicine, University of Copenhagen, Blegdamsvej 3B, 2200 Copenhagen, Denmark.

Ambrin Fatima (A)

Department of Cellular and Molecular Medicine, University of Copenhagen, Blegdamsvej 3B, 2200 Copenhagen, Denmark.
Department of Biological and Biomedical Sciences, Aga Khan University, Karachi 74800, Pakistan.

Lars Allan Larsen (LA)

Department of Cellular and Molecular Medicine, University of Copenhagen, Blegdamsvej 3B, 2200 Copenhagen, Denmark.

Roberta Zuntini (R)

Medical Genetics Unit, Azienda USL-IRCCS di Reggio Emilia, 42123 Reggio Emilia, Italy.

Manuela Napoli (M)

Neuroradiology Unit, Azienda USL-IRCCS di Reggio Emilia, 42123 Reggio Emilia, Italy.

Livia Garavelli (L)

Medical Genetics Unit, Azienda USL-IRCCS di Reggio Emilia, 42123 Reggio Emilia, Italy.

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Classifications MeSH