Primary cilia sense glutamine availability and respond via asparagine synthetase.


Journal

Nature metabolism
ISSN: 2522-5812
Titre abrégé: Nat Metab
Pays: Germany
ID NLM: 101736592

Informations de publication

Date de publication:
03 2023
Historique:
received: 01 09 2022
accepted: 02 02 2023
medline: 29 3 2023
pubmed: 7 3 2023
entrez: 6 3 2023
Statut: ppublish

Résumé

Depriving cells of nutrients triggers an energetic crisis, which is resolved by metabolic rewiring and organelle reorganization. Primary cilia are microtubule-based organelles at the cell surface, capable of integrating multiple metabolic and signalling cues, but their precise sensory function is not fully understood. Here we show that primary cilia respond to nutrient availability and adjust their length via glutamine-mediated anaplerosis facilitated by asparagine synthetase (ASNS). Nutrient deprivation causes cilia elongation, mediated by reduced mitochondrial function, ATP availability and AMPK activation independently of mTORC1. Of note, glutamine removal and replenishment is necessary and sufficient to induce ciliary elongation or retraction, respectively, under nutrient stress conditions both in vivo and in vitro by restoring mitochondrial anaplerosis via ASNS-dependent glutamate generation. Ift88-mutant cells lacking cilia show reduced glutamine-dependent mitochondrial anaplerosis during metabolic stress, due to reduced expression and activity of ASNS at the base of cilia. Our data indicate a role for cilia in responding to, and possibly sensing, cellular glutamine levels via ASNS during metabolic stress.

Identifiants

pubmed: 36879119
doi: 10.1038/s42255-023-00754-6
pii: 10.1038/s42255-023-00754-6
pmc: PMC10042734
doi:

Substances chimiques

Glutamine 0RH81L854J
Aspartate-Ammonia Ligase EC 6.3.1.1

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

385-397

Informations de copyright

© 2023. The Author(s).

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Auteurs

Maria Elena Steidl (ME)

Molecular Basis of Cystic Kidney Disorders Unit, Division of Genetics and Cell Biology, IRCCS, San Raffaele Scientific Institute, Milan, Italy.
Ph.D Program in Molecular and Cellular Biology, Vita-Salute San Raffaele University, Milan, Italy.

Elisa A Nigro (EA)

Molecular Basis of Cystic Kidney Disorders Unit, Division of Genetics and Cell Biology, IRCCS, San Raffaele Scientific Institute, Milan, Italy.

Anne Kallehauge Nielsen (AK)

Molecular Basis of Cystic Kidney Disorders Unit, Division of Genetics and Cell Biology, IRCCS, San Raffaele Scientific Institute, Milan, Italy.
Ph.D Program in Molecular and Cellular Biology, Vita-Salute San Raffaele University, Milan, Italy.

Roberto Pagliarini (R)

Molecular Basis of Cystic Kidney Disorders Unit, Division of Genetics and Cell Biology, IRCCS, San Raffaele Scientific Institute, Milan, Italy.

Laura Cassina (L)

Molecular Basis of Cystic Kidney Disorders Unit, Division of Genetics and Cell Biology, IRCCS, San Raffaele Scientific Institute, Milan, Italy.

Matteo Lampis (M)

Molecular Basis of Cystic Kidney Disorders Unit, Division of Genetics and Cell Biology, IRCCS, San Raffaele Scientific Institute, Milan, Italy.
Department of Biosystems Science and Engineering, ETH Zurich, Basel, Switzerland.

Christine Podrini (C)

Molecular Basis of Cystic Kidney Disorders Unit, Division of Genetics and Cell Biology, IRCCS, San Raffaele Scientific Institute, Milan, Italy.

Marco Chiaravalli (M)

Molecular Basis of Cystic Kidney Disorders Unit, Division of Genetics and Cell Biology, IRCCS, San Raffaele Scientific Institute, Milan, Italy.

Valeria Mannella (V)

Center for Omics Sciences, IRCCS, San Raffaele Scientific Institute, Milan, Italy.

Gianfranco Distefano (G)

Molecular Basis of Cystic Kidney Disorders Unit, Division of Genetics and Cell Biology, IRCCS, San Raffaele Scientific Institute, Milan, Italy.

Ming Yang (M)

MRC, Cancer Unit Cambridge, Hutchison/MRC Research Centre, University of Cambridge, Cambridge, UK.
CECAD Research Center, Cologne, Germany.

Mariam Aslanyan (M)

Department of Human Genetics and Radboud Institute for Molecular Life Sciences, Radboud University Medical Center, Nijmegen, the Netherlands.

Giovanna Musco (G)

Biomolecular Nuclear Magnetic Resonance Unit, Division of Genetics and Cell Biology, IRCCS, San Raffaele Scientific Institute, Milan, Italy.

Ronald Roepman (R)

Department of Human Genetics and Radboud Institute for Molecular Life Sciences, Radboud University Medical Center, Nijmegen, the Netherlands.

Christian Frezza (C)

MRC, Cancer Unit Cambridge, Hutchison/MRC Research Centre, University of Cambridge, Cambridge, UK.
CECAD Research Center, Cologne, Germany.

Alessandra Boletta (A)

Molecular Basis of Cystic Kidney Disorders Unit, Division of Genetics and Cell Biology, IRCCS, San Raffaele Scientific Institute, Milan, Italy. boletta.alessandra@hsr.it.

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