FIRRM cooperates with FIGNL1 to promote RAD51 disassembly during DNA repair.


Journal

Science advances
ISSN: 2375-2548
Titre abrégé: Sci Adv
Pays: United States
ID NLM: 101653440

Informations de publication

Date de publication:
09 08 2023
Historique:
medline: 11 8 2023
pubmed: 9 8 2023
entrez: 9 8 2023
Statut: ppublish

Résumé

Interstrand DNA cross-links (ICLs) represent complex lesions that compromise genomic stability. Several pathways have been involved in ICL repair, but the extent of factors involved in the resolution of ICL-induced DNA double-strand breaks (DSBs) remains poorly defined. Using CRISPR-based genomics, we identified FIGNL1 interacting regulator of recombination and mitosis (FIRRM) as a sensitizer of the ICL-inducing agent mafosfamide. Mechanistically, we showed that FIRRM, like its interactor Fidgetin like 1 (FIGNL1), contributes to the resolution of RAD51 foci at ICL-induced DSBs. While the stability of FIGNL1 and FIRRM is interdependent, expression of a mutant of FIRRM (∆WCF), which stabilizes the protein in the absence of FIGNL1, allows the resolution of RAD51 foci and cell survival, suggesting that FIRRM has FIGNL1-independent function during DNA repair. In line with this model, FIRRM binds preferentially single-stranded DNA in vitro, raising the possibility that it directly contributes to RAD51 disassembly by interacting with DNA. Together, our findings establish FIRRM as a promoting factor of ICL repair.

Identifiants

pubmed: 37556550
doi: 10.1126/sciadv.adf4082
pmc: PMC10411901
doi:

Substances chimiques

Rad51 Recombinase EC 2.7.7.-
Proteins 0
DNA 9007-49-2

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

eadf4082

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Auteurs

Edgar Pinedo-Carpio (E)

Lady Davis Institute for Medical Research, Segal Cancer Centre, Jewish General Hospital, 3755 Chemin de la Côte-Sainte-Catherine, Montréal, QC H3T 1E2, Canada.
Division of Experimental Medicine, McGill University, Montréal, QC H4A 3J1, Canada.

Julien Dessapt (J)

CHU de Québec Research Center-Université Laval (L'Hôtel-Dieu de Québec), Laval University Cancer Research Center, Québec, QC G1R 3S3, Canada.
Department of Molecular Biology, Medical Biochemistry and Pathology, Université Laval, Québec, QC G1V 0A6, Canada.

Adèle Beneyton (A)

CHU de Québec Research Center-Université Laval (L'Hôtel-Dieu de Québec), Laval University Cancer Research Center, Québec, QC G1R 3S3, Canada.
Department of Molecular Biology, Medical Biochemistry and Pathology, Université Laval, Québec, QC G1V 0A6, Canada.

Lauralicia Sacre (L)

Department of Biochemistry, McGill University, Montréal, QC H3G 0B1, Canada.

Marie-Anne Bérubé (MA)

CHU de Québec Research Center-Université Laval (L'Hôtel-Dieu de Québec), Laval University Cancer Research Center, Québec, QC G1R 3S3, Canada.
Department of Molecular Biology, Medical Biochemistry and Pathology, Université Laval, Québec, QC G1V 0A6, Canada.

Romain Villot (R)

Département de Biochimie et Médecine Moléculaire, Université de Montréal, Montréal, QC H3C 3J7, Canada.
Maisonneuve-Rosemont Hospital Research Centre, Montréal, QC H1T 2M4 Canada.

Elise G Lavoie (EG)

CHU de Québec Research Center-Université Laval (L'Hôtel-Dieu de Québec), Laval University Cancer Research Center, Québec, QC G1R 3S3, Canada.
Department of Molecular Biology, Medical Biochemistry and Pathology, Université Laval, Québec, QC G1V 0A6, Canada.

Yan Coulombe (Y)

CHU de Québec Research Center-Université Laval (L'Hôtel-Dieu de Québec), Laval University Cancer Research Center, Québec, QC G1R 3S3, Canada.
Department of Molecular Biology, Medical Biochemistry and Pathology, Université Laval, Québec, QC G1V 0A6, Canada.

Andréanne Blondeau (A)

CHU de Québec Research Center-Université Laval (L'Hôtel-Dieu de Québec), Laval University Cancer Research Center, Québec, QC G1R 3S3, Canada.
Department of Molecular Biology, Medical Biochemistry and Pathology, Université Laval, Québec, QC G1V 0A6, Canada.

Jonathan Boulais (J)

Montreal Clinical Research Institute (IRCM), Montreal, QC H2W 1R7, Canada.

Abba Malina (A)

Lady Davis Institute for Medical Research, Segal Cancer Centre, Jewish General Hospital, 3755 Chemin de la Côte-Sainte-Catherine, Montréal, QC H3T 1E2, Canada.
Maisonneuve-Rosemont Hospital Research Centre, Montréal, QC H1T 2M4 Canada.

Vincent M Luo (VM)

Lady Davis Institute for Medical Research, Segal Cancer Centre, Jewish General Hospital, 3755 Chemin de la Côte-Sainte-Catherine, Montréal, QC H3T 1E2, Canada.
Department of Microbiology and Immunology, McGill University, Montréal, QC H3A 2B4, Canada.

Anna-Maria Lazaratos (AM)

Département de Biochimie et Médecine Moléculaire, Université de Montréal, Montréal, QC H3C 3J7, Canada.
Montreal Clinical Research Institute (IRCM), Montreal, QC H2W 1R7, Canada.

Jean-François Côté (JF)

Montreal Clinical Research Institute (IRCM), Montreal, QC H2W 1R7, Canada.
Département de Médecine, Université de Montréal, Montréal, QC H3C 3J7 Canada.

Frédérick A Mallette (FA)

Département de Biochimie et Médecine Moléculaire, Université de Montréal, Montréal, QC H3C 3J7, Canada.
Maisonneuve-Rosemont Hospital Research Centre, Montréal, QC H1T 2M4 Canada.
Département de Médecine, Université de Montréal, Montréal, QC H3C 3J7 Canada.

Alba Guarné (A)

Department of Biochemistry, McGill University, Montréal, QC H3G 0B1, Canada.

Jean-Yves Masson (JY)

CHU de Québec Research Center-Université Laval (L'Hôtel-Dieu de Québec), Laval University Cancer Research Center, Québec, QC G1R 3S3, Canada.
Department of Molecular Biology, Medical Biochemistry and Pathology, Université Laval, Québec, QC G1V 0A6, Canada.

Amélie Fradet-Turcotte (A)

CHU de Québec Research Center-Université Laval (L'Hôtel-Dieu de Québec), Laval University Cancer Research Center, Québec, QC G1R 3S3, Canada.
Department of Molecular Biology, Medical Biochemistry and Pathology, Université Laval, Québec, QC G1V 0A6, Canada.

Alexandre Orthwein (A)

Lady Davis Institute for Medical Research, Segal Cancer Centre, Jewish General Hospital, 3755 Chemin de la Côte-Sainte-Catherine, Montréal, QC H3T 1E2, Canada.
Division of Experimental Medicine, McGill University, Montréal, QC H4A 3J1, Canada.
Montreal Clinical Research Institute (IRCM), Montreal, QC H2W 1R7, Canada.
Department of Microbiology and Immunology, McGill University, Montréal, QC H3A 2B4, Canada.
Department of Radiation Oncology, Winship Cancer Institute, Emory University, Atlanta, GA 30322, USA.
Gerald Bronfman Department of Oncology, McGill University, Montréal, QC H4A 3T2, Canada.

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Classifications MeSH