Biallelic


Journal

Journal of medical genetics
ISSN: 1468-6244
Titre abrégé: J Med Genet
Pays: England
ID NLM: 2985087R

Informations de publication

Date de publication:
01 2023
Historique:
received: 02 09 2021
accepted: 09 11 2021
pubmed: 9 12 2021
medline: 28 12 2022
entrez: 8 12 2021
Statut: ppublish

Résumé

Hydrops fetalis, a pathological fluid accumulation in two or more body compartments, is aetiologically heterogeneous. We investigated a consanguineous family with recurrent pregnancy loss due to severe early-onset non-immune hydrops fetalis. Whole exome sequencing in four fetuses with hydrops fetalis revealed that they were homozygous for the angiopoietin-2 ( Pathogenic heterozygous

Sections du résumé

BACKGROUND
Hydrops fetalis, a pathological fluid accumulation in two or more body compartments, is aetiologically heterogeneous. We investigated a consanguineous family with recurrent pregnancy loss due to severe early-onset non-immune hydrops fetalis.
METHODS AND RESULTS
Whole exome sequencing in four fetuses with hydrops fetalis revealed that they were homozygous for the angiopoietin-2 (
CONCLUSION
Pathogenic heterozygous

Identifiants

pubmed: 34876502
pii: jmedgenet-2021-108179
doi: 10.1136/jmedgenet-2021-108179
pmc: PMC9811075
doi:

Substances chimiques

Angiopoietin-2 0
ANGPT2 protein, human 0
Codon, Nonsense 0

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

57-64

Informations de copyright

© Author(s) (or their employer(s)) 2023. Re-use permitted under CC BY. Published by BMJ.

Déclaration de conflit d'intérêts

Competing interests: PB has received support from Belgian Fonds de la Recherche Scientifique for attending meetings and/or travel.

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Auteurs

Marie F Smeland (MF)

Department of Medical Genetics, University Hospital of North Norway, Tromsø, Norway.

Pascal Brouillard (P)

Human Molecular Genetics, de Duve Institute, Universite catholique de Louvain, Brussels, Belgium.

Trine Prescott (T)

Department of Medical Genetics, Telemark Hospital, Skien, Norway.

Laurence M Boon (LM)

Center for Vascular Anomalies, Division of Plastic Surgery, VASCERN VASCA European Reference Centre, University Hospital Saint-Luc, Bruxelles, Belgium.

Bodil Hvingel (B)

Department of Obstetrics and Gynecology, University Hospital of North Norway, Tromsø, Norway.

Cecilie V Nordbakken (CV)

Department of Clinical Pathology, University Hospital of North Norway, Tromsø, Norway.

Mona Nystad (M)

Department of Obstetrics and Gynecology, University Hospital of North Norway, Tromsø, Norway.
Department of Clinical Medicine, University Hospital of North Norway, Tromsø, Norway.

Øystein L Holla (ØL)

Department of Medical Genetics, Telemark Hospital, Skien, Norway oholla@sthf.no.

Miikka Vikkula (M)

Human Molecular Genetics, de Duve Institute, Universite catholique de Louvain, Brussels, Belgium.
Center for Vascular Anomalies, Division of Plastic Surgery, VASCERN VASCA European Reference Centre, University Hospital Saint-Luc, Bruxelles, Belgium.

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