SCN1A overexpression, associated with a genomic region marked by a risk variant for a common epilepsy, raises seizure susceptibility.


Journal

Acta neuropathologica
ISSN: 1432-0533
Titre abrégé: Acta Neuropathol
Pays: Germany
ID NLM: 0412041

Informations de publication

Date de publication:
07 2022
Historique:
received: 16 03 2022
accepted: 30 04 2022
revised: 29 04 2022
pubmed: 14 5 2022
medline: 25 6 2022
entrez: 13 5 2022
Statut: ppublish

Résumé

Mesial temporal lobe epilepsy with hippocampal sclerosis and a history of febrile seizures is associated with common variation at rs7587026, located in the promoter region of SCN1A. We sought to explore possible underlying mechanisms. SCN1A expression was analysed in hippocampal biopsy specimens of individuals with mesial temporal lobe epilepsy with hippocampal sclerosis who underwent surgical treatment, and hippocampal neuronal cell loss was quantitatively assessed using immunohistochemistry. In healthy individuals, hippocampal volume was measured using MRI. Analyses were performed stratified by rs7587026 type. To study the functional consequences of increased SCN1A expression, we generated, using transposon-mediated bacterial artificial chromosome transgenesis, a zebrafish line expressing exogenous scn1a, and performed EEG analysis on larval optic tecta at 4 day post-fertilization. Finally, we used an in vitro promoter analysis to study whether the genetic motif containing rs7587026 influences promoter activity. Hippocampal SCN1A expression differed by rs7587026 genotype (Kruskal-Wallis test P = 0.004). Individuals homozygous for the minor allele showed significantly increased expression compared to those homozygous for the major allele (Dunn's test P = 0.003), and to heterozygotes (Dunn's test P = 0.035). No statistically significant differences in hippocampal neuronal cell loss were observed between the three genotypes. Among 597 healthy participants, individuals homozygous for the minor allele at rs7587026 displayed significantly reduced mean hippocampal volume compared to major allele homozygotes (Cohen's D = - 0.28, P = 0.02), and to heterozygotes (Cohen's D = - 0.36, P = 0.009). Compared to wild type, scn1lab-overexpressing zebrafish larvae exhibited more frequent spontaneous seizures [one-way ANOVA F(4,54) = 6.95 (P < 0.001)]. The number of EEG discharges correlated with the level of scn1lab overexpression [one-way ANOVA F(4,15) = 10.75 (P < 0.001]. Finally, we showed that a 50 bp promoter motif containing rs7587026 exerts a strong regulatory role on SCN1A expression, though we could not directly link this to rs7587026 itself. Our results develop the mechanistic link between rs7587026 and mesial temporal lobe epilepsy with hippocampal sclerosis and a history of febrile seizures. Furthermore, we propose that quantitative precision may be important when increasing SCN1A expression in current strategies aiming to treat seizures in conditions involving SCN1A haploinsufficiency, such as Dravet syndrome.

Identifiants

pubmed: 35551471
doi: 10.1007/s00401-022-02429-0
pii: 10.1007/s00401-022-02429-0
pmc: PMC9217876
doi:

Substances chimiques

NAV1.1 Voltage-Gated Sodium Channel 0
SCN1A protein, human 0
Zebrafish Proteins 0
scn1laa protein, zebrafish 0

Types de publication

Journal Article Research Support, N.I.H., Extramural Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

107-127

Subventions

Organisme : NHGRI NIH HHS
ID : U41 HG007234
Pays : United States
Organisme : Wellcome Trust
ID : WT104033AIA
Pays : United Kingdom
Organisme : Wellcome Trust
Pays : United Kingdom
Organisme : Wellcome Trust
ID : WT108749/Z/15/Z
Pays : United Kingdom
Organisme : Wellcome Trust
ID : WT200990/Z/16/Z
Pays : United Kingdom
Organisme : Department of Health
Pays : United Kingdom

Informations de copyright

© 2022. The Author(s).

Références

Abugessaisa I, Noguchi S, Hasegawa A, Harshbarger J (2017) Data Descriptor : FANTOM 5 CAGE profiles of human and mouse reprocessed for GRCh 38 and GRCm 38 genome assemblies. Sci Data 4:170107. https://doi.org/10.1038/sdata.2017.107
doi: 10.1038/sdata.2017.107 pubmed: 28850105 pmcid: 5574367
Afrikanova T, Serruys A-SK, Buenafe OEM, Clinckers R, Smolders I (2013) Validation of the zebrafish pentylenetetrazol seizure model: locomotor versus electrographic responses to antiepileptic drugs. PLoS One 8:54166. https://doi.org/10.1371/journal.pone.0054166
doi: 10.1371/journal.pone.0054166
Annegers JF, Hauser WA, Shirts SB, Kurland LT (1987) Factors prognostic of unprovoked seizures after febrile convulsions. N Engl J Med 316:493–498. https://doi.org/10.1056/NEJM198702263160901
doi: 10.1056/NEJM198702263160901 pubmed: 3807992
Blümcke I, Pauli E, Clusmann H, Schramm J, Becker A, Elger C et al (2007) A new clinico-pathological classification system for mesial temporal sclerosis. Acta Neuropathol 113:235–244. https://doi.org/10.1007/s00401-006-0187-0
doi: 10.1007/s00401-006-0187-0 pubmed: 17221203 pmcid: 1794628
Blümcke I, Thom M, Aronica E, Armstrong DD, Bartolomei F, Bernasconi A et al (2013) International consensus classification of hippocampal sclerosis in temporal lobe epilepsy: a task force report from the ILAE commission on diagnostic methods. Epilepsia 54:1315–1329. https://doi.org/10.1111/epi.12220
doi: 10.1111/epi.12220 pubmed: 23692496
Casadei R, Pelleri MC, Vitale L, Facchin F, Lenzi L, Canaider S et al (2011) Identification of housekeeping genes suitable for gene expression analysis in the zebrafish. Gene Expr Patterns 11:271–276. https://doi.org/10.1016/j.gep.2011.01.003
doi: 10.1016/j.gep.2011.01.003 pubmed: 21281742
Chang CC, Chow CC, Tellier LCAM, Vattikuti S, Purcell SM, Lee JJ (2015) Second-generation PLINK: rising to the challenge of larger and richer datasets. Gigascience 4:7. https://doi.org/10.1186/s13742-015-0047-8
doi: 10.1186/s13742-015-0047-8 pubmed: 25722852 pmcid: 4342193
Chèneby J, Ménétrier Z, Mestdagh M, Rosnet T, Douida A, Rhalloussi W et al (2020) ReMap 2020: a database of regulatory regions from an integrative analysis of human and Arabidopsis DNA-binding sequencing experiments. Nucleic Acids Res 48:D180–D188. https://doi.org/10.1093/nar/gkz945
doi: 10.1093/nar/gkz945 pubmed: 31665499
Claes L, Del-Favero J, Ceulemans B, Lagae L, Van Broeckhoven C, De Jonghe P (2001) De novo mutations in the sodium-channel gene SCN1A cause severe myoclonic epilepsy of infancy. Am J Hum Genet 68:1327–1332. https://doi.org/10.1086/320609
doi: 10.1086/320609 pubmed: 11359211 pmcid: 1226119
Colasante G, Lignani G, Brusco S, Di Berardino C, Carpenter J, Giannelli S et al (2019) dCas9-based Scn1a gene activation restores inhibitory interneuron excitability and attenuates seizures in Dravet syndrome mice. Mol Ther 28:235–253. https://doi.org/10.1016/j.ymthe.2019.08.018
doi: 10.1016/j.ymthe.2019.08.018 pubmed: 31607539 pmcid: 6952031
Dale AM, Fischl B, Sereno MI (1999) Cortical surface-based analysis. Neuroimage 9:179–194. https://doi.org/10.1006/nimg.1998.0395
doi: 10.1006/nimg.1998.0395 pubmed: 9931268
Dupret B, Völkel P, Follet P, Le Bourhis X, Angrand PO (2018) Combining genotypic and phenotypic analyses on single mutant zebrafish larvae. MethodsX 5:244–256. https://doi.org/10.1016/j.mex.2018.03.002
doi: 10.1016/j.mex.2018.03.002 pubmed: 30090702 pmcid: 6078847
Dutton SBB, Dutt K, Papale LA, Helmers S, Goldin AL, Escayg A (2017) Early-life febrile seizures worsen adult phenotypes in Scn1a mutants. Exp Neurol 293:159–171. https://doi.org/10.1016/j.expneurol.2017.03.026
doi: 10.1016/j.expneurol.2017.03.026 pubmed: 28373025 pmcid: 5538963
Engel J, Pitkänen A (2020) Biomarkers for epileptogenesis and its treatment. Neuropharmacology 167:107735. https://doi.org/10.1016/j.neuropharm.2019.107735
doi: 10.1016/j.neuropharm.2019.107735 pubmed: 31377200
Feenstra B, Pasternak B, Geller F, Carstensen L, Wang T, Huang F et al (2014) Common variants associated with general and MMR vaccine-related febrile seizures. Nat Genet 46:1274–1282. https://doi.org/10.1038/ng.3129
doi: 10.1038/ng.3129 pubmed: 25344690 pmcid: 4244308
Fischl B, Liu A, Dale AM (2001) Automated manifold surgery: Constructing geometrically accurate and topologically correct models of the human cerebral cortex. IEEE Trans Med Imaging 20:70–80. https://doi.org/10.1109/42.906426
doi: 10.1109/42.906426 pubmed: 11293693
Fischl B, Salat DH, Busa E, Albert M, Dieterich M, Haselgrove C et al (2002) Whole brain segmentation: automated labeling of neuroanatomical structures in the human brain. Neuron 33:341–355. https://doi.org/10.1016/S0896-6273(02)00569-X
doi: 10.1016/S0896-6273(02)00569-X pubmed: 11832223
Fischl B, Sereno MI, Dale AM (1999) Cortical surface-based analysis: II. Inflation, flattening, and a surface-based coordinate system. Neuroimage 9:195–207. https://doi.org/10.1006/nimg.1998.0396
doi: 10.1006/nimg.1998.0396 pubmed: 9931269
The FANTOM Consortium and the RIKEN PMI and CLST (DGT) (2014) A promoter-level mammalian expression atlas. Nature 507:462–470. https://doi.org/10.1038/NATURE13182
doi: 10.1038/NATURE13182
Frankish A, Diekhans M, Ferreira AM, Johnson R, Jungreis I, Loveland J et al (2019) GENCODE reference annotation for the human and mouse genomes. Nucleic Acids Res 47:D766–D773. https://doi.org/10.1093/nar/gky955
doi: 10.1093/nar/gky955 pubmed: 30357393
French JA, Williamson PD, Thadani YVM, Darcey TTM, Mattson RH, Spencer SS et al (1993) Characteristics of medial temporal lobe epilepsy: I. Results of history and physical examination. Ann Neurol 34:774–780. https://doi.org/10.1002/ana.410340604
doi: 10.1002/ana.410340604 pubmed: 8250525
Grasby KL, Jahanshad N, Painter JN, Colodro-Conde L, Bralten J, Hibar DP et al (2020) The genetic architecture of the human cerebral cortex. Science. https://doi.org/10.1126/science.aay6690
doi: 10.1126/science.aay6690 pubmed: 32193296 pmcid: 7295264
Hezroni H, Koppstein D, Schwartz MG, Avrutin A, Bartel DP, Ulitsky I (2015) Principles of long noncoding RNA evolution derived from direct comparison of transcriptomes in 17 species. Cell Rep 11:1110–1122. https://doi.org/10.1016/j.celrep.2015.04.023
doi: 10.1016/j.celrep.2015.04.023 pubmed: 25959816 pmcid: 4576741
Hon CC, Ramilowski JA, Harshbarger J, Bertin N, Rackham OJL, Gough J et al (2017) An atlas of human long non-coding RNAs with accurate 5′ ends. Nature 543:199–204. https://doi.org/10.1038/nature21374
doi: 10.1038/nature21374 pubmed: 28241135 pmcid: 6857182
International League Against Epilepsy Consortium on Complex Epilepsies (2018) Genome-wide mega-analysis identifies 16 loci and highlights diverse biological mechanisms in the common epilepsies. Nat Commun 9:5269. https://doi.org/10.1038/s41467-018-07524-z
doi: 10.1038/s41467-018-07524-z
Ishii A, Watkins JC, Chen D, Hirose S, Hammer MF (2017) Clinical implications of SCN1A missense and truncation variants in a large Japanese cohort with Dravet syndrome. Epilepsia 58:282–290. https://doi.org/10.1111/epi.13639
doi: 10.1111/epi.13639 pubmed: 28012175
Di Iulio J, Bartha I, Wong EHM, Yu HC, Lavrenko V, Yang D et al (2018) The human noncoding genome defined by genetic diversity. Nat Genet 503(50):333–337. https://doi.org/10.1038/S41588-018-0062-7
doi: 10.1038/S41588-018-0062-7
Jaffe AE, Shin J, Collado-Torres L, Leek JT, Tao R, Li C et al (2015) Developmental regulation of human cortex transcription and its clinical relevance at single base resolution. Nat Neurosci 18:154–161. https://doi.org/10.1038/nn.3898
doi: 10.1038/nn.3898 pubmed: 25501035
Kasperavičiute D, Catarino CB, Matarin M, Leu C, Novy J, Tostevin A et al (2013) Epilepsy, hippocampal sclerosis and febrile seizures linked by common genetic variation around SCN1A. Brain 136:3140–3150. https://doi.org/10.1093/brain/awt233
doi: 10.1093/brain/awt233 pubmed: 24014518 pmcid: 3784283
Kent WJ, Sugnet CW, Furey TS, Roskin KM, Pringle TH, Zahler AM et al (2002) The human genome browser at UCSC. Genome Res 12:996–1006. https://doi.org/10.1101/GR.229102
doi: 10.1101/GR.229102 pubmed: 12045153 pmcid: 186604
Kim SA, Cho CS, Kim SR, Bull SB, Yoo YJ (2018) A new haplotype block detection method for dense genome sequencing data based on interval graph modeling of clusters of highly correlated SNPs. Bioinformatics 34:388–397. https://doi.org/10.1093/BIOINFORMATICS/BTX609
doi: 10.1093/BIOINFORMATICS/BTX609 pubmed: 29028986
Kjeldsen MJ, Kyvik KO, Friis ML, Christensen K (2002) Genetic and environmental factors in febrile seizures: a Danish population-based twin study. Epilepsy Res 51:167–177. https://doi.org/10.1016/S0920-1211(02)00121-3
doi: 10.1016/S0920-1211(02)00121-3 pubmed: 12350392
Kral T, Clusmann H, Urbach J, Schramm J, Elger CE, Kurthen M et al (2002) Preoperative evaluation for epilepsy surgery (Bonn algorithm). Zentralbl Neurochir 63:106–110. https://doi.org/10.1055/s-2002-35826
doi: 10.1055/s-2002-35826 pubmed: 12457335
Lagarde J, Uszczynska-Ratajczak B, Carbonell S, Pérez-Lluch S, Abad A, Davis C et al (2017) High-throughput annotation of full-length long noncoding RNAs with capture long-read sequencing. Nat Genet 49:1731–1740. https://doi.org/10.1038/ng.3988
doi: 10.1038/ng.3988 pubmed: 29106417 pmcid: 5709232
Leu C, Stevelink R, Smith AW et al (2019) Polygenic burden in focal and generalized epilepsies. Brain 142:3473–3481. https://doi.org/10.1093/brain/awz292
doi: 10.1093/brain/awz292 pubmed: 31608925 pmcid: 6821205
Lévesque M, Avoli M, Bernard C (2016) Animal models of temporal lobe epilepsy following systemic chemoconvulsant administration. J Neurosci Methods 260:45–52. https://doi.org/10.1016/j.jneumeth.2015.03.009
doi: 10.1016/j.jneumeth.2015.03.009 pubmed: 25769270
Lewis DV, Shinnar S, Hesdorffer DC, Bagiella E, Bello JA, Chan S et al (2014) Hippocampal sclerosis after febrile status epilepticus: the FEBSTAT study. Ann Neurol 75:178–185. https://doi.org/10.1002/ana.24081
doi: 10.1002/ana.24081 pubmed: 24318290 pmcid: 3980500
Livak KJ, Schmittgen TD (2001) Analysis of relative gene expression data using real-time quantitative PCR and the 2-ΔΔCT method. Methods 25:402–408. https://doi.org/10.1006/meth.2001.1262
doi: 10.1006/meth.2001.1262 pubmed: 11846609
Lonsdale J, Thomas J, Salvatore M, Phillips R, Lo E, Shad S et al (2013) The genotype-tissue expression (GTEx) PROJECT. Nat Genet 45:580–585. https://doi.org/10.1038/ng.2653
doi: 10.1038/ng.2653
Van Loo KMJ, Schaub C, Pernhorst K, Yaari Y, Beck H, Schoch S et al (2012) Transcriptional regulation of T-type calcium channel CaV3.2: bi-directionality by early growth response 1 (Egr1) and repressor element 1 (RE-1) protein-silencing transcription factor (REST). J Biol Chem 287:15489–15501. https://doi.org/10.1074/JBC.M111.310763
doi: 10.1074/JBC.M111.310763 pubmed: 22431737 pmcid: 3346130
Löscher W (2020) The holy grail of epilepsy prevention: preclinical approaches to antiepileptogenic treatments. Neuropharmacology 167:107605. https://doi.org/10.1016/j.neuropharm.2019.04.011
doi: 10.1016/j.neuropharm.2019.04.011 pubmed: 30980836
McCurley AT, Callard GV (2008) Characterization of housekeeping genes in zebrafish: male-female differences and effects of tissue type, developmental stage and chemical treatment. BMC Mol Biol 9:1–12. https://doi.org/10.1186/1471-2199-9-102
doi: 10.1186/1471-2199-9-102
Pernhorst K, Herms S, Hoffmann P, Cichon S, Schulz H, Sander T et al (2013) TLR4, ATF-3 and IL8 inflammation mediator expression correlates with seizure frequency in human epileptic brain tissue. Seizure 22:675–678. https://doi.org/10.1016/j.seizure.2013.04.023
doi: 10.1016/j.seizure.2013.04.023 pubmed: 23706953
Pernhorst K, Raabe A, Niehusmann P, Van Loo KMJ, Grote A, Hoffmann P et al (2011) Promoter variants determine γ-aminobutyric acid homeostasis-related gene transcription in human epileptic hippocampi. J Neuropathol Exp Neurol 70:1080–1088. https://doi.org/10.1097/NEN.0b013e318238b9af
doi: 10.1097/NEN.0b013e318238b9af pubmed: 22082659
Pittau F, Bisulli F, Mai R, Fares JE, Vignatelli L, Labate A et al (2009) Prognostic factors in patients with mesial temporal lobe epilepsy. Epilepsia 50:41–44. https://doi.org/10.1111/j.1528-1167.2008.01969.x
doi: 10.1111/j.1528-1167.2008.01969.x pubmed: 19125847
Purcell S, Neale B, Todd-Brown K, Thomas L, Ferreira MAR, Bender D et al (2007) PLINK: a tool set for whole-genome association and population-based linkage analyses. Am J Hum Genet 81:559–575. https://doi.org/10.1086/519795
doi: 10.1086/519795 pubmed: 17701901 pmcid: 1950838
Robinson MD, McCarthy DJ, Smyth GK (2010) edgeR: a bioconductor package for differential expression analysis of digital gene expression data. Bioinformatics 26:139–140. https://doi.org/10.1093/BIOINFORMATICS/BTP616
doi: 10.1093/BIOINFORMATICS/BTP616 pubmed: 19910308
Salgueiro-Pereira AR, Duprat F, Pousinha PA, Loucif A, Douchamps V, Regondi C et al (2019) A two-hit story: seizures and genetic mutation interaction sets phenotype severity in SCN1A epilepsies. Neurobiol Dis 125:31–44. https://doi.org/10.1016/j.nbd.2019.01.006
doi: 10.1016/j.nbd.2019.01.006 pubmed: 30659983
Schönberger A, Niehusmann P, Urbach H, Majores M, Grote A, Holthausen H et al (2009) Increased frequency of distinct TSC2 allelic variants in focal cortical dysplasias with balloon cells and mineralization: original article. Neuropathology 29:559–565. https://doi.org/10.1111/j.1440-1789.2009.01018.x
doi: 10.1111/j.1440-1789.2009.01018.x pubmed: 19422538
Scott RC, King MD, Gadian DG, Neville BGR, Connelly A (2003) Hippocampal abnormalities after prolonged febrile convulsion: a longitudinal MRI study. Brain 126:2551–2557. https://doi.org/10.1093/brain/awg262
doi: 10.1093/brain/awg262 pubmed: 12937081
Semah F, Picot MC, Adam C, Broglin D, Arzimanoglou A, Bazin B et al (1998) Is the underlying cause of epilepsy a major prognostic factor for recurrence? Neurology 51:1256–1262. https://doi.org/10.1212/wnl.51.5.1256
doi: 10.1212/wnl.51.5.1256 pubmed: 9818842
Stein JL, Medland SE, Vasquez AA, Hibar DP, Senstad RE, Winkler AM et al (2012) Identification of common variants associated with human hippocampal and intracranial volumes. Nat Genet 44:552–561. https://doi.org/10.1038/ng.2250
doi: 10.1038/ng.2250 pubmed: 22504417 pmcid: 3635491
Stephen LJ, Kwan P, Brodie MJ (2001) Does the cause of localisation-related epilepsy influence the response to antiepileptic drug treatment? Epilepsia 42:357–362. https://doi.org/10.1046/j.1528-1157.2001.29000.x
doi: 10.1046/j.1528-1157.2001.29000.x pubmed: 11442153
Tai XY, Bernhardt B, Thom M, Thompson P, Baxendale S, Koepp M et al (2018) Review: neurodegenerative processes in temporal lobe epilepsy with hippocampal sclerosis: clinical, pathological and neuroimaging evidence. Neuropathol Appl Neurobiol 44:70–90. https://doi.org/10.1111/nan.12458
doi: 10.1111/nan.12458 pubmed: 29288503
Team RC (2015) R: a language and environment for statistical computing. Foundation for Statistical Computing, Vienna
Thijs RD, Surges R, O’Brien TJ, Sander JW (2019) Epilepsy in adults. Lancet 393:689–701. https://doi.org/10.1016/S0140-6736(18)32596-0
doi: 10.1016/S0140-6736(18)32596-0 pubmed: 30686584
Thom M (2014) Review: hippocampal sclerosis in epilepsy: a neuropathology review. Neuropathol Appl Neurobiol 40:520–543. https://doi.org/10.1111/nan.12150
doi: 10.1111/nan.12150 pubmed: 24762203 pmcid: 4265206
Tilgner H, Jahanbani F, Blauwkamp T, Moshrefi A, Jaeger E, Chen F et al (2015) Comprehensive transcriptome analysis using synthetic long-read sequencing reveals molecular co-association of distant splicing events. Nat Biotechnol 33:736–742. https://doi.org/10.1038/nbt.3242
doi: 10.1038/nbt.3242 pubmed: 25985263 pmcid: 4832928
Tsortouktzidis D, Schulz H, Hamed M, Vatter H, Surges R, Schoch S et al (2021) Gene expression analysis in epileptic hippocampi reveals a promoter haplotype conferring reduced aldehyde dehydrogenase 5a1 expression and responsiveness. Epilepsia 62:e29–e34. https://doi.org/10.1111/epi.16789
doi: 10.1111/epi.16789 pubmed: 33319393
Uhlén M, Fagerberg L, Hallström BM, Lindskog C, Oksvold P, Mardinoglu A et al (2015) Tissue-based map of the human proteome. Science 347:1260419. https://doi.org/10.1126/science.1260419
doi: 10.1126/science.1260419 pubmed: 25613900
Whelan CD, Altmann A, Botía JA, Jahanshad N, Hibar DP, Absil J et al (2018) Structural brain abnormalities in the common epilepsies assessed in a worldwide ENIGMA study. Brain 141:391–408. https://doi.org/10.1093/brain/awx341
doi: 10.1093/brain/awx341 pubmed: 29365066 pmcid: 5837616
Wieser HG, ILAE Commission on Neurosurgery of Epilepsy (2004) Mesial temporal lobe epilepsy with hippocampal sclerosis. Epilepsia 45:695–714. https://doi.org/10.1111/j.0013-9580.2004.09004.x
doi: 10.1111/j.0013-9580.2004.09004.x pubmed: 15144438
Woitecki AMH, Müller JA, van Loo KMJ, Sowade RF, Becker AJ, Schoch S (2016) Identification of synaptotagmin 10 as effector of NPAS4-mediated protection from excitotoxic neurodegeneration. J Neurosci 36:2561–2570. https://doi.org/10.1523/JNEUROSCI.2027-15.2016
doi: 10.1523/JNEUROSCI.2027-15.2016 pubmed: 26936998 pmcid: 6604865
Zhang YH, Burgess R, Malone JP, Glubb GC, Helbig KL, Vadlamudi L et al (2017) Genetic epilepsy with febrile seizures plus. Neurology 89:1210–1219. https://doi.org/10.1212/WNL.0000000000004384
doi: 10.1212/WNL.0000000000004384 pubmed: 28842445
Zuberi SM, Brunklaus A, Birch R, Reavey E, Duncan J, Forbes GH (2011) Genotype-phenotype associations in SCN1A-related epilepsies. Neurology 76:594–600. https://doi.org/10.1212/WNL.0b013e31820c309b
doi: 10.1212/WNL.0b013e31820c309b pubmed: 21248271
de Zubicaray GI, Chiang MC, McMahon KL, Shattuck DW, Toga AW, Martin NG et al (2008) Meeting the challenges of neuroimaging genetics. Brain Imaging Behav 2:258–263. https://doi.org/10.1007/s11682-008-9029-0
doi: 10.1007/s11682-008-9029-0 pubmed: 20016769 pmcid: 2794202

Auteurs

Katri Silvennoinen (K)

Department of Clinical and Experimental Epilepsy, UCL Queen Square Institute of Neurology, Box 29, Queen Square, London, WC1N 3BG, UK.
Chalfont Centre for Epilepsy, Chalfont St Peter, Bucks, SL9 0RJ, UK.

Kinga Gawel (K)

Chemical Neuroscience Group, Centre for Molecular Medicine Norway (NCMM), Faculty of Medicine, University of Oslo, 0349, Oslo, Norway.
Department of Experimental and Clinical Pharmacology, Medical University of Lublin, 20-090, Lublin, Poland.

Despina Tsortouktzidis (D)

Institute of Neuropathology, Medical Faculty, University of Bonn, Section for Translational Epilepsy Research, 53127, Bonn, Germany.
Department of Epileptology, Medical Faculty, University of Bonn, 53127, Bonn, Germany.

Julika Pitsch (J)

Institute of Neuropathology, Medical Faculty, University of Bonn, Section for Translational Epilepsy Research, 53127, Bonn, Germany.
Department of Epileptology, Medical Faculty, University of Bonn, 53127, Bonn, Germany.

Saud Alhusaini (S)

Department of Molecular and Cellular Therapeutics, The Royal College of Surgeons in Ireland, Dublin 2, Ireland.
Department of Neurology, Yale University School of Medicine, New Haven, CT, 06520, USA.

Karen M J van Loo (KMJ)

Institute of Neuropathology, Medical Faculty, University of Bonn, Section for Translational Epilepsy Research, 53127, Bonn, Germany.
Department of Epileptology and Neurology, RWTH Aachen University, 52074, Aachen, Germany.

Richard Picardo (R)

Department of Neuropathology, UCL Queen Square Institute of Neurology, London, WC1N 3BG, UK.

Zuzanna Michalak (Z)

Department of Neuropathology, UCL Queen Square Institute of Neurology, London, WC1N 3BG, UK.

Susanna Pagni (S)

Department of Clinical and Experimental Epilepsy, UCL Queen Square Institute of Neurology, Box 29, Queen Square, London, WC1N 3BG, UK.
Chalfont Centre for Epilepsy, Chalfont St Peter, Bucks, SL9 0RJ, UK.

Helena Martins Custodio (H)

Department of Clinical and Experimental Epilepsy, UCL Queen Square Institute of Neurology, Box 29, Queen Square, London, WC1N 3BG, UK.
Chalfont Centre for Epilepsy, Chalfont St Peter, Bucks, SL9 0RJ, UK.

James Mills (J)

Department of Clinical and Experimental Epilepsy, UCL Queen Square Institute of Neurology, Box 29, Queen Square, London, WC1N 3BG, UK.
Chalfont Centre for Epilepsy, Chalfont St Peter, Bucks, SL9 0RJ, UK.

Christopher D Whelan (CD)

Department of Molecular and Cellular Therapeutics, The Royal College of Surgeons in Ireland, Dublin 2, Ireland.
Imaging Genetics Center, Mark and Mary Stevens Neuroimaging and Informatics Institute, Keck School of Medicine, University of Southern California, Marina del Rey, Los Angele, CA, 90292, USA.

Greig I de Zubicaray (GI)

School of Psychology, Faculty of Health, Queensland University of Technology (QUT), Brisbane, QLD, 4059, Australia.

Katie L McMahon (KL)

School of Clinical Sciences, Faculty of Health, Queensland University of Technology (QUT), Brisbane, QLD, 4029, Australia.

Wietske van der Ent (W)

Chemical Neuroscience Group, Centre for Molecular Medicine Norway (NCMM), Faculty of Medicine, University of Oslo, 0349, Oslo, Norway.

Karolina J Kirstein-Smardzewska (KJ)

Chemical Neuroscience Group, Centre for Molecular Medicine Norway (NCMM), Faculty of Medicine, University of Oslo, 0349, Oslo, Norway.

Ettore Tiraboschi (E)

Chemical Neuroscience Group, Centre for Molecular Medicine Norway (NCMM), Faculty of Medicine, University of Oslo, 0349, Oslo, Norway.

Jonathan M Mudge (JM)

European Molecular Biology Laboratory, European Bioinformatics Institute, Wellcome Genome Campus, Cambridge, CB10 1SD, UK.

Adam Frankish (A)

European Molecular Biology Laboratory, European Bioinformatics Institute, Wellcome Genome Campus, Cambridge, CB10 1SD, UK.

Maria Thom (M)

Department of Neuropathology, UCL Queen Square Institute of Neurology, London, WC1N 3BG, UK.

Margaret J Wright (MJ)

Queensland Brain Institute, University of Queensland, St Lucia, 4072 QLD, Australia.

Paul M Thompson (PM)

Imaging Genetics Center, Mark and Mary Stevens Neuroimaging and Informatics Institute, Keck School of Medicine, University of Southern California, Marina del Rey, Los Angele, CA, 90292, USA.

Susanne Schoch (S)

Institute of Neuropathology, Medical Faculty, University of Bonn, Section for Translational Epilepsy Research, 53127, Bonn, Germany.
Department of Epileptology, Medical Faculty, University of Bonn, 53127, Bonn, Germany.

Albert J Becker (AJ)

Institute of Neuropathology, Medical Faculty, University of Bonn, Section for Translational Epilepsy Research, 53127, Bonn, Germany.

Camila V Esguerra (CV)

Chemical Neuroscience Group, Centre for Molecular Medicine Norway (NCMM), Faculty of Medicine, University of Oslo, 0349, Oslo, Norway.

Sanjay M Sisodiya (SM)

Department of Clinical and Experimental Epilepsy, UCL Queen Square Institute of Neurology, Box 29, Queen Square, London, WC1N 3BG, UK. s.sisodiya@ucl.ac.uk.
Chalfont Centre for Epilepsy, Chalfont St Peter, Bucks, SL9 0RJ, UK. s.sisodiya@ucl.ac.uk.

Articles similaires

[Redispensing of expensive oral anticancer medicines: a practical application].

Lisanne N van Merendonk, Kübra Akgöl, Bastiaan Nuijen
1.00
Humans Antineoplastic Agents Administration, Oral Drug Costs Counterfeit Drugs

Smoking Cessation and Incident Cardiovascular Disease.

Jun Hwan Cho, Seung Yong Shin, Hoseob Kim et al.
1.00
Humans Male Smoking Cessation Cardiovascular Diseases Female
Humans United States Aged Cross-Sectional Studies Medicare Part C
1.00
Humans Yoga Low Back Pain Female Male

Classifications MeSH