Systematic exploration of dynamic splicing networks reveals conserved multistage regulators of neurogenesis.

RNA-binding proteins alternative splicing gene regulation high-throughput screening neurogenesis single-cell profiling

Journal

Molecular cell
ISSN: 1097-4164
Titre abrégé: Mol Cell
Pays: United States
ID NLM: 9802571

Informations de publication

Date de publication:
18 08 2022
Historique:
received: 10 11 2021
revised: 16 04 2022
accepted: 29 06 2022
pubmed: 2 8 2022
medline: 24 8 2022
entrez: 1 8 2022
Statut: ppublish

Résumé

Alternative splicing (AS) is a critical regulatory layer; yet, factors controlling functionally coordinated splicing programs during developmental transitions are poorly understood. Here, we employ a screening strategy to identify factors controlling dynamic splicing events important for mammalian neurogenesis. Among previously unknown regulators, Rbm38 acts widely to negatively control neural AS, in part through interactions mediated by the established repressor of splicing, Ptbp1. Puf60, a ubiquitous factor, is surprisingly found to promote neural splicing patterns. This activity requires a conserved, neural-differential exon that remodels Puf60 co-factor interactions. Ablation of this exon rewires distinct AS networks in embryonic stem cells and at different stages of mouse neurogenesis. Single-cell transcriptome analyses further reveal distinct roles for Rbm38 and Puf60 isoforms in establishing neuronal identity. Our results describe important roles for previously unknown regulators of neurogenesis and establish how an alternative exon in a widely expressed splicing factor orchestrates temporal control over cell differentiation.

Identifiants

pubmed: 35914530
pii: S1097-2765(22)00654-2
doi: 10.1016/j.molcel.2022.06.036
pmc: PMC10686216
mid: NIHMS1941304
pii:
doi:

Substances chimiques

RNA-Binding Proteins 0
Rbm38 protein, mouse 0

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

2982-2999.e14

Subventions

Organisme : Intramural NIH HHS
ID : ZIA BC012019
Pays : United States

Informations de copyright

Copyright © 2022. Published by Elsevier Inc.

Déclaration de conflit d'intérêts

Declaration of interests B.J.B. and A.-C.G. are members of the Molecular Cell advisory board. The remaining authors declare no competing interests.

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Auteurs

Hong Han (H)

Donnelly Centre, University of Toronto, Toronto, ON M5S 3E1, Canada. Electronic address: hong.han@utoronto.ca.

Andrew J Best (AJ)

Donnelly Centre, University of Toronto, Toronto, ON M5S 3E1, Canada.

Ulrich Braunschweig (U)

Donnelly Centre, University of Toronto, Toronto, ON M5S 3E1, Canada.

Nicholas Mikolajewicz (N)

Donnelly Centre, University of Toronto, Toronto, ON M5S 3E1, Canada.

Jack Daiyang Li (JD)

Donnelly Centre, University of Toronto, Toronto, ON M5S 3E1, Canada; Department of Molecular Genetics, University of Toronto, Toronto, ON M5S 1A8, Canada.

Jonathan Roth (J)

Donnelly Centre, University of Toronto, Toronto, ON M5S 3E1, Canada; Department of Molecular Genetics, University of Toronto, Toronto, ON M5S 1A8, Canada.

Fuad Chowdhury (F)

Donnelly Centre, University of Toronto, Toronto, ON M5S 3E1, Canada.

Federica Mantica (F)

Centre for Genomic Regulation, Barcelona Institute of Science and Technology, Dr. Aiguader, 88, Barcelona 08003, Spain.

Syed Nabeel-Shah (S)

Donnelly Centre, University of Toronto, Toronto, ON M5S 3E1, Canada; Department of Molecular Genetics, University of Toronto, Toronto, ON M5S 1A8, Canada.

Guillermo Parada (G)

Donnelly Centre, University of Toronto, Toronto, ON M5S 3E1, Canada.

Kevin R Brown (KR)

Donnelly Centre, University of Toronto, Toronto, ON M5S 3E1, Canada.

Dave O'Hanlon (D)

Donnelly Centre, University of Toronto, Toronto, ON M5S 3E1, Canada.

Jiarun Wei (J)

Donnelly Centre, University of Toronto, Toronto, ON M5S 3E1, Canada.

Yuxi Yao (Y)

Donnelly Centre, University of Toronto, Toronto, ON M5S 3E1, Canada; Department of Molecular Genetics, University of Toronto, Toronto, ON M5S 1A8, Canada.

Abdelrahman Abou Zid (AA)

Donnelly Centre, University of Toronto, Toronto, ON M5S 3E1, Canada; Institute for Biomaterials and Biomedical Engineering, University of Toronto, Toronto, ON M5S 3G9, Canada.

Lim Caden Comsa (LC)

Donnelly Centre, University of Toronto, Toronto, ON M5S 3E1, Canada.

Mark Jen (M)

Lunenfeld-Tanenbaum Research Institute, Mount Sinai Hospital, Toronto, ON M5G 1X5, Canada.

Jenny Wang (J)

Lunenfeld-Tanenbaum Research Institute, Mount Sinai Hospital, Toronto, ON M5G 1X5, Canada.

Alessandro Datti (A)

Lunenfeld-Tanenbaum Research Institute, Mount Sinai Hospital, Toronto, ON M5G 1X5, Canada.

Thomas Gonatopoulos-Pournatzis (T)

Donnelly Centre, University of Toronto, Toronto, ON M5S 3E1, Canada; Center for Cancer Research National Cancer Institute, Frederick, MD 21702-1201, USA.

Robert J Weatheritt (RJ)

EMBL Australia, Garvan Institute of Medical Research, Darlinghurst, NSW 2010, Australia; St. Vincent Clinical School, University of New South Wales, Darlinghurst, NSW 2010, Australia.

Jack F Greenblatt (JF)

Donnelly Centre, University of Toronto, Toronto, ON M5S 3E1, Canada; Department of Molecular Genetics, University of Toronto, Toronto, ON M5S 1A8, Canada.

Jeffrey L Wrana (JL)

Department of Molecular Genetics, University of Toronto, Toronto, ON M5S 1A8, Canada; Lunenfeld-Tanenbaum Research Institute, Mount Sinai Hospital, Toronto, ON M5G 1X5, Canada.

Manuel Irimia (M)

Centre for Genomic Regulation, Barcelona Institute of Science and Technology, Dr. Aiguader, 88, Barcelona 08003, Spain; Universitat Pompeu Fabra, Barcelona, Spain; ICREA, Barcelona, Spain.

Anne-Claude Gingras (AC)

Department of Molecular Genetics, University of Toronto, Toronto, ON M5S 1A8, Canada; Lunenfeld-Tanenbaum Research Institute, Mount Sinai Hospital, Toronto, ON M5G 1X5, Canada.

Jason Moffat (J)

Donnelly Centre, University of Toronto, Toronto, ON M5S 3E1, Canada; Department of Molecular Genetics, University of Toronto, Toronto, ON M5S 1A8, Canada; Institute for Biomaterials and Biomedical Engineering, University of Toronto, Toronto, ON M5S 3G9, Canada. Electronic address: j.moffat@utoronto.ca.

Benjamin J Blencowe (BJ)

Donnelly Centre, University of Toronto, Toronto, ON M5S 3E1, Canada; Department of Molecular Genetics, University of Toronto, Toronto, ON M5S 1A8, Canada. Electronic address: b.blencowe@utoronto.ca.

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